Concurrent adrenal and extra-adrenal myelolipoma: A case report.

Adrenal Computed tomography Myelolipoma Retroperitoneal

Journal

International journal of surgery case reports
ISSN: 2210-2612
Titre abrégé: Int J Surg Case Rep
Pays: Netherlands
ID NLM: 101529872

Informations de publication

Date de publication:
Mar 2024
Historique:
received: 06 01 2024
revised: 09 02 2024
accepted: 12 02 2024
medline: 3 3 2024
pubmed: 3 3 2024
entrez: 2 3 2024
Statut: ppublish

Résumé

Myelolipoma, a benign tumor characterized by mature fat cells and hematopoietic cells, is predominantly found in the adrenal glands, accounting for 6-16 % of all adrenal tumors. These tumors are often asymptomatic and discovered incidentally during imaging. We present a rare case of concurrent adrenal and extra-adrenal myelolipomas, contributing to the limited research in this area. A 65-year-old female with a history of Steven-Johnson syndrome presented with epigastric pain, initially diagnosed with emphysematous cholecystitis. Imaging revealed unexpected lesions near the left kidney. During surgery for presumed cholecystitis, significant hemorrhaging occurred following an attempted biopsy of the left adrenal lesion. This complication necessitated a complete adrenalectomy. Pathological examination confirmed the presence of myelolipomas in the left adrenal gland, para-aortic, and left para-iliac regions. The simultaneous occurrence of adrenal and extra-adrenal myelolipomas is exceptionally rare, posing diagnostic and management challenges. This case highlights the complexity of managing patients with multiple comorbidities and the critical importance of differentiating myelolipomas from other fat-containing retroperitoneal masses. The incidental discovery of these tumors and their potential for significant intraoperative complications, as seen in our case, underscores the need for careful surgical planning and thorough preoperative assessment. This case emphasizes the diagnostic challenges and management complexities in patients with incidental findings of myelolipoma, particularly when accompanied by significant medical histories. The occurrence of unexpected intraoperative complications highlights the importance of cautious decision-making in surgical interventions. This report provides valuable insights into the unpredictable nature of medical practice and the management of rare pathologies.

Identifiants

pubmed: 38430892
pii: S2210-2612(24)00179-2
doi: 10.1016/j.ijscr.2024.109398
pmc: PMC10943931
pii:
doi:

Types de publication

Case Reports

Langues

eng

Pagination

109398

Informations de copyright

Copyright © 2024 The Authors. Published by Elsevier Ltd.. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of competing interest The authors declare that they have no conflict of interest.

Références

Lancet Diabetes Endocrinol. 2020 Nov;8(11):894-902
pubmed: 33065059
World J Surg Oncol. 2008 Jul 04;6:72
pubmed: 18601731
Radiographics. 1997 Nov-Dec;17(6):1373-85
pubmed: 9397452
Endocr J. 2020 Feb 28;67(2):141-152
pubmed: 31694993
Endocrine. 2017 Nov;58(2):289-294
pubmed: 28866749
Endocrine. 2018 Jan;59(1):7-15
pubmed: 29164520
Int J Surg. 2023 May 01;109(5):1136-1140
pubmed: 37013953
Clin Endocrinol (Oxf). 2020 Jul;93(1):11-18
pubmed: 32275787
BMC Urol. 2023 Jul 8;23(1):114
pubmed: 37420221
Clin Nucl Med. 2020 Jul;45(7):570-571
pubmed: 32453082
Curr Urol. 2020 Jun;14(2):85-91
pubmed: 32774233
Abdom Imaging. 2014 Apr;39(2):394-7
pubmed: 24370965

Auteurs

Golnaz Moradi (G)

Department of Radiology, Sina Hospital, Tehran University of Medical Sciences, Tehran, Iran. Electronic address: Golnazz.moradi@gmail.com.

Diana Zarei (D)

Advanced Diagnostic and Interventional Radiology Research Center (ADIR), Tehran University of Medical Sciences, Tehran, Iran.

Mahbod Issaiy (M)

Advanced Diagnostic and Interventional Radiology Research Center (ADIR), Tehran University of Medical Sciences, Tehran, Iran.

Classifications MeSH