Substantially Delayed Maturation of Growth Plate Chondrocytes in "Humanized"

ANIMAL MODELS BIOCHEMICAL MARKERS OF BONE TURNOVER BONE MODELING AND REMODELING CELL/TISSUE SIGNALING – ENDOCRINE PATHWAYS CHONDROCYTE AND CARTILAGE BIOLOGY GENETIC ANIMAL MODELS GROWTH PLATE PTH/Vit D/FGF23

Journal

JBMR plus
ISSN: 2473-4039
Titre abrégé: JBMR Plus
Pays: England
ID NLM: 101707013

Informations de publication

Date de publication:
Oct 2023
Historique:
received: 20 03 2023
revised: 05 07 2023
accepted: 11 07 2023
medline: 9 10 2023
pubmed: 9 10 2023
entrez: 9 10 2023
Statut: epublish

Résumé

Activating parathyroid hormone (PTH)/PTH-related Peptide (PTHrP) receptor (PTH1R) mutations causes Jansen's metaphyseal chondrodysplasia (JMC), a rare disease characterized by growth plate abnormalities, short stature, and PTH-independent hypercalcemia. Previously generated transgenic JMC mouse models, in which the human

Identifiants

pubmed: 37808400
doi: 10.1002/jbm4.10802
pii: JBM410802
pmc: PMC10556264
doi:

Types de publication

Journal Article

Langues

eng

Pagination

e10802

Informations de copyright

© 2023 The Authors. JBMR Plus published by Wiley Periodicals LLC on behalf of American Society for Bone and Mineral Research.

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Auteurs

Monica Reyes (M)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Damla Firat (D)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Patrick Hanna (P)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Mohd Khan (M)

Department of Orthopedic Surgery University of Pennsylvania, Perelman Medical School Philadelphia PA USA.

Michael Bruce (M)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Maria Shvedova (M)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Tatsuya Kobayashi (T)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Ernestina Schipani (E)

Department of Orthopedic Surgery University of Pennsylvania, Perelman Medical School Philadelphia PA USA.

Thomas J Gardella (TJ)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Harald Jüppner (H)

Endocrine Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.
Pediatric Nephrology Unit Massachusetts General Hospital and Harvard Medical School Boston MA USA.

Classifications MeSH