Intrathecal delivery of a bicistronic AAV9 vector expressing β-hexosaminidase A corrects Sandhoff disease in a murine model: A dosage study.

AAV GM2 gangliosidosis Sandhoff Tay-Sachs dosage gene therapy hexosaminidase A viral vector

Journal

Molecular therapy. Methods & clinical development
ISSN: 2329-0501
Titre abrégé: Mol Ther Methods Clin Dev
Pays: United States
ID NLM: 101624857

Informations de publication

Date de publication:
14 Mar 2024
Historique:
received: 10 04 2023
accepted: 30 11 2023
medline: 11 1 2024
pubmed: 11 1 2024
entrez: 11 1 2024
Statut: epublish

Résumé

The pathological accumulation of GM2 ganglioside associated with Tay-Sachs disease (TSD) and Sandhoff disease (SD) occurs in individuals who possess mutant forms of the heterodimer β-hexosaminidase A (Hex A) because of mutation of the

Identifiants

pubmed: 38205442
doi: 10.1016/j.omtm.2023.101168
pii: S2329-0501(23)00207-3
pmc: PMC10777117
doi:

Banques de données

ClinicalTrials.gov
['NCT04798235']

Types de publication

Journal Article

Langues

eng

Pagination

101168

Informations de copyright

© 2023 The Authors.

Déclaration de conflit d'intérêts

The authors declare no competing interests.

Auteurs

Alex E Ryckman (AE)

Centre for Neuroscience Studies, Queen's University, Kingston, ON K7L 3N6, Canada.

Natalie M Deschenes (NM)

Centre for Neuroscience Studies, Queen's University, Kingston, ON K7L 3N6, Canada.

Brianna M Quinville (BM)

Centre for Neuroscience Studies, Queen's University, Kingston, ON K7L 3N6, Canada.

Karlaina J L Osmon (KJL)

Centre for Neuroscience Studies, Queen's University, Kingston, ON K7L 3N6, Canada.

Melissa Mitchell (M)

Medical Genetics/Departments of Pediatrics, Queen's University, Kingston, ON K7L 2V7, Canada.

Zhilin Chen (Z)

Department of Biomedical and Molecular Sciences, Queen's University, Kingston, ON K7L 3N6, Canada.

Steven J Gray (SJ)

Department of Pediatrics, University of Texas Southwestern Medical Center, Dallas, TX 75390, USA.

Jagdeep S Walia (JS)

Centre for Neuroscience Studies, Queen's University, Kingston, ON K7L 3N6, Canada.
Department of Biomedical and Molecular Sciences, Queen's University, Kingston, ON K7L 3N6, Canada.
Medical Genetics/Departments of Pediatrics, Queen's University, Kingston, ON K7L 2V7, Canada.

Classifications MeSH