Diagnosis and management of vulvar Darier disease: A case report.

Acantholysis Darier disease Retinoids Steroids Vulva

Journal

Case reports in women's health
ISSN: 2214-9112
Titre abrégé: Case Rep Womens Health
Pays: Netherlands
ID NLM: 101682122

Informations de publication

Date de publication:
Sep 2023
Historique:
received: 20 06 2023
revised: 14 09 2023
accepted: 15 09 2023
medline: 27 9 2023
pubmed: 27 9 2023
entrez: 27 9 2023
Statut: epublish

Résumé

Darier disease is an autosomal dominant disorder with hyperkeratotic papules affecting primarily seborrheic areas of the upper chest, back, forehead, scalp, nasolabial folds, ears, and, less frequently, the oral mucosa. A typical eruption consists of keratotic and crusted skin-colored papules and plaques. Pruritus occurs in 80% of patients, and pain is rare. Lesions can be triggered by exposure to ultraviolet light, heat, or stress. Secondary infections of the lesions are a common complication. A definitive diagnosis is obtained by a biopsy showing histological features such as acantholysis, suprabasal clefts, and "corps rond and grains". Here we present a 37-year-old woman admitted to the gynecology department with pruritic lesions she had noticed on her vulva and perineum for three months. A vulvar biopsy led to the diagnosis of Darier disease. She was referred to the dermatology department and treated with oral acitretin since systemic retinoids are offered as the first-line treatment of the disease.

Identifiants

pubmed: 37753222
doi: 10.1016/j.crwh.2023.e00545
pii: S2214-9112(23)00069-3
pmc: PMC10518574
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e00545

Informations de copyright

© 2023 The Authors. Published by Elsevier B.V.

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Auteurs

Ipek Evruke (I)

Akcakoca State Hospital, Department of Obstetrics and Gynecology, Duzce, Turkey.

Funda Gungor Ugurlucan (FG)

Istanbul University, Istanbul Faculty of Medicine, Department of Obstetrics and Gynecology, Istanbul, Turkey.

Begum Yeni Erdem (BY)

Istanbul University, Istanbul Faculty of Medicine, Department of Pathology, Istanbul, Turkey.

Sule Ozturk Sari (SO)

Istanbul University, Istanbul Faculty of Medicine, Department of Pathology, Istanbul, Turkey.

Classifications MeSH