Clinical safety and feasibility of a novel implantable neuroimmune modulation device for the treatment of rheumatoid arthritis: initial results from the randomized, double-blind, sham-controlled RESET-RA study.

Inflammatory reflex Neuroimmune modulation Rheumatoid arthritis Vagus nerve stimulation

Journal

Bioelectronic medicine
ISSN: 2332-8886
Titre abrégé: Bioelectron Med
Pays: England
ID NLM: 101660849

Informations de publication

Date de publication:
13 Mar 2024
Historique:
received: 21 10 2023
accepted: 12 12 2023
medline: 13 3 2024
pubmed: 13 3 2024
entrez: 13 3 2024
Statut: epublish

Résumé

Rheumatoid arthritis (RA) is a chronic inflammatory autoimmune disease that causes persistent synovitis, bone damage, and progressive joint destruction. Neuroimmune modulation through electrical stimulation of the vagus nerve activates the inflammatory reflex and has been shown to inhibit the production and release of inflammatory cytokines and decrease clinical signs and symptoms in RA. The RESET-RA study was designed to determine the safety and efficacy of an active implantable device for treating RA. The RESET-RA study is a randomized, double-blind, sham-controlled, multi-center, two-stage pivotal trial that enrolled patients with moderate-to-severe RA who were incomplete responders or intolerant to at least one biologic or targeted synthetic disease-modifying anti-rheumatic drug. A neuroimmune modulation device (SetPoint Medical, Valencia, CA) was implanted on the left cervical vagus nerve within the carotid sheath in all patients. Following post-surgical clearance, patients were randomly assigned (1:1) to active stimulation or non-active (control) stimulation for 1 min once per day. A predefined blinded interim analysis was performed in patients enrolled in the study's initial stage (Stage 1) that included demographics, enrollment rates, device implantation rates, and safety of the surgical procedure, device, and stimulation over 12 weeks of treatment. Sixty patients were implanted during Stage 1 of the study. All device implant procedures were completed without intraoperative complications, infections, or surgical revisions. No unanticipated adverse events were reported during the perioperative period and at the end of 12 weeks of follow-up. No study discontinuations were due to adverse events, and no serious adverse events were related to the device or stimulation. Two serious adverse events were related to the implantation procedure: vocal cord paresis and prolonged hoarseness. These were reported in two patients and are known complications of surgical implantation procedures with vagus nerve stimulation devices. The adverse event of vocal cord paresis resolved after vocal cord augmentation injections with filler and speech therapy. The prolonged hoarseness had improved with speech therapy, but mild hoarseness persists. The surgical procedures for implantation of the novel neuroimmune modulation device for the treatment of RA were safe, and the device and its use were well tolerated. NCT04539964; August 31, 2020.

Sections du résumé

BACKGROUND BACKGROUND
Rheumatoid arthritis (RA) is a chronic inflammatory autoimmune disease that causes persistent synovitis, bone damage, and progressive joint destruction. Neuroimmune modulation through electrical stimulation of the vagus nerve activates the inflammatory reflex and has been shown to inhibit the production and release of inflammatory cytokines and decrease clinical signs and symptoms in RA. The RESET-RA study was designed to determine the safety and efficacy of an active implantable device for treating RA.
METHODS METHODS
The RESET-RA study is a randomized, double-blind, sham-controlled, multi-center, two-stage pivotal trial that enrolled patients with moderate-to-severe RA who were incomplete responders or intolerant to at least one biologic or targeted synthetic disease-modifying anti-rheumatic drug. A neuroimmune modulation device (SetPoint Medical, Valencia, CA) was implanted on the left cervical vagus nerve within the carotid sheath in all patients. Following post-surgical clearance, patients were randomly assigned (1:1) to active stimulation or non-active (control) stimulation for 1 min once per day. A predefined blinded interim analysis was performed in patients enrolled in the study's initial stage (Stage 1) that included demographics, enrollment rates, device implantation rates, and safety of the surgical procedure, device, and stimulation over 12 weeks of treatment.
RESULTS RESULTS
Sixty patients were implanted during Stage 1 of the study. All device implant procedures were completed without intraoperative complications, infections, or surgical revisions. No unanticipated adverse events were reported during the perioperative period and at the end of 12 weeks of follow-up. No study discontinuations were due to adverse events, and no serious adverse events were related to the device or stimulation. Two serious adverse events were related to the implantation procedure: vocal cord paresis and prolonged hoarseness. These were reported in two patients and are known complications of surgical implantation procedures with vagus nerve stimulation devices. The adverse event of vocal cord paresis resolved after vocal cord augmentation injections with filler and speech therapy. The prolonged hoarseness had improved with speech therapy, but mild hoarseness persists.
CONCLUSIONS CONCLUSIONS
The surgical procedures for implantation of the novel neuroimmune modulation device for the treatment of RA were safe, and the device and its use were well tolerated.
TRIAL REGISTRATION BACKGROUND
NCT04539964; August 31, 2020.

