Generation of induced pluripotent stem cell line (RCMGi012-A) from fibroblasts of patient with mucopolysaccharidosis type VI.


Journal

Stem cell research
ISSN: 1876-7753
Titre abrégé: Stem Cell Res
Pays: England
ID NLM: 101316957

Informations de publication

Date de publication:
Dec 2023
Historique:
received: 18 09 2023
revised: 08 11 2023
accepted: 20 11 2023
pubmed: 26 11 2023
medline: 26 11 2023
entrez: 25 11 2023
Statut: ppublish

Résumé

Skin fibroblasts obtained from a 5-year-old girl with genetically proven (two heterozygous mutations in ARSB gene) and clinically manifested mucopolysaccharidosis type VI were successfully transformed into induced pluripotent stem cells by using Sendai virus-based reprogramming vectors including the four Yamanaka factors namely SOX2, OCT3/4, KLF4, and c-MYC. These iPSCs expressed pluripotency markers, had a normal karyotype and the potential to differentiate into three germ layers in spontaneous differentiation assay. The line may be used for cell differentiation and pharmacological investigations, and also may provide a model for development of a personalized treatment including drug screening and genome editing.

Identifiants

pubmed: 38006675
pii: S1873-5061(23)00245-3
doi: 10.1016/j.scr.2023.103259
pii:
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

103259

Informations de copyright

Copyright © 2023 The Authors. Published by Elsevier B.V. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of Competing Interest The authors declare that they have no known competing financial interests or personal relationships that could have appeared to influence the work reported in this paper.

Auteurs

Ekaterina Kondrateva (E)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation. Electronic address: ekaterina.kondratyeva@gmail.com.

Olga Grigorieva (O)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Irina Panchuk (I)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Igor Bychkov (I)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Ekaterina Zakharova (E)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Vyacheslav Tabakov (V)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Victoria Pozhitnova (V)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Ekaterina Voronina (E)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Olga Shchagina (O)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Alexander Lavrov (A)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Svetlana Smirnikhina (S)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Sergey Kutsev (S)

Research Centre for Medical Genetics, Moscow 115522, Russian Federation.

Classifications MeSH