Quantification of Solid Embryonic Cerebellar Graft Volume in a Degenerative Ataxia Model.

Cerebellum Lurcher mice Neurotransplantation Olivocerebellar degeneration

Journal

Cerebellum (London, England)
ISSN: 1473-4230
Titre abrégé: Cerebellum
Pays: United States
ID NLM: 101089443

Informations de publication

Date de publication:
02 Mar 2024
Historique:
accepted: 23 02 2024
medline: 2 3 2024
pubmed: 2 3 2024
entrez: 2 3 2024
Statut: aheadofprint

Résumé

Substitution of lost neurons by neurotransplantation would be a possible management of advanced degenerative cerebellar ataxias in which insufficient cerebellar reserve remains. In this study, we examined the volume and structure of solid embryonic cerebellar grafts in adult Lurcher mice, a model of olivocerebellar degeneration, and their healthy littermates. Grafts taken from enhanced green fluorescent protein (EGFP)-positive embryos were injected into the cerebellum of host mice. Two or six months later, the brains were examined histologically. The grafts were identified according to the EGFP fluorescence in frozen sections and their volumes were estimated using the Cavalieri principle. For gross histological evaluation, graft-containing slices were processed using Nissl and hematoxylin-eosin staining. Adjustment of the volume estimation approach suggested that it is reasonable to use all sections without sampling, but that calculation of values for up to 20% of lost section using linear interpolation does not constitute substantial error. Mean graft volume was smaller in Lurchers than in healthy mice when examined 6 months after the transplantation. We observed almost no signs of graft destruction. In some cases, compact grafts disorganized the structure of the host's cerebellar cortex. In Lurchers, the grafts had a limited contact with the host's cerebellum. Also, graft size was of greater variability in Lurchers than in healthy mice. The results are in compliance with our previous findings that Lurcher phenotype-associated factors have a negative effect on graft development. These factors can hypothetically include cerebellar morphology, local tissue milieu, or systemic factors such as immune system abnormalities.

Identifiants

pubmed: 38430389
doi: 10.1007/s12311-024-01676-z
pii: 10.1007/s12311-024-01676-z
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Univerzita Karlova v Praze
ID : Cooperatio Program (research areas NEUR and MED/DIAG)
Organisme : Ministry of Education, Youth and Sports of the Czech Republic
ID : CZ.02.1.01/0.0/0.0/16_019/0000787 "Fighting INfectious Diseases"
Organisme : Ministry of Education, Youth and Sports of the Czech Republic
ID : CZ.02.1.01/0.0/0.0/16_019/0000787 "Fighting INfectious Diseases"
Organisme : European Union - Next Generation EU
ID : LX22NPO5107 (MEYS)

Informations de copyright

© 2024. The Author(s), under exclusive licence to Springer Science+Business Media, LLC, part of Springer Nature.

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Auteurs

Zdenka Purkartova (Z)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic.

Kristyna Krakorova (K)

Department of Neurology, Faculty Hospital in Pilsen and Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Vaclav Babuska (V)

Department of Medical Chemistry and Biochemistry, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Jan Tuma (J)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic.
Laboratory of Neurodegenerative Disorders, Biomedical Center, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Zbyněk Houdek (Z)

Department of Biology, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Nilpawan Roy Choudhury (N)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic.

Stepan Kapl (S)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic.

Yaroslav Kolinko (Y)

Department of Histology and Embryology, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.
Laboratory of Quantitative Histology, Biomedical Center, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Martina Sucha (M)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic.

Elena Porras-Garcia (E)

Department of Physiology, Anatomy and Cellular Biology, Pablo de Olavide University, Seville, Spain.

Milena Kralickova (M)

Department of Histology and Embryology, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic.

Jan Cendelin (J)

Department of Pathophysiology, Faculty of Medicine in Pilsen, Charles University, Alej Svobody 76, 323 00, Plzen, Czech Republic. jan.cendelin@lfp.cuni.cz.
Laboratory of Neurodegenerative Disorders, Biomedical Center, Faculty of Medicine in Pilsen, Charles University, Pilsen, Czech Republic. jan.cendelin@lfp.cuni.cz.

Classifications MeSH