Identifiants

pubmed: 38475923
doi: 10.1186/s42234-023-00138-x
pii: 10.1186/s42234-023-00138-x
doi:

Banques de données

ClinicalTrials.gov
['NCT04539964']

Types de publication

Journal Article

Langues

eng

Pagination

8

Subventions

Organisme : SetPoint Medical
ID : SetPoint Medical

Informations de copyright

© 2024. The Author(s).

Références

Aalbers MW, Rijkers K, Klinkenberg S, Majoie M, Cornips EM. Vagus nerve stimulation lead removal or replacement: surgical technique, institutional experience, and literature overview. Acta Neurochir. 2015;157:1917–24. https://doi.org/10.1007/s00701-015-2547-9 .
doi: 10.1007/s00701-015-2547-9 pubmed: 26335753
Ardell JL, Nier H, Hammer M, Southerland EM, Ardell CL, Beaumont E, et al. Defining the neural fulcrum for chronic vagus nerve stimulation: implications for integrated cardiac control. J Physiol. 2017;595(22):6887–903. https://doi.org/10.1113/jp274678 .
doi: 10.1113/jp274678 pubmed: 28862330 pmcid: 5685838
Ben-Menachem E. Vagus-nerve stimulation for the treatment of Epilepsy. Lancet Neurol. 2002;1:477–82. https://doi.org/10.1016/s1474-4422(02)00220-x .
doi: 10.1016/s1474-4422(02)00220-x pubmed: 12849332
Ben-Menachem E, Hellström K, Waldton C, Augustinsson LE. Evaluation of refractory Epilepsy treated with vagus nerve stimulation for up to 5 years. Neurology. 1999;52:1265–7. https://doi.org/10.1212/wnl.52.6.1265 .
doi: 10.1212/wnl.52.6.1265 pubmed: 10214754
Bonaz B, Sinniger V, Hoffmann D, Clarençon D, Mathieu N, Dantzer C, et al. Chronic vagus nerve stimulation in Crohn’s Disease: a 6-month follow-up pilot study. Neurogastroenterol Motil. 2016;28:948–53. https://doi.org/10.1111/joim.12611 .
doi: 10.1111/joim.12611 pubmed: 26920654
Borovikova LV, Ivanova S, Zhang M, Yang H, Botchkina GI, Watkins LR, et al. Vagus nerve stimulation attenuates the systemic inflammatory response to endotoxin. Nature. 2000;405(6785):458–62. https://doi.org/10.1038/35013070 .
doi: 10.1038/35013070 pubmed: 10839541
D’Haens G, Eberhardson M, Cabrijan Z, Danese S, van den Berg R, Löwenberg M, et al. Neuroimmune modulation through vagus nerve stimulation reduces inflammatory activity in Crohn's disease patients: a prospective open label study. J Crohns Colitis. 2023;jjad151. https://doi.org/10.1093/ecco-jcc/jjad151 .
Ebina K, Hashimoto M, Yamamoto W, Hirano T, Hara R, Katayama M, et al. Drug tolerability and reasons for discontinuation of seven biologics in elderly patients with rheumatoid arthritis -the ANSWER cohort study. PLoS ONE. 2019;14(5):e0216624. https://doi.org/10.1371/journal.pone.0216624 .
doi: 10.1371/journal.pone.0216624 pubmed: 31067271 pmcid: 6505948
Fetzer S, Dibué M, Nagel AM, Trollmann R. A systematic review of magnetic resonance imaging in patients with an implanted vagus nerve stimulation system. Neuroradiology. 2021;63:1407–17. https://doi.org/10.1007/s00234-021-02705-y .
doi: 10.1007/s00234-021-02705-y pubmed: 33846830 pmcid: 8376717
Fisher B, DesMarteau JA, Koontz EH, Wilks SJ, Melamed SE. Responsive vagus nerve stimulation for drug resistant Epilepsy: a review of new features and practical guidance for advanced practice providers. Front Neurol. 2021;11:1863. https://doi.org/10.3389/fneur.2020.610379 .
doi: 10.3389/fneur.2020.610379
Frisell T, Bower H, Morin M, Baecklund E, Di Giuseppe D, Delcoigne B, et al. Safety of biological and targeted synthetic disease-modifying anti-rheumatic Drugs for rheumatoid arthritis as used in clinical practice: results from the ARTIS programme. Ann Rheum Dis. 2023;82(5):601–10. https://doi.org/10.1136/ard-2022-223762 .
doi: 10.1136/ard-2022-223762 pubmed: 36787994
Genovese MC, Gaylis NB, Sikes D, Kivitz A, Horowitz DL, Peterfy C, et al. Safety and efficacy of neurostimulation with a miniaturised vagus nerve stimulation device in patients with multidrug-refractory rheumatoid arthritis: a two-stage multicentre, randomised pilot study. Lancet Rheumatol. 2020;2(9):e527-538. https://doi.org/10.1016/S2665-9913(20)30172-7 .
doi: 10.1016/S2665-9913(20)30172-7
