PRKACA-related, atrial defects-polydactyly-multiple congenital malformation syndrome in an Indian patient.

PRKACA PRKACA-related atrial defects-polydactyly-multiple congenital malformation syndrome skeletal ciliopathies

Journal

American journal of medical genetics. Part A
ISSN: 1552-4833
Titre abrégé: Am J Med Genet A
Pays: United States
ID NLM: 101235741

Informations de publication

Date de publication:
15 Feb 2024
Historique:
revised: 16 01 2024
received: 06 12 2023
accepted: 27 01 2024
medline: 15 2 2024
pubmed: 15 2 2024
entrez: 15 2 2024
Statut: aheadofprint

Résumé

PRKACA-related, atrial defects-polydactyly-multiple congenital malformation syndrome is a recently described skeletal ciliopathy, which is caused by disease-causing variants in PRKACA. The primary phenotypic description includes atrial septal defects, and limb anomalies including polydactyly and short limbs. To date, only four molecularly proven patients have been reported in the literature with a recurrent variant, c.409G>A p.Gly137Arg in PRKACA. In this study, we report the fifth affected individual with the same variant and review the clinical features and radiographic findings of this rare syndrome.

Identifiants

pubmed: 38357848
doi: 10.1002/ajmg.a.63566
doi:

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Pagination

e63566

Subventions

Organisme : Department of Biotechnology, Ministry of Science and Technology, India
ID : BTI/AAQ/01/CDFD-Flagship/2019
Organisme : Department of Science and Technology, Ministry of Science and Technology, India
ID : SB/SO/HS/005/2014

Informations de copyright

© 2024 Wiley Periodicals LLC.

Auteurs

Sivagamy Sithambaram (S)

Manchester Universities Hospital, NHS Foundation Trust, Manchester, UK.

Prince Jacob (P)

Department of Medical Genetics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal, Karnataka, India.

Kausthubham Neethukrishna (K)

Department of Medical Genetics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal, Karnataka, India.

Gandham SriLakshmi Bhavani (GS)

Department of Medical Genetics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal, Karnataka, India.

Ashwin Dalal (A)

Diagnostics Division, Centre for DNA Fingerprinting & Diagnostics, Hyderabad, India.

Hitesh Shah (H)

Department of Pediatric Orthopaedics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal, Karnataka, India.

Katta Mohan Girisha (KM)

Department of Medical Genetics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal, Karnataka, India.
Department of Genetics, College of Medicine and Health Sciences, Sultan Qaboos University, Muscat, Oman.

Classifications MeSH