Polygenic profiles define aspects of clinical heterogeneity in attention deficit hyperactivity disorder.


Journal

Nature genetics
ISSN: 1546-1718
Titre abrégé: Nat Genet
Pays: United States
ID NLM: 9216904

Informations de publication

Date de publication:
30 Nov 2023
Historique:
received: 10 07 2021
accepted: 25 10 2023
medline: 1 12 2023
pubmed: 1 12 2023
entrez: 30 11 2023
Statut: aheadofprint

Résumé

Attention deficit hyperactivity disorder (ADHD) is a complex disorder that manifests variability in long-term outcomes and clinical presentations. The genetic contributions to such heterogeneity are not well understood. Here we show several genetic links to clinical heterogeneity in ADHD in a case-only study of 14,084 diagnosed individuals. First, we identify one genome-wide significant locus by comparing cases with ADHD and autism spectrum disorder (ASD) to cases with ADHD but not ASD. Second, we show that cases with ASD and ADHD, substance use disorder and ADHD, or first diagnosed with ADHD in adulthood have unique polygenic score (PGS) profiles that distinguish them from complementary case subgroups and controls. Finally, a PGS for an ASD diagnosis in ADHD cases predicted cognitive performance in an independent developmental cohort. Our approach uncovered evidence of genetic heterogeneity in ADHD, helping us to understand its etiology and providing a model for studies of other disorders.

Identifiants

pubmed: 38036780
doi: 10.1038/s41588-023-01593-7
pii: 10.1038/s41588-023-01593-7
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Lundbeckfonden (Lundbeck Foundation)
ID : R335-2019-2318
Organisme : Lundbeckfonden (Lundbeck Foundation)
ID : R208-2015-3951
Organisme : Lundbeckfonden (Lundbeck Foundation)
ID : R102-A9118
Organisme : Lundbeckfonden (Lundbeck Foundation)
ID : R155-2014-1724
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U24AG051129S1
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : UH2AG064706
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : UH2AG064706S1
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041022
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041028
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041048
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041089
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041106
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041117
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041120
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041134
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041148
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041156
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U01DA041174
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U24DA041123
Organisme : U.S. Department of Health & Human Services | National Institutes of Health (NIH)
ID : U24DA041147
Organisme : Fonden for Faglig Udvikling af Speciallægepraksis
ID : 38850/16
Organisme : Simons Foundation
ID : SFARI 311789
Organisme : U.S. Department of Health & Human Services | NIH | National Institute of Mental Health (NIMH)
ID : 5U01MH094432-02
Organisme : EC | Horizon 2020 Framework Programme (EU Framework Programme for Research and Innovation H2020)
ID : 667302
Organisme : EC | Horizon 2020 Framework Programme (EU Framework Programme for Research and Innovation H2020)
ID : 847879
Organisme : Helsefonden (Health Foundation)
ID : 19-8-0260

Informations de copyright

© 2023. The Author(s), under exclusive licence to Springer Nature America, Inc.

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Auteurs

Sonja LaBianca (S)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Isabell Brikell (I)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
National Centre for Register-based Research, Department of Economics and Business Economics, Aarhus University, Aarhus, Denmark.

Dorte Helenius (D)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Robert Loughnan (R)

Department of Cognitive Science, University of California, San Diego, La Jolla, CA, USA.
Center for Population Neuroscience and Genetics, Laureate Institute for Brain Research, Tulsa, OK, USA.

Joel Mefford (J)

Department of Neurology, University of California, Los Angeles, Los Angeles, CA, USA.

Clare E Palmer (CE)

Center for Human Development, University of California, San Diego, La Jolla, CA, USA.

Rebecca Walker (R)

Department of Human Genetics, University of California, Los Angeles, Los Angeles, CA, USA.
Center for Autism Research and Treatment, Semel Institute, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, USA.

Jesper R Gådin (JR)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Morten Krebs (M)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Vivek Appadurai (V)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Morteza Vaez (M)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Esben Agerbo (E)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
National Centre for Register-based Research, Department of Economics and Business Economics, Aarhus University, Aarhus, Denmark.
Centre for Integrated Register-based Research, Aarhus University, Aarhus, Denmark.

Marianne Giørtz Pedersen (MG)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
National Centre for Register-based Research, Department of Economics and Business Economics, Aarhus University, Aarhus, Denmark.
Centre for Integrated Register-based Research, Aarhus University, Aarhus, Denmark.

Anders D Børglum (AD)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
Department of Biomedicine - Human Genetics, Aarhus University, Aarhus, Denmark.
Centre for Integrative Sequencing, Aarhus University, Aarhus, Denmark.

David M Hougaard (DM)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
Center for Neonatal Screening, Department for Congenital Disorders, Statens Serum Institut, Copenhagen, Denmark.

Ole Mors (O)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
Psychosis Research Unit, Aarhus University Hospital - Psychiatry, Aarhus, Denmark.

Merete Nordentoft (M)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
Copenhagen Mental Health Center, Mental Health Services Capital Region of Denmark Copenhagen, Copenhagen, Denmark.
Department of Clinical Medicine, Faculty of Health and Medical Sciences, University of Copenhagen, Copenhagen, Denmark.

Preben Bo Mortensen (PB)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
National Centre for Register-based Research, Department of Economics and Business Economics, Aarhus University, Aarhus, Denmark.
Centre for Integrated Register-based Research, Aarhus University, Aarhus, Denmark.

Kenneth S Kendler (KS)

Virginia Institute for Psychiatric and Behavioral Genetics, Virginia Commonwealth University, Richmond, VA, USA.
Department of Psychiatry, Virginia Commonwealth University, Richmond, VA, USA.

Terry L Jernigan (TL)

Department of Cognitive Science, University of California, San Diego, La Jolla, CA, USA.
Center for Human Development, University of California, San Diego, La Jolla, CA, USA.
Department of Psychiatry, University of California, San Diego, La Jolla, CA, USA.
Department of Radiology, University of California, San Diego, La Jolla, CA, USA.

Daniel H Geschwind (DH)

Department of Neurology, University of California, Los Angeles, Los Angeles, CA, USA.
Department of Human Genetics, University of California, Los Angeles, Los Angeles, CA, USA.
Center for Autism Research and Treatment, Semel Institute, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, USA.
Program in Neurobehavioral Genetics, Semel Institute, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, USA.

Andrés Ingason (A)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.

Andrew W Dahl (AW)

Section of Genetic Medicine, University of Chicago, Chicago, IL, USA.

Noah Zaitlen (N)

Department of Neurology, University of California, Los Angeles, Los Angeles, CA, USA.

Søren Dalsgaard (S)

The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark.
National Centre for Register-based Research, Department of Economics and Business Economics, Aarhus University, Aarhus, Denmark.
Centre for Integrated Register-based Research, Aarhus University, Aarhus, Denmark.

Thomas M Werge (TM)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark. thomas.werge@regionh.dk.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark. thomas.werge@regionh.dk.
Department of Clinical Medicine, Faculty of Health and Medical Sciences, University of Copenhagen, Copenhagen, Denmark. thomas.werge@regionh.dk.

Andrew J Schork (AJ)

Institute of Biological Psychiatry, Mental Health Center Sct. Hans, Mental Health Services Copenhagen, Roskilde, Denmark. andrew.joseph.schork@regionh.dk.
The Lundbeck Foundation Initiative for Integrative Psychiatric Research, Copenhagen, Denmark. andrew.joseph.schork@regionh.dk.
Neurogenomics Division, The Translational Genomics Research Institute, Phoenix, AZ, USA. andrew.joseph.schork@regionh.dk.

Classifications MeSH