Monocular Torsional Oscillopsia in Dentato-olivary Disconnection.

Dentate nucleus Guillain-Mollaret triangle Inferior olivary nucleus Nystagmus Oscillopsia

Journal

Cerebellum (London, England)
ISSN: 1473-4230
Titre abrégé: Cerebellum
Pays: United States
ID NLM: 101089443

Informations de publication

Date de publication:
27 Oct 2023
Historique:
accepted: 22 10 2023
medline: 27 10 2023
pubmed: 27 10 2023
entrez: 27 10 2023
Statut: aheadofprint

Résumé

Monocular torsional eye oscillations are a rare form of disconjugate nystagmus and the underlying pathophysiology is not well understood. Here, we present and discuss a case with disabling torsional oscillopsia in one eye only. The patient exhibited (i) spontaneous pendular torsional nystagmus of the left eye and (ii) rhythmic involuntary movements of the soft palate and uvula, consistent with the syndrome of oculopalatal tremor with monocular nystagmus. Brain MRI revealed an infarct of the left dentate nucleus in the cerebellum and, more caudally, a secondary hypertrophic degeneration of the right inferior olivary nucleus. To account for the presence of torsional nystagmus on the eye contralateral to the side of inferior olivary hypertrophy and ipsilateral to the lesioned dentate nucleus, we discuss the hypothesis of a (inferior olivary nucleus-mediated) malfunctioning adaptation of the anterior canal vestibulo-ocular reflex.

Identifiants

pubmed: 37889471
doi: 10.1007/s12311-023-01626-1
pii: 10.1007/s12311-023-01626-1
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2023. The Author(s), under exclusive licence to Springer Science+Business Media, LLC, part of Springer Nature.

Références

Anagnostou E, Karathanasis D, Evangelopoulos ME. The Heimann-Bielschowsky phenomenon after optic neuritis. Mult Scler Relat Disord. 2022;58:103523.
doi: 10.1016/j.msard.2022.103523 pubmed: 35042093
Thurston ES, Saul RF. Superior oblique myokymia: quantitative description of the eye movement. Neurology. 1991;41:1679–81.
doi: 10.1212/WNL.41.10.1679 pubmed: 1922819
Yousry I, Dieterich M, Naidich TP, Schmid UD, Yousry TA. Superior oblique myokymia: magnetic resonance imaging support for the neurovascular compression hypothesis. Ann Neurol. 2002;51:361–8.
doi: 10.1002/ana.10118 pubmed: 11891831
Shaikh AG, Hong S, Liao K, Tian J, Solomon D, Zee DS, Optican LRJ, LM. Oculopalatal tremor explained by a model of inferior olivary hypertrophy and cerebellar plasticity. Brain. 2010;133:923–40.
doi: 10.1093/brain/awp323 pubmed: 20080879 pmcid: 2842510
Tilikete C, Desestret V. Hypertrophic olivary degeneration and palatal or oculopalatal tremor. Front Neurol. 2017;8:302.
doi: 10.3389/fneur.2017.00302 pubmed: 28706504 pmcid: 5490180
Kim JS, Moon SY, Choi KD, Kim JH, Sharpe JA. Patterns of ocular oscillation in oculopalatal tremor: imaging correlations. Neurology. 2007;68:1128–35.
doi: 10.1212/01.wnl.0000258665.37827.f6 pubmed: 17404195
Jang L, Borruat FX. Oculopalatal tremor: variations on a theme by Guillain and Mollaret. Eur Neurol. 2014;72:144–9.
doi: 10.1159/000360531 pubmed: 25139385
Tempia F, Dieringer N, Strata P. Adaptation and habituation of the vestibulo-ocular reflex in intact and inferior olive-lesioned rats. Exp Brain Res. 1991;86:568–78.
doi: 10.1007/BF00230530 pubmed: 1761090
Ito M, Sakurai M, Tongroach P. Climbing fiber induced depression of both mossy fiber responsiveness and glutamate sensitivity of cerebellar Purkinje cells. J Physiol. 1982;324:113–34.
doi: 10.1113/jphysiol.1982.sp014103 pubmed: 7097592 pmcid: 1250696
Nakada T, Kwee IL. Oculopalatal myoclonus. Brain. 1986;109:431–41.
doi: 10.1093/brain/109.3.431 pubmed: 3719284
Ito M, Nisimaru N, Yamamoto M. Specific patterns of neuronal connexions involved in the control of the rabbit’s vestibulo-ocular reflexes by the cerebellar flocculus. J Physiol. 1977;265:833–54.
doi: 10.1113/jphysiol.1977.sp011747 pubmed: 300801 pmcid: 1307851

Auteurs

Evangelos Anagnostou (E)

Department of Neurology, Eginition Hospital, National and Kapodistrian University of Athens, Vas. Sophias Avenue 74, 11528, Athens, Greece. eanagnost@eginitio.uoa.gr.

Stathis Gerakoulis (S)

Department of Neurology, Eginition Hospital, National and Kapodistrian University of Athens, Vas. Sophias Avenue 74, 11528, Athens, Greece.

Georgios Armenis (G)

Department of Neurology, Eginition Hospital, National and Kapodistrian University of Athens, Vas. Sophias Avenue 74, 11528, Athens, Greece.

Athena Zachou (A)

Research Unit of Radiology-2nd Department of Radiology, Medical School, National and Kapodistrian University of Athens, Athens, Greece.

Georgios Velonakis (G)

Research Unit of Radiology-2nd Department of Radiology, Medical School, National and Kapodistrian University of Athens, Athens, Greece.

Classifications MeSH