Two Cases of Frontal Variation of Idiopathic Calvarial Thinning-Therapeutic Effect of Denosumab and Romosozumab.

bifrontal osteodystrophy bilateral thinning of the frontal bones denosumab idiopathic calvarial thinning osteoporosis romosozumab

Journal

JCEM case reports
ISSN: 2755-1520
Titre abrégé: JCEM Case Rep
Pays: England
ID NLM: 9918609886906676

Informations de publication

Date de publication:
Nov 2023
Historique:
received: 29 06 2023
medline: 13 11 2023
pubmed: 13 11 2023
entrez: 13 11 2023
Statut: epublish

Résumé

Idiopathic calvarial thinning is a rare condition that causes progressive, painless thinning of the skull bones without systemic disease. We present 2 cases of idiopathic calvarial thinning involving the bifrontal region. Both patients exhibited forehead depression and had normal biochemical tests except for mild vitamin D deficiency. The first patient received treatment with denosumab for 3 years, showing no further progression of the skull thinning. The second patient was treated with denosumab for 3 years, followed by romosozumab for 1 year, resulting in no further progression and even slight recovery of the skull thickness. These cases demonstrate that idiopathic calvarial thinning can involve the bifrontal region and highlight the favorable treatment and prognosis with denosumab or romosozumab.

Identifiants

pubmed: 37954836
doi: 10.1210/jcemcr/luad122
pii: luad122
pmc: PMC10634628
doi:

Types de publication

Case Reports

Langues

eng

Pagination

luad122

Informations de copyright

© The Author(s) 2023. Published by Oxford University Press on behalf of the Endocrine Society.

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Auteurs

Seungjin Baek (S)

Department of Internal Medicine, Endocrine Research Institute, Severance Hospital, Yonsei University College of Medicine, Seoul 03722, Republic of Korea.

Namki Hong (N)

Department of Internal Medicine, Endocrine Research Institute, Severance Hospital, Yonsei University College of Medicine, Seoul 03722, Republic of Korea.

Yumie Rhee (Y)

Department of Internal Medicine, Endocrine Research Institute, Severance Hospital, Yonsei University College of Medicine, Seoul 03722, Republic of Korea.

Classifications MeSH