Hammer N, Glätzner J, Feja C, Kühne C, Meixensberger J, Planitzer U, et al. Human vagus nerve branching in the cervical region. PLoS One. 2015;10(2):e0118006. https://doi.org/10.1371/journal.pone.0118006 .
Handforth A, DeGiorgio CM, Schachter SC, Uthman BM, Naritoku DK, Tecoma ES, et al. Vagus nerve stimulation therapy for partial-onset seizures: a randomized active-control trial. Neurology. 1998;51:48–55. https://doi.org/10.1212/wnl.51.1.48 .
doi: 10.1212/wnl.51.1.48 pubmed: 9674777
Heck C, Helmers SL, DeGiorgio CM. Vagus nerve stimulation therapy, Epilepsy, and device parameters: scientific basis and recommendations for use. Neurology. 2002;59(6 suppl 4):31–7. https://doi.org/10.1212/wnl.59.6_suppl_4.s31 .
doi: 10.1212/wnl.59.6_suppl_4.s31
Hsieh PH, Wu O, Geue C, McIntosh E, McInnes IB, Siebert S. Economic burden of rheumatoid arthritis: a systematic review of literature in biologic era. Ann Rheum Dis. 2020;79(6):771–7. https://doi.org/10.1136/annrheumdis-2019-216243 .
doi: 10.1136/annrheumdis-2019-216243 pubmed: 32245893
Kahlow H, Olivecrona M. Complications of vagal nerve stimulation for drug-resistant Epilepsy: a single center longitudinal study of 143 patients. Seizure. 2013;22:827–33. https://doi.org/10.1016/j.seizure.2013.06.011 .
doi: 10.1016/j.seizure.2013.06.011 pubmed: 23867218
Kawatkar AA, Jacobsen SJ, Levy GD, Medhekar SS, Venkatasubramaniam KV, Herrinton LJ. Direct medical expenditure associated with rheumatoid arthritis in a nationally representative sample from the medical expenditure panel survey. Arthritis Care Res (Hoboken). 2012;64(11):1649–56. https://doi.org/10.1002/acr.21755 .
doi: 10.1002/acr.21755 pubmed: 22674912
Klinkenberg S, Aalbers MW, Vles JS, Cornips EM, Rijkers K, Leenen L, et al. Vagus nerve stimulation in children with intractable Epilepsy: a randomized controlled trial. Dev Med Child Neurol. 2012;54(9):855–61. https://doi.org/10.1111/j.1469-8749.2012.04305.x .
doi: 10.1111/j.1469-8749.2012.04305.x pubmed: 22540141
Koopman FA, Chavan SS, Miljko S, Grazio S, Sokolovic S, Schuurman PR, et al. Vagus nerve stimulation inhibits cytokine production and attenuates disease severity in rheumatoid arthritis. Proceedings of the National Academy of Sciences. 2016;113(29):8284–9. https://doi.org/10.1073/pnas.1605635113 .
doi: 10.1073/pnas.1605635113
Koopman FA, Van Maanen MA, Vervoordeldonk MJ, Tak PP. Balancing the autonomic nervous system to reduce inflammation in rheumatoid arthritis. J Intern Med. 2017;282(1):64–75. https://doi.org/10.1111/joim.12626 .
doi: 10.1111/joim.12626 pubmed: 28547815
Levine YA, Faltys M, Zitnik R. Activation of the Inflammatory Reflex in Rheumatoid Arthritis and Inflammatory Bowel Disease; preclinical evidence. In: Krames ES Peckham PH Rezai AR eds. Neuromodulation. 2nd ed. London: Elsevier; 2018a. p. 1493–502.
Levine YA, Simon J, Faltys M. Neurophysiologic and chronic safety testing of a miniaturized active implanted device with Integrated Electrodes for Bioelectronic Medicine Applications. Conf Proc IEEE Eng Med Biol Soc. 2018b;3689–92. https://doi.org/10.1109/EMBC.2018.8513061 .
Levine YA, Faltys M, Chernoff D. Harnessing the inflammatory reflex for the treatment of inflammation-mediated Diseases. Cold Spring Harb Perspect Med. 2020;10(1): a034330.
doi: 10.1101/cshperspect.a034330 pubmed: 30833463 pmcid: 6938662
LivaNova Inc. VNS Therapy Physician’s Manual. Volume 26–0009–7600/6 US. LivaNova, Inc.; 2020. https://www.livanova.com/epilepsy-vnstherapy/en-us/hcp/product-manuals . Accessed 25 July 2023.
Milby AH, Halpern CH, Baltuch GH. Vagus nerve stimulation in the treatment of refractory Epilepsy. Neurotherapeutics. 2009. https://doi.org/10.1016/j.nurt.2009.01.010 .
doi: 10.1016/j.nurt.2009.01.010 pubmed: 19332314 pmcid: 5084198
Morris GL 3rd, Mueller WM. Long-term treatment with vagus nerve stimulation in patients with refractory epilepsy. The Vagus Nerve Stimulation Study Group E01–E05. Neurology. 1999;53:1731–5. https://doi.org/10.1212/wnl.53.8.173 .
doi: 10.1212/wnl.53.8.173 pubmed: 10563620
O’Reardon JP, Cristancho P, Peshek AD. Vagus nerve stimulation (VNS) and treatment of depression: to the brainstem and beyond. Psychiatry (Edgmont). 2006;3:54–63.
pubmed: 21103178
