ClC-1 Chloride Channel: Inputs on the Structure-Function Relationship of Myotonia Congenita-Causing Mutations.

channelopathy chloride channel electrophysiology mutation myotonia

Journal

Biomedicines
ISSN: 2227-9059
Titre abrégé: Biomedicines
Pays: Switzerland
ID NLM: 101691304

Informations de publication

Date de publication:
24 Sep 2023
Historique:
received: 24 07 2023
revised: 11 08 2023
accepted: 24 08 2023
medline: 28 10 2023
pubmed: 28 10 2023
entrez: 28 10 2023
Statut: epublish

Résumé

Myotonia congenita is a hereditary muscle disease mainly characterized by muscle hyperexcitability, which leads to a sustained burst of discharges that correlates with the magnitude and duration of involuntary aftercontractions, muscle stiffness, and hypertrophy. Mutations in the chloride voltage-gated channel 1 (

Identifiants

pubmed: 37892996
pii: biomedicines11102622
doi: 10.3390/biomedicines11102622
pmc: PMC10604815
pii:
doi:

Types de publication

Journal Article Review

Langues

eng

Subventions

Organisme : Fondazione AIRC per la Ricerca sul Cancro
ID : IG 21558
Organisme : Italian Research Ministry
ID : PRIN 20174TB8KW
Organisme : Fondazione Telethon
ID : GMR22T102
Organisme : Fondazione Telethon / Cariplo
ID : GJC22008
Organisme : Universidad de Costa Rica
ID : 742-B4-318

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Auteurs

Oscar Brenes (O)

Departamento de Fisiología, Escuela de Medicina, Universidad de Costa Rica, San José 11501-2060, Costa Rica.
Centro de Investigación en Neurociencias (CIN), Universidad de Costa Rica, San José 11501-2060, Costa Rica.

Michael Pusch (M)

Istituto di Biofisica, Consiglio Nazionale delle Ricerche (CNR), Via De Marini 6, 16149 Genova, Italy.

Fernando Morales (F)

Instituto de Investigaciones en Salud (INISA), Universidad de Costa Rica, San José 11501-2060, Costa Rica.

Classifications MeSH