Complex Autism Spectrum Disorder in a Patient with a Novel De Novo Heterozygous

MYT1L autism spectrum disorder (ASD) de novo neurodevelopmental disorder single nucleotide variant (SNV) whole genome sequencing (WGS)

Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
24 Nov 2023
Historique:
received: 31 10 2023
revised: 20 11 2023
accepted: 20 11 2023
medline: 23 12 2023
pubmed: 23 12 2023
entrez: 23 12 2023
Statut: epublish

Résumé

Autism spectrum disorder (ASD) comprises a group of complex neurodevelopmental features seen in many different forms due to variable causes. Highly impactful ASD-susceptibility genes are involved in pathways associated with brain development, chromatin remodeling, and transcription regulation. In this study, we investigate a proband with complex ASD. Whole genome sequencing revealed a novel de novo missense mutation of a highly conserved amino acid residue (NP_001289981.1:p.His516Gln; chr2:1917275; hg38) in the

Identifiants

pubmed: 38136944
pii: genes14122122
doi: 10.3390/genes14122122
pii:
doi:

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Genome British Columbia
ID : B22ITG

Auteurs

Silas Yip (S)

Department of Medical Genetics, University of British Columbia (UBC), Vancouver, BC V6H 3N1, Canada.
BC Children's Hospital Research Institute, Vancouver, BC V6H 3N1, Canada.

Kristina Calli (K)

Department of Medical Genetics, University of British Columbia (UBC), Vancouver, BC V6H 3N1, Canada.
BC Children's Hospital Research Institute, Vancouver, BC V6H 3N1, Canada.
Autism Spectrum Interdisciplinary Research (ASPIRE) Program, Vancouver, BC V6H 3N1, Canada.

Ying Qiao (Y)

Department of Medical Genetics, University of British Columbia (UBC), Vancouver, BC V6H 3N1, Canada.
BC Children's Hospital Research Institute, Vancouver, BC V6H 3N1, Canada.
Autism Spectrum Interdisciplinary Research (ASPIRE) Program, Vancouver, BC V6H 3N1, Canada.

Brett Trost (B)

The Centre for Applied Genomics and Program in Genetics and Genomic Biology, The Hospital for Sick Children, Toronto, ON M5G 0A4, Canada.

Stephen W Scherer (SW)

The Centre for Applied Genomics and Program in Genetics and Genomic Biology, The Hospital for Sick Children, Toronto, ON M5G 0A4, Canada.
McLaughlin Centre and Department of Molecular Genetics, University of Toronto, Toronto, ON M5G 0A4, Canada.

M E Suzanne Lewis (MES)

Department of Medical Genetics, University of British Columbia (UBC), Vancouver, BC V6H 3N1, Canada.
BC Children's Hospital Research Institute, Vancouver, BC V6H 3N1, Canada.
Autism Spectrum Interdisciplinary Research (ASPIRE) Program, Vancouver, BC V6H 3N1, Canada.

Classifications MeSH