Panebianco M, Zavanone C, Dupont S, Restivo DA, Pavone A. Vagus nerve stimulation therapy in partial Epilepsy: a review. Acta Neurol Belgica. 2016;116:241–8. https://doi.org/10.1007/s13760-016-0616-3 .
doi: 10.1007/s13760-016-0616-3
Pavlov VA, Chavan SS, Tracey KJ. Molecular and functional neuroscience in immunity. Annu Rev Immunol. 2018;36:783–812. https://doi.org/10.1146/annurev-immunol-042617-053158 .
doi: 10.1146/annurev-immunol-042617-053158 pubmed: 29677475 pmcid: 6057146
Penry JK, Dean JC. Prevention of intractable partial seizures by intermittent vagal stimulation in humans: preliminary results. Epilepsia. 1990;31(Suppl 2):40–3. https://doi.org/10.1111/j.1528-1157.1990.tb05848.x .
doi: 10.1111/j.1528-1157.1990.tb05848.x
Radawski C, Genovese MC, Hauber B, Nowell WB, Hollis K, Gaich CL, et al. Patient perceptions of unmet medical need in rheumatoid arthritis: a cross-sectional survey in the USA. Rheumatol Therapy. 2019;6:461–71. https://doi.org/10.1007/s40744-019-00168-5 .
doi: 10.1007/s40744-019-00168-5
Rush AJ, Marangell LB, Sackeim HA, George MS, Brannan SK, Davis SM, et al. Vagus nerve stimulation for treatment-resistant depression: a randomized, controlled acute phase trial. Biol Psychiat. 2005a;58(5):347–345. https://doi.org/10.1016/j.biopsych.2005.05.025 .
doi: 10.1016/j.biopsych.2005.05.025 pubmed: 16139580
Rush AJ, Sackeim HA, Marangell LB, George MS, Brannan SK, Davis SM, et al. Effects of 12 months of vagus nerve stimulation in treatment-resistant depression: a naturalistic study. Biol Psychiatry. 2005b;58:355–63. https://doi.org/10.1016/j.biopsych.2005.05.024 .
doi: 10.1016/j.biopsych.2005.05.024 pubmed: 16139581
Schett G, Gravallese E. Bone erosion in rheumatoid arthritis: mechanisms, diagnosis, and treatment. Nat Rev Rheumatol. 2012;8:656. https://doi.org/10.1038/nrrheum.2012.153 .
doi: 10.1038/nrrheum.2012.153 pubmed: 23007741 pmcid: 4096779
Smolen JS. Rheumatoid arthritis primer—behind the scenes. Nat Reviews Disease Primers. 2020;6(1):32. https://doi.org/10.1038/s41572-020-0168-y .
doi: 10.1038/s41572-020-0168-y
Smolen JS, Aletaha D, McInnes IB. Rheumatoid arthritis. Lancet. 2016;388:2023–38. https://doi.org/10.1016/S0140-6736(16)30173-8 .
doi: 10.1016/S0140-6736(16)30173-8 pubmed: 27156434
Strand V, Tundia N, Song Y, Macaulay D, Fuldeore M. Economic burden of patients with inadequate response to targeted immunomodulators for rheumatoid arthritis. J Manag Care Spec Pharm. 2018;24(4):344–52. https://doi.org/10.18553/jmcp.2018.24.4.344 .
doi: 10.18553/jmcp.2018.24.4.344 pubmed: 29578852
The Vagus Nerve Stimulation Study Group. A randomized controlled trial of chronic vagus nerve stimulation for treatment of medically intractable seizures. Neurology. 1995;45:224–30. https://doi.org/10.1212/wnl.45.2.224 .
doi: 10.1212/wnl.45.2.224
Tracey KJ. The inflammatory reflex. Nature. 2002;420:853–9. https://doi.org/10.1038/nature01321 .
Tracey KJ. Reflex control of immunity. Nat Rev Immunol. 2009;9(6):418–28. https://doi.org/10.1038/nri2566 .
doi: 10.1038/nri2566 pubmed: 19461672 pmcid: 4535331
US Food and Drug Administration FDA Requires Warnings about Increased Risk of Serious Heart-Related Events., Cancer, Blood Clots, and Death for JAK Inhibitors that Treat Certain Chronic Inflammatory Conditions. 2021 Available online: https://www.fda.gov/drugs/drug-safety-and-availability/fda-requires-warnings-about-increased-risk-serious-heart-related-events-cancer-blood-clots-and-death . Accessed 24 Aug 2023.
Waimann CA, Marengo MF, De Achaval S, Cox VL, Garcia-Gonzalez A, Reveille JD, et al. Electronic monitoring of oral therapies in ethnically diverse and economically disadvantaged patients with rheumatoid arthritis: consequences of low adherence. Arthr Rhuem. 2013;65(6):1421–9. https://doi.org/10.1002/art.37917 .
doi: 10.1002/art.37917
Winthrop KL, Weinblatt ME, Bathon J, Burmester GR, Mease PJ, Crofford L, et al. Unmet need in rheumatology: reports from the targeted therapies meeting. Ann Rheum Dis. 2020;79(1):88–93. https://doi.org/10.1136/annrheumdis-2019-216151 .
doi: 10.1136/annrheumdis-2019-216151 pubmed: 31662322

