Heterogeneity of small duct- and large duct-type intrahepatic cholangiocarcinoma.

cholangiocarcinoma heterogeneity intrahepatic molecular pathology surgical oncology

Journal

Histopathology
ISSN: 1365-2559
Titre abrégé: Histopathology
Pays: England
ID NLM: 7704136

Informations de publication

Date de publication:
26 Feb 2024
Historique:
revised: 29 01 2024
received: 16 10 2023
accepted: 09 02 2024
medline: 27 2 2024
pubmed: 27 2 2024
entrez: 27 2 2024
Statut: aheadofprint

Résumé

The histological subtype of intrahepatic cholangiocarcinoma (iCCA) is associated with different mutational characteristics that impact clinical management. So far, data are lacking on the presence of small duct iCCA (SD-iCCA) and large duct iCCA (LD-iCCA) in a single patient. The aim of the current study was to determine the presence and degree of intratumoural heterogeneity of SD- and LD-iCCA features in different tumour regions. All patients treated with surgically resected iCCA at Frankfurt University Hospital between December 2005 and March 2023 were retrospectively analysed. Histomorphological features of SD- and LD-iCCA were evaluated by an expert hepatobiliary pathologist. Tissue samples suspicious for subtype heterogeneity were further investigated. Immunohistochemistry for N-cadherin, S100P, MUC5AC, MUC6, TFF1 and AGR2 and mutational profiling with the Illumina TruSight Oncology 500 (TSO500) assay were performed separately for the SD- and LD-iCCA regions. Of 129 patients with surgically resected iCCA, features of either SD- or LD-iCCA were present in 67.4% (n = 87) and 24.8% of the patients (n = 32), respectively; 7.8% (n = 10) had histomorphological features of both SD- and LD-iCCA, seven patients (5.4%) of which had sufficient formalin-fixed, paraffin-embedded tissue for further analysis. Heterogeneity of both subtypes could be confirmed with immunohistochemistry. In five of seven (71.4%) patients, molecular profiling revealed intratumoural differences in genetic alterations between the SD- and LD-iCCA region. In one patient, a BRAF mutation (p.V600E) was found in the SD-iCCA but not in the LD-iCCA region of the tumour. A marked portion of patients with iCCA exhibits both SD- and LD-iCCA in different tumour regions. In case of the presence of histopathological heterogeneity, mutational profiling should be considered to avoid missing therapeutically relevant genetic alterations.

Identifiants

pubmed: 38409827
doi: 10.1111/his.15162
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Goethe-Universität Frankfurt am Main

Informations de copyright

© 2024 The Authors. Histopathology published by John Wiley & Sons Ltd.

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Auteurs

Maximilian N Kinzler (MN)

Goethe University Frankfurt, University Hospital, Medical Clinic 1, Frankfurt am Main, Germany.

Falko Schulze (F)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Jan Jeroch (J)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Christina Schmitt (C)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Silvana Ebner (S)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Steffen Gretser (S)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Julia Bein (J)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Fabian Finkelmeier (F)

Goethe University Frankfurt, University Hospital, Medical Clinic 1, Frankfurt am Main, Germany.
Frankfurt Cancer Institute (FCI), Goethe University Frankfurt, Frankfurt am Main, Germany.

Jörg Trojan (J)

Goethe University Frankfurt, University Hospital, Medical Clinic 1, Frankfurt am Main, Germany.

Stefan Zeuzem (S)

Goethe University Frankfurt, University Hospital, Medical Clinic 1, Frankfurt am Main, Germany.

Andreas A Schnitzbauer (AA)

Department of General, Visceral, Transplant and Thoracic Surgery, Goethe University Frankfurt, University Hospital, Frankfurt am Main, Germany.

Melanie C Demes (MC)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Henning Reis (H)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.

Peter J Wild (PJ)

Goethe University Frankfurt, University Hospital, Dr Senckenberg Institute of Pathology, Frankfurt am Main, Germany.
Frankfurt Cancer Institute (FCI), Goethe University Frankfurt, Frankfurt am Main, Germany.
Frankfurt Institute for Advanced Studies (FIAS), Frankfurt am Main, Germany.

Dirk Walter (D)

Goethe University Frankfurt, University Hospital, Medical Clinic 1, Frankfurt am Main, Germany.

Classifications MeSH