RHBDL4-triggered downregulation of COPII adaptor protein TMED7 suppresses TLR4-mediated inflammatory signaling.


Journal

Nature communications
ISSN: 2041-1723
Titre abrégé: Nat Commun
Pays: England
ID NLM: 101528555

Informations de publication

Date de publication:
07 Mar 2024
Historique:
received: 09 02 2023
accepted: 30 01 2024
medline: 8 3 2024
pubmed: 8 3 2024
entrez: 7 3 2024
Statut: epublish

Résumé

The toll-like receptor 4 (TLR4) is a central regulator of innate immunity that primarily recognizes bacterial lipopolysaccharide cell wall constituents to trigger cytokine secretion. We identify the intramembrane protease RHBDL4 as a negative regulator of TLR4 signaling. We show that RHBDL4 triggers degradation of TLR4's trafficking factor TMED7. This counteracts TLR4 transport to the cell surface. Notably, TLR4 activation mediates transcriptional upregulation of RHBDL4 thereby inducing a negative feedback loop to reduce TLR4 trafficking to the plasma membrane. This secretory cargo tuning mechanism prevents the over-activation of TLR4-dependent signaling in an in vitro Mycobacterium tuberculosis macrophage infection model and consequently alleviates septic shock in a mouse model. A hypomorphic RHBDL4 mutation linked to Kawasaki syndrome, an ill-defined inflammatory disorder in children, further supports the pathophysiological relevance of our findings. In this work, we identify an RHBDL4-mediated axis that acts as a rheostat to prevent over-activation of the TLR4 pathway.

Identifiants

pubmed: 38453906
doi: 10.1038/s41467-024-45615-2
pii: 10.1038/s41467-024-45615-2
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

1528

Subventions

Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : ID 201348542 - CRC 1036/TP12

Informations de copyright

© 2024. The Author(s).

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Auteurs

Julia D Knopf (JD)

Center for Molecular Biology of Heidelberg University (ZMBH), Heidelberg, Germany.
Center for Biochemistry and Cologne Excellence Cluster on Cellular Stress Responses in Aging-Associated Diseases (CECAD), Faculty of Medicine, University of Cologne, Cologne, Germany.

Susanne S Steigleder (SS)

Center for Molecular Biology of Heidelberg University (ZMBH), Heidelberg, Germany.
Center for Biochemistry and Cologne Excellence Cluster on Cellular Stress Responses in Aging-Associated Diseases (CECAD), Faculty of Medicine, University of Cologne, Cologne, Germany.

Friederike Korn (F)

Center for Molecular Biology of Heidelberg University (ZMBH), Heidelberg, Germany.
Center for Biochemistry and Cologne Excellence Cluster on Cellular Stress Responses in Aging-Associated Diseases (CECAD), Faculty of Medicine, University of Cologne, Cologne, Germany.

Nathalie Kühnle (N)

Center for Molecular Biology of Heidelberg University (ZMBH), Heidelberg, Germany.

Marina Badenes (M)

Instituto Gulbenkian de Ciência (IGC), Oeiras, Portugal.
Faculty of Veterinary Medicine, Lusofona University and Faculty of Veterinary Nursing, Polytechnic Institute of Lusofonia, Lisbon, Portugal.

Marina Tauber (M)

Center for Biochemistry and Cologne Excellence Cluster on Cellular Stress Responses in Aging-Associated Diseases (CECAD), Faculty of Medicine, University of Cologne, Cologne, Germany.

Sebastian J Theobald (SJ)

Department I of Internal Medicine, Faculty of Medicine and University Hospital Cologne, University of Cologne, 50937, Cologne, Germany.
Center for Molecular Medicine Cologne (CMMC), University of Cologne, 50931, Cologne, Germany.
German Center for Infection Research (DZIF), Partner Site Bonn-Cologne, 50931, Cologne, Germany.

Jan Rybniker (J)

Department I of Internal Medicine, Faculty of Medicine and University Hospital Cologne, University of Cologne, 50937, Cologne, Germany.
Center for Molecular Medicine Cologne (CMMC), University of Cologne, 50931, Cologne, Germany.
German Center for Infection Research (DZIF), Partner Site Bonn-Cologne, 50931, Cologne, Germany.

Colin Adrain (C)

Instituto Gulbenkian de Ciência (IGC), Oeiras, Portugal.
Patrick G Johnston Centre for Cancer Research, Queen's University Belfast, Belfast, UK.

Marius K Lemberg (MK)

Center for Molecular Biology of Heidelberg University (ZMBH), Heidelberg, Germany. m.lemberg@uni-koeln.de.
Center for Biochemistry and Cologne Excellence Cluster on Cellular Stress Responses in Aging-Associated Diseases (CECAD), Faculty of Medicine, University of Cologne, Cologne, Germany. m.lemberg@uni-koeln.de.

Classifications MeSH