Auteurs

Daniel Peterson (D)

Neurosurgery, Austin Neurosurgeons (Arise Medical Center), Austin, TX, USA.

Mark Van Poppel (M)

Neurosurgery, Carolina Neurosurgery & Spine Associates, Charlotte, NC, USA.

Warren Boling (W)

Neurosurgery, Loma Linda University Health, Loma Linda, CA, USA.

Perry Santos (P)

Integris Health Baptist Medical Center, Head and Neck Surgery, Oklahoma City, OK, USA.

Jason Schwalb (J)

Neurosurgery, Henry Ford Medical Group, Detroit, MI, USA.

Howard Eisenberg (H)

Neurosurgery, University of Maryland Medical Center, Baltimore, MD, USA.

Ashesh Mehta (A)

The Feinstein Institutes for Medical Research, Neurosurgery, Donald and Barbara Zucker School of Medicine at Hofstra/Northwell, Manhasset, NY, USA.

Heather Spader (H)

Neurosurgery, University of Virginia, Charlottesville, VA, USA.

James Botros (J)

Neurosurgery, University of New Mexico, Albuquerque, NM, USA.

Frank D Vrionis (FD)

Neurosurgery, Marcus Neuroscience Institute, Boca Raton, FL, USA.

Andrew Ko (A)

Neurosurgery, University of Washington, Seattle, WA, USA.

P David Adelson (PD)

Neurosurgery, Phoenix Children's Hospital, Phoenix, AZ, USA.
Rockefeller Neuroscience Institute, Neurosurgery, West Virginia University Medicine, Morgantown, WV, USA.

Bradley Lega (B)

Neurological Surgery, The University of Texas Southwestern Medical Center, Dallas, TX, USA.

Peter Konrad (P)

Rockefeller Neuroscience Institute, Neurosurgery, West Virginia University Medicine, Morgantown, WV, USA.

Guillermo Calle (G)

Product Development, SetPoint Medical, Valencia, CA, USA.

Fernando L Vale (FL)

Medical College of Georgia at Augusta University, Augusta, GA, USA.

Richard Bucholz (R)

Division of Neurological Surgery, St. Louis University, St. Louis, MO, USA.

R Mark Richardson (RM)

Neurosurgery, Massachusetts General Hospital, Boston, MA, USA. Mark.Richardson@MGH.HARVARD.EDU.

Classifications MeSH