Oncocytic papillary cystadenoma of the larynx: a case report.

Ectopic minor salivary glands Minor salivary gland tumors Minor salivary glands Warthin’s tumor

Journal

Journal of medical case reports
ISSN: 1752-1947
Titre abrégé: J Med Case Rep
Pays: England
ID NLM: 101293382

Informations de publication

Date de publication:
20 Mar 2024
Historique:
received: 20 01 2024
accepted: 30 01 2024
medline: 20 3 2024
pubmed: 20 3 2024
entrez: 20 3 2024
Statut: epublish

Résumé

Cystadenoma of the salivary glands is a rare benign clinical condition affecting both major and minor salivary glands equally. It constitutes approximately 2% of total neoplasms and 4.2-4.7% of benign formations in minor salivary glands. Typically presenting as a slow-growing, painless neoplasm, it can be distinguished from Cystadenolymphoma (Whartin's Tumor) by the absence of lymphoid elements in histological examination. While mostly located in the oral cavity and oropharynx, it can also be found in sinonasal mucosa, and rare cases have been identified in the larynx. A 75-year-old Caucasian woman presented to the ear, nose, and throat department with complaints of dysphonia and headaches persisting for several months. Dysphonia had developed months after an unspecified vocal cord surgery elsewhere. Flexible laryngoscopy identified a left-sided cystic swelling affecting the supraglottic space, leading to respiratory obstruction and dysphonia. Head and neck computed tomography confirmed a 1.9 × 1.7 cm bilobed cystic mass originating from the left Morgagni ventricle. Microlaryngoscopy with CO Ectopic minor salivary gland tumors, both benign and malignant, should be taken into consideration as potential differential diagnosis for any swelling arising within the upper digestive tract mucosa. Ears, nose, and throat clinical examination completed by videolaryngoscopy can easily point out the location of the mass. Imaging is mandatory for differential diagnosis and for surgical planning. Surgical excision can provide both diagnosis and definitive cure.

Sections du résumé

BACKGROUND BACKGROUND
Cystadenoma of the salivary glands is a rare benign clinical condition affecting both major and minor salivary glands equally. It constitutes approximately 2% of total neoplasms and 4.2-4.7% of benign formations in minor salivary glands. Typically presenting as a slow-growing, painless neoplasm, it can be distinguished from Cystadenolymphoma (Whartin's Tumor) by the absence of lymphoid elements in histological examination. While mostly located in the oral cavity and oropharynx, it can also be found in sinonasal mucosa, and rare cases have been identified in the larynx.
CASE PRESENTATION METHODS
A 75-year-old Caucasian woman presented to the ear, nose, and throat department with complaints of dysphonia and headaches persisting for several months. Dysphonia had developed months after an unspecified vocal cord surgery elsewhere. Flexible laryngoscopy identified a left-sided cystic swelling affecting the supraglottic space, leading to respiratory obstruction and dysphonia. Head and neck computed tomography confirmed a 1.9 × 1.7 cm bilobed cystic mass originating from the left Morgagni ventricle. Microlaryngoscopy with CO
CONCLUSION CONCLUSIONS
Ectopic minor salivary gland tumors, both benign and malignant, should be taken into consideration as potential differential diagnosis for any swelling arising within the upper digestive tract mucosa. Ears, nose, and throat clinical examination completed by videolaryngoscopy can easily point out the location of the mass. Imaging is mandatory for differential diagnosis and for surgical planning. Surgical excision can provide both diagnosis and definitive cure.

Identifiants

pubmed: 38504337
doi: 10.1186/s13256-024-04425-2
pii: 10.1186/s13256-024-04425-2
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

172

Informations de copyright

© 2024. The Author(s).

Références

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Auteurs

Alberto Caranti (A)

ENT & Audiology Department, University Hospital of Ