A Wolfram-like syndrome family: Case report.

WFS1 gene optic atrophy sensorineural hearing loss wolfram-like syndrome

Journal

European journal of ophthalmology
ISSN: 1724-6016
Titre abrégé: Eur J Ophthalmol
Pays: United States
ID NLM: 9110772

Informations de publication

Date de publication:
12 Mar 2024
Historique:
medline: 12 3 2024
pubmed: 12 3 2024
entrez: 12 3 2024
Statut: aheadofprint

Résumé

Wolfram-like syndrome (WFLS) is an autosomal dominant inherited disease characterized by a single heterozygous pathogenic variant in the We reported a case of a 10-year-old boy and his family members who initially experienced hearing impairment (HI), followed by optic atrophy. Genetic testing revealed the presence of a Wolfram-like syndrome, a rare neurodegenerative genetic disorder, manifested as deafness, optic atrophy, and diabetes mellitus. There hasn't been a definite treatment yet. Early identification of the variant in the

Sections du résumé

BACKGROUND BACKGROUND
Wolfram-like syndrome (WFLS) is an autosomal dominant inherited disease characterized by a single heterozygous pathogenic variant in the
CASE PRESENTATION METHODS
We reported a case of a 10-year-old boy and his family members who initially experienced hearing impairment (HI), followed by optic atrophy. Genetic testing revealed the presence of a
CONCLUSION CONCLUSIONS
Wolfram-like syndrome, a rare neurodegenerative genetic disorder, manifested as deafness, optic atrophy, and diabetes mellitus. There hasn't been a definite treatment yet. Early identification of the variant in the

Identifiants

pubmed: 38470317
doi: 10.1177/11206721241237552
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

11206721241237552

Déclaration de conflit d'intérêts

Declaration of conflicting interestsThe author(s) declared no potential conflicts of interest with respect to the research, authorship, and/or publication of this article.

Auteurs

Siying Li (S)

Department of Ophthalmology, Peking University People's Hospital, Beijing, China.
Eye Diseases and Optometry Institute, Beijing, China.
Beijing Key Laboratory of Diagnosis and Therapy of Retinal and Choroid Diseases, College of Optometry, Peking University Health Science Center, Beijing, China.

Xiaoxin Li (X)

Department of Ophthalmology, Peking University People's Hospital, Beijing, China.
Eye Diseases and Optometry Institute, Beijing, China.
Beijing Key Laboratory of Diagnosis and Therapy of Retinal and Choroid Diseases, College of Optometry, Peking University Health Science Center, Beijing, China.

Jinfeng Qu (J)

Department of Ophthalmology, Peking University People's Hospital, Beijing, China.
Eye Diseases and Optometry Institute, Beijing, China.
Beijing Key Laboratory of Diagnosis and Therapy of Retinal and Choroid Diseases, College of Optometry, Peking University Health Science Center, Beijing, China.

Classifications MeSH