Locally Advanced Adrenocortical Carcinoma in Children and Adolescents-Enigmatic and Challenging Cases.

adrenocortical carcinoma children and adolescents locally advanced disease

Journal

Cancers
ISSN: 2072-6694
Titre abrégé: Cancers (Basel)
Pays: Switzerland
ID NLM: 101526829

Informations de publication

Date de publication:
28 Aug 2023
Historique:
received: 31 07 2023
revised: 21 08 2023
accepted: 25 08 2023
medline: 9 9 2023
pubmed: 9 9 2023
entrez: 9 9 2023
Statut: epublish

Résumé

Locally advanced tumors account for approximately 50% of children and adolescents with adrenocortical carcinoma (ACC), and of these, up to 50% relapse. We explored the five-item microscopic score and the pS-GRAS score for guiding management. Data from children and adolescents with COG stage II and III ACC registered in the MET studies were included. The five-item and pS-GRAS score were retrospectively calculated. By December 2021, 55 patients with stage II and III (stage II In patients with COG stage III, but not stage II, the five-item score affected EFS. Further studies are needed to identify patients at risk in COG stage II.

Sections du résumé

BACKGROUND BACKGROUND
Locally advanced tumors account for approximately 50% of children and adolescents with adrenocortical carcinoma (ACC), and of these, up to 50% relapse. We explored the five-item microscopic score and the pS-GRAS score for guiding management.
METHODS METHODS
Data from children and adolescents with COG stage II and III ACC registered in the MET studies were included. The five-item and pS-GRAS score were retrospectively calculated.
RESULTS RESULTS
By December 2021, 55 patients with stage II and III (stage II
CONCLUSIONS CONCLUSIONS
In patients with COG stage III, but not stage II, the five-item score affected EFS. Further studies are needed to identify patients at risk in COG stage II.

Identifiants

pubmed: 37686571
pii: cancers15174296
doi: 10.3390/cancers15174296
pmc: PMC10486626
pii:
doi:

Types de publication

Journal Article

Langues

eng

Subventions

Organisme : Deutsche Kinderkrebsstiftung
ID : 2014.16, DKS 2017.16, DKS 2021.11
Organisme : W.A. Drenckmann Stiftung
ID : not applicable
Organisme : Mitteldeutsche Kinderkrebsstiftung
ID : not applicable
Organisme : Magdeburger Förderkreis krebskranker Kinder e.V.
ID : not applicable

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Auteurs

Michaela Kuhlen (M)

Pediatrics and Adolescents Medicine, Faculty of Medicine, University of Augsburg, 86156 Augsburg, Germany.

Pascal Mier (P)

Pediatric Hematology/Oncology, Department of Pediatrics, Otto von Guericke University Children's Hospital, 39106 Magdeburg, Germany.

Marina Kunstreich (M)

Pediatrics and Adolescents Medicine, Faculty of Medicine, University of Augsburg, 86156 Augsburg, Germany.
Pediatric Hematology/Oncology, Department of Pediatrics, Otto von Guericke University Children's Hospital, 39106 Magdeburg, Germany.

Lienhard Lessel (L)

Pediatric Hematology/Oncology, Department of Pediatrics, Otto von Guericke University Children's Hospital, 39106 Magdeburg, Germany.

Christoph Slavetinsky (C)

Department of Paediatric Surgery and Paediatric Urology, University Children's Hospital Tuebingen, 72076 Tuebingen, Germany.

Jörg Fuchs (J)

Department of Paediatric Surgery and Paediatric Urology, University Children's Hospital Tuebingen, 72076 Tuebingen, Germany.

Guido Seitz (G)

Department of Pediatric Surgery and Urology, University Hospital Giessen-Marburg, 35043 Marburg, Germany.

Paul-Martin Holterhus (PM)

Division of Paediatric Endocrinology and Diabetes, Department of Paediatrics, University Hospital Schleswig-Holstein, Christian-Albrechts-University Kiel, 24105 Kiel, Germany.

Stefan A Wudy (SA)

Paediatric Endocrinology & Diabetology, Steroid Research & Mass Spectrometry Unit, Centre of Child and Adolescent Medicine, Justus Liebig University, 35392 Giessen, Germany.

Christian Vokuhl (C)

Section of Pediatric Pathology, Institute of Pathology, University of Bonn, 53127 Bonn, Germany.

Michael C Frühwald (MC)

Pediatrics and Adolescents Medicine, Faculty of Medicine, University of Augsburg, 86156 Augsburg, Germany.

Peter Vorwerk (P)

Pediatric Hematology/Oncology, Department of Pediatrics, Otto von Guericke University Children's Hospital, 39106 Magdeburg, Germany.

Antje Redlich (A)

Pediatric Hematology/Oncology, Department of Pediatrics, Otto von Guericke University Children's Hospital, 39106 Magdeburg, Germany.

Classifications MeSH