NEUROIMAGING FINDINGS IN FETAL HEMIMEGALENCEPHALY: CASE STUDY AND REVIEW.


Journal

Fetal diagnosis and therapy
ISSN: 1421-9964
Titre abrégé: Fetal Diagn Ther
Pays: Switzerland
ID NLM: 9107463

Informations de publication

Date de publication:
25 Nov 2023
Historique:
received: 29 08 2023
accepted: 17 11 2023
medline: 27 11 2023
pubmed: 27 11 2023
entrez: 26 11 2023
Statut: aheadofprint

Résumé

Limited information exists in the prenatal literature regarding the neuroimaging features of fetal hemimegalencephaly. This report describes ultrasound and magnetic resonance imaging (MRI) findings in a second-trimester fetus with an isolated, severe form of hemimegalencephaly. The most prominent imaging findings included unilateral enlarged cerebral hemisphere and ipsilateral ventriculomegaly causing cerebral asymmetry, midline shift and macrocephaly. Abnormal cortical development imaging signs were also evident. A literature review encompassing 23 reports describing 36 cases, including ours, is presented. Characteristic ultrasound findings for the diagnosis of hemimegalencephaly are not always apparent prenatally. Asymmetric ventriculomegaly emerges as the most common but nonspecific presenting feature during routine second- or third-trimester ultrasound scans. Subsequent high-resolution prenatal neurosonography and fetal MRI facilitate definitive prenatal diagnosis, showcasting associated features primarily related to cortical migration, differentiation, and maturation. Postnatally, the prognosis is poor due to intractable seizures, hemiplegia and progressive neurodevelopmental delay.

Sections du résumé

BACKGROUND BACKGROUND
Limited information exists in the prenatal literature regarding the neuroimaging features of fetal hemimegalencephaly.
SUMMARY CONCLUSIONS
This report describes ultrasound and magnetic resonance imaging (MRI) findings in a second-trimester fetus with an isolated, severe form of hemimegalencephaly. The most prominent imaging findings included unilateral enlarged cerebral hemisphere and ipsilateral ventriculomegaly causing cerebral asymmetry, midline shift and macrocephaly. Abnormal cortical development imaging signs were also evident. A literature review encompassing 23 reports describing 36 cases, including ours, is presented.
KEY MESSAGES CONCLUSIONS
Characteristic ultrasound findings for the diagnosis of hemimegalencephaly are not always apparent prenatally. Asymmetric ventriculomegaly emerges as the most common but nonspecific presenting feature during routine second- or third-trimester ultrasound scans. Subsequent high-resolution prenatal neurosonography and fetal MRI facilitate definitive prenatal diagnosis, showcasting associated features primarily related to cortical migration, differentiation, and maturation. Postnatally, the prognosis is poor due to intractable seizures, hemiplegia and progressive neurodevelopmental delay.

Identifiants

pubmed: 38008087
pii: 000535406
doi: 10.1159/000535406
doi:

Types de publication

Journal Article Review

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

S. Karger AG, Basel.

Auteurs

Classifications MeSH