Four Novel Disease-Causing Variants in the

CADASIL next-generation sequencing (NGS) targeted gene sequencing the NOTCH3 gene

Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
28 Aug 2023
Historique:
received: 01 08 2023
revised: 21 08 2023
accepted: 22 08 2023
medline: 28 9 2023
pubmed: 28 9 2023
entrez: 28 9 2023
Statut: epublish

Résumé

Cerebral autosomal dominant arteriopathy with subcortical infarcts and leukoencephalopathy (CADASIL) is an inherited disease with unknown mechanisms and a broad phenotypic spectrum. It is caused by pathogenic variants in the Peripheral blood samples were collected from five patients from four unrelated families to extract genomic DNA. In four patients, analysis of exons 2, 3, 4, 5, 6 and adjacent intronic regions of the We found four previously undescribed pathogenic variants in the

Sections du résumé

BACKGROUND BACKGROUND
Cerebral autosomal dominant arteriopathy with subcortical infarcts and leukoencephalopathy (CADASIL) is an inherited disease with unknown mechanisms and a broad phenotypic spectrum. It is caused by pathogenic variants in the
CASE PRESENTATION METHODS
Peripheral blood samples were collected from five patients from four unrelated families to extract genomic DNA. In four patients, analysis of exons 2, 3, 4, 5, 6 and adjacent intronic regions of the
CONCLUSION CONCLUSIONS
We found four previously undescribed pathogenic variants in the

Identifiants

pubmed: 37761855
pii: genes14091715
doi: 10.3390/genes14091715
pmc: PMC10531103
pii:
doi:

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

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Auteurs

Fatima Bostanova (F)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Polina Tsygankova (P)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Ilya Nagornov (I)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Elena Dadali (E)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Lyudmila Bessonova (L)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Aleksey Kulesh (A)

Department of Neurology and Medical Genetics, Vagner Perm State Medical University, Perm 614990, Russia.

Viktor Drobakha (V)

Department of Neurology and Medical Genetics, Vagner Perm State Medical University, Perm 614990, Russia.

Irina Danchenko (I)

Perm Regional Clinical Hospital Perm Multiple Sclerosis Center, Perm 614015, Russia.

Ilya Kanivets (I)

Medical Center Genomed, Perm 614036, Russia.

Ekaterina Zakharova (E)

Research Centre for Medical Genetics, Moscow 115522, Russia.

Classifications MeSH