Biologically informed deep learning for explainable epigenetic clocks.


Journal

Scientific reports
ISSN: 2045-2322
Titre abrégé: Sci Rep
Pays: England
ID NLM: 101563288

Informations de publication

Date de publication:
15 Jan 2024
Historique:
received: 17 01 2023
accepted: 20 12 2023
medline: 16 1 2024
pubmed: 16 1 2024
entrez: 15 1 2024
Statut: epublish

Résumé

Ageing is often characterised by progressive accumulation of damage, and it is one of the most important risk factors for chronic disease development. Epigenetic mechanisms including DNA methylation could functionally contribute to organismal aging, however the key functions and biological processes may govern ageing are still not understood. Although age predictors called epigenetic clocks can accurately estimate the biological age of an individual based on cellular DNA methylation, their models have limited ability to explain the prediction algorithm behind and underlying key biological processes controlling ageing. Here we present XAI-AGE, a biologically informed, explainable deep neural network model for accurate biological age prediction across multiple tissue types. We show that XAI-AGE outperforms the first-generation age predictors and achieves similar results to deep learning-based models, while opening up the possibility to infer biologically meaningful insights of the activity of pathways and other abstract biological processes directly from the model.

Identifiants

pubmed: 38225268
doi: 10.1038/s41598-023-50495-5
pii: 10.1038/s41598-023-50495-5
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

1306

Subventions

Organisme : European Union's Horizon 2020
ID : 101021607
Organisme : National Research, Development and Innovation Office
ID : K128780
Organisme : Nemzeti Kutatási Fejlesztési és Innovációs Hivatal
ID : NKFIH-OTKA-FK142835
Organisme : European Union project
ID : RRF-2.3.1-21-2022-00004

Informations de copyright

© 2024. The Author(s).

Références

López-Otín, C., Blasco, M. A., Partridge, L., Serrano, M. & Kroemer, G. The hallmarks of aging. Cell 153(6), 1194–1217 (2013).
pubmed: 23746838 pmcid: 3836174 doi: 10.1016/j.cell.2013.05.039
Baker, G. & Sprott, R. Biomarkers of aging. Exp. Gerontol. 23, 223–239 (1988).
pubmed: 3058488 doi: 10.1016/0531-5565(88)90025-3
Warner, H. R. The future of aging interventions. J. Gerontol. A 59, B692–B696 (2004).
doi: 10.1093/gerona/59.7.B692
Jylhävä, J., Pedersen, N. L. & Hägg, S. Biological age predictors. EBioMedicine 21, 29–36 (2017).
pubmed: 28396265 pmcid: 5514388 doi: 10.1016/j.ebiom.2017.03.046
Field, A. E., Wang, T., Havas, A., Ideker, T. & Adams, P. D. Dna methylation clocks in aging: Categories, causes, and consequences. Mol. Cell 71, 882–895 (2018).
pubmed: 30241605 pmcid: 6520108 doi: 10.1016/j.molcel.2018.08.008
Horvath, S. Dna methylation age of human tissues and cell types. Genome Biol. 14, R115 (2013).
pubmed: 24138928 pmcid: 4015143 doi: 10.1186/gb-2013-14-10-r115
Lee, H. Y., Lee, S. D. & Shin, K.-J. Forensic DNA methylation profiling from evidence material for investigative leads. BMB Rep. 49, 359–369 (2016).
pubmed: 27099236 pmcid: 5032003 doi: 10.5483/BMBRep.2016.49.7.070
Horvath, S. & Raj, K. DNA methylation-based biomarkers and the epigenetic clock theory of ageing. Nat. Rev. Genet. 19, 371–384 (2018).
pubmed: 29643443 doi: 10.1038/s41576-018-0004-3
Berdyshev, G., Korotaev, G., Boiarskikh, G. & Vaniushin, B. Nucleotide composition of DNA and RNA from somatic tissues of humpback and its changes during spawning. Biokhimiia 31, 988–993 (1967).
Ahuja, N., Li, Q., Mohan, A. L., Baylin, S. B. & Issa, J. P. Aging and DNA methylation in colorectal mucosa and cancer. Cancer Res. 58, 5489–5494 (1998).
pubmed: 9850084
Fraga, M. F. & Esteller, M. Epigenetics and aging: The targets and the marks. Trends Genet. 23(8), 413–418 (2007).
pubmed: 17559965 doi: 10.1016/j.tig.2007.05.008
Bollati, V. et al. Decline in genomic DNA methylation through aging in a cohort of elderly subjects. Mech. Ageing Dev. 130(4), 234–239 (2009).
pubmed: 19150625 doi: 10.1016/j.mad.2008.12.003
Christensen, B. C. et al. Aging and environmental exposures alter tissue-specific DNA methylation dependent upon CPG island context. PLoS Genet. 5, e1000602 (2009).
pubmed: 19680444 pmcid: 2718614 doi: 10.1371/journal.pgen.1000602
Rodríguez-Rodero, S., Fernández-Morera, J., Fernandez, A., Menéndez-Torre, E. & Fraga, M. Epigenetic regulation of aging. Discov. Med. 10, 225–233 (2010).
pubmed: 20875344
Mugatroyd, C., Yonghe, W., Bockmühl, Y. & Spengler, D. The Janus face of DNA methylation in aging. Aging 2(2), 107–110 (2010).
pmcid: 2850147 doi: 10.18632/aging.100124
...Teschendorff, A. E. et al. Age-dependent DNA methylation of genes that are suppressed in stem cells is a hallmark of cancer. Genome Res. 20(4), 440–446 (2010).
pubmed: 20219944 pmcid: 2847747 doi: 10.1101/gr.103606.109
Bell, J. T. et al. Epigenome-wide scans identify differentially methylated regions for age and age-related phenotypes in a healthy ageing population. PLoS Genet. 8, e1002629 (2012).
pubmed: 22532803 pmcid: 3330116 doi: 10.1371/journal.pgen.1002629
Zheng, S. C., Widschwendter, M. & Teschendorff, A. E. Epigenetic drift, epigenetic clocks and cancer risk. Epigenomics 8(5), 705–719 (2016).
pubmed: 27104983 doi: 10.2217/epi-2015-0017
Bernstein, B. E. et al. The NIH roadmap epigenomics mapping consortium. Nat. Biotechnol. 28, 1045–1048 (2010).
pubmed: 20944595 pmcid: 3607281 doi: 10.1038/nbt1010-1045
...Li, Y. et al. The DNA methylome of human peripheral blood mononuclear cells. PLoS Biol. 8(11), 1–9 (2010).
doi: 10.1371/journal.pbio.1000533
Thompson, R. F. et al. Tissue-specific dysregulation of DNA methylation in aging. Aging Cell 9(4), 506–518 (2010).
pubmed: 20497131 doi: 10.1111/j.1474-9726.2010.00577.x
Baubec, T. & Schübeler, D. Genomic patterns and context specific interpretation of DNA methylation. Curr. Opin. Genet. Dev. 25, 85–92 (2014).
pubmed: 24614011 doi: 10.1016/j.gde.2013.11.015
Palla, G. et al. Hierarchy and control of ageing-related methylation networks. PLoS Comput. Biol. 17(9), e1009327. https://doi.org/10.1371/journal.pcbi.1009327 (2021).
doi: 10.1371/journal.pcbi.1009327 pubmed: 34534207 pmcid: 8480875
...Horvath, S. et al. Epigenetic clock for skin and blood cells applied to Hutchinson Gilford progeria syndrome and ex vivo studies. Aging 10, 1758–1775 (2018).
pubmed: 30048243 pmcid: 6075434 doi: 10.18632/aging.101508
...Zhang, Q. et al. Improved precision of epigenetic clock estimates across tissues and its implication for biological ageing. Genome Med. 11, 54 (2019).
pubmed: 31443728 pmcid: 6708158 doi: 10.1186/s13073-019-0667-1
Hannum, G. et al. Genome-wide methylation profiles reveal quantitative views of human aging rates. Mol. Cell 49(2), 359–367 (2013).
pubmed: 23177740 doi: 10.1016/j.molcel.2012.10.016
Levine, M. E. et al. An epigenetic biomarker of aging for lifespan and healthspan. Aging 10, 573–591 (2018).
pubmed: 29676998 pmcid: 5940111 doi: 10.18632/aging.101414
Lu, A. T. et al. DNA methylation Grimage strongly predicts lifespan and Healthspan. Aging 11, 303–327 (2019).
pubmed: 30669119 pmcid: 6366976 doi: 10.18632/aging.101684
Fahy, G. M. et al. Reversal of epigenetic aging and immunosenescent trends in humans. Aging Cell 18(6), e13028 (2019).
pubmed: 31496122 pmcid: 6826138 doi: 10.1111/acel.13028
Kabacik, S. et al. The relationship between epigenetic age and the hallmarks of aging in human cells. Nat. Aging 2, 484–493 (2002).
doi: 10.1038/s43587-022-00220-0
Aliferi, A. et al. DNA methylation-based age prediction using massively parallel sequencing data and multiple machine learning models. Forensic Sci. Int. 37, 215–226 (2018).
doi: 10.1016/j.fsigen.2018.09.003
Galkin, F. et al. Human gut microbiome aging clock based on taxonomic profiling and deep learning. iScience 23(6), 101199 (2020).
pubmed: 32534441 pmcid: 7298543 doi: 10.1016/j.isci.2020.101199
Levy, J. J. et al. Methylnet: An automated and modular deep learning approach for DNA methylation analysis. BMC Bioinform. 21, 108 (2020).
doi: 10.1186/s12859-020-3443-8
Galkin, F., Mamoshina, P., Kochetov, K., Sidorenko, D. & Zhavoronkov, A. Deepmage: A methylation aging clock developed with deep learning. Aging Dis. 12, 1252–1262 (2021).
pubmed: 34341706 pmcid: 8279523 doi: 10.14336/AD.2020.1202
Elmarakeby, H. et al. Biologically informed deep neural network for prostate cancer discovery. Nature 598, 1–5 (2021).
doi: 10.1038/s41586-021-03922-4
Gill, D. et al. Multi-omic rejuvenation of human cells by maturation phase transient reprogramming. Elife 11, e71624 (2021).
doi: 10.7554/eLife.71624
Fabregat, A. et al. The reactome pathway knowledgebase. Nucleic Acids Res. 46, 11 (2017).
Shrikumar, A., Greenside, P. & Kundaje, A. Learning Important Features Through Propagating Activation Differences (2017).
McEwen, L. et al. The pedbe clock accurately estimates dna methylation age in pediatric buccal cells. Proc. Natl. Acad. Sci. USA 117, 201820843 (2019).
Hossain, S. Visualization of Bioinformatics Data with Dash Bio 126–133 (2019).
Minteer, C. et al. Revisiting the bad luck hypothesis: Cancer risk and aging are linked to replication-driven changes to the epigenome. bioRxiv https://doi.org/10.1101/2022.09.14.507975 (2022).
doi: 10.1101/2022.09.14.507975
Clement, J. et al. Umbilical cord plasma concentrate has beneficial effects on DNA methylation grimage and human clinical biomarkers. Aging Cell 09, e13696 (2022).
doi: 10.1111/acel.13696
Conboy, I. et al. Rejuvenation of aged progenitor cells by exposure to a young systemic environment. Nature 433, 760–764 (2005).
pubmed: 15716955 doi: 10.1038/nature03260
Hoeijmakers, J. H. J. DNA damage, aging, and cancer. N. Engl. J. Med. 361(15), 1475–1485 (2009).
pubmed: 19812404 doi: 10.1056/NEJMra0804615
Schumacher, B., Pothof, J., Vijg, J. & Hoeijmakers, J. H. J. The central role of DNA damage in the ageing process. Nature 592(7856), 695–703 (2021).
pubmed: 33911272 pmcid: 9844150 doi: 10.1038/s41586-021-03307-7
Melzer, D., Pilling, L. C. & Ferrucci, L. The genetics of human ageing. Nat. Rev. Genet. 21(2), 88–101 (2020).
pubmed: 31690828 doi: 10.1038/s41576-019-0183-6
Yang, Z. et al. Correlation of an epigenetic mitotic clock with cancer risk. Genome Biol. 17, 205 (2016).
pubmed: 27716309 pmcid: 5046977 doi: 10.1186/s13059-016-1064-3
Teschendorff, A. E. A comparison of epigenetic mitotic-like clocks for cancer risk prediction. Genome Med. 12, 56 (2020).
pubmed: 32580750 pmcid: 7315560 doi: 10.1186/s13073-020-00752-3
Zhou, W. et al. Dna methylation loss in late-replicating domains is linked to mitotic cell division. Nat. Genet. 50, 591–602 (2018).
pubmed: 29610480 pmcid: 5893360 doi: 10.1038/s41588-018-0073-4
Benitah, S. A. & Welz, P. S. Circadian regulation of adult stem cell homeostasis and aging. Cell Stem Cell 26, 817–831 (2020).
pubmed: 32502402 doi: 10.1016/j.stem.2020.05.002
Takahashi, J. S. Transcriptional architecture of the mammalian circadian clock. Nat. Rev. Genet. 18, 164–179 (2017).
pubmed: 27990019 doi: 10.1038/nrg.2016.150
Masri, S. & Sassone-Corsi, P. The emerging link between cancer, metabolism, and circadian rhythms. Nat. Med. 24, 1795–1803 (2018).
pubmed: 30523327 pmcid: 6535395 doi: 10.1038/s41591-018-0271-8
Reinke, H. & Asher, G. Crosstalk between metabolism and circadian clocks. Nat. Rev. Mol. Cell Biol. 20, 227–241 (2019).
pubmed: 30635659 doi: 10.1038/s41580-018-0096-9
Patke, A., Young, M. W. & Axelrod, S. Molecular mechanisms and physiological importance of circadian rhythms. Nat. Rev. Mol. Cell Biol. 21, 67–84 (2020).
pubmed: 31768006 doi: 10.1038/s41580-019-0179-2
Nassan, M. & Videnovic, A. Circadian rhythms in neurodegenerative disorders. Nat. Rev. Neurol. 18, 7–24 (2022).
pubmed: 34759373 doi: 10.1038/s41582-021-00577-7
Maity, A. K., Hu, X., Zhu, T. & Teschendorff, A. E. Inference of age-associated transcription factor regulatory activity changes in single cells. Nat. Aging 2, 548–561 (2022).
pubmed: 37118452 doi: 10.1038/s43587-022-00233-9
Oh, E. S. & Petronis, A. Origins of human disease: The chrono-epigenetic perspective. Nat. Rev. Genet. 22, 533–546 (2021).
pubmed: 33903745 doi: 10.1038/s41576-021-00348-6
de Lima Camillo, L. P., Lapierre, L. R. & Singh, R. A pan-tissue dna-methylation epigenetic clock based on deep learning. npj Aging 8(1), 4 (2022).
pmcid: 9158789 doi: 10.1038/s41514-022-00085-y

Auteurs

Aurel Prosz (A)

Danish Cancer Institute, Copenhagen, Denmark.

Orsolya Pipek (O)

Department of Physics of Complex Systems, ELTE Eötvös Loránd University, Budapest, Hungary.

Judit Börcsök (J)

Danish Cancer Institute, Copenhagen, Denmark.
Biotech Research & Innovation Centre (BRIC), University of Copenhagen, Copenhagen, Denmark.

Gergely Palla (G)

Department of Biological Physics, ELTE Eötvös Loránd University, Budapest, Hungary.
Health Services Management Training Centre, Semmelweis University, Budapest, Hungary.

Zoltan Szallasi (Z)

Danish Cancer Institute, Copenhagen, Denmark.

Sandor Spisak (S)

Institute of Enzymology, HUN-REN Research Centre for Natural Sciences, Budapest, Hungary. spisak.sandor@ttk.hu.

István Csabai (I)

Department of Physics of Complex Systems, ELTE Eötvös Loránd University, Budapest, Hungary.

Classifications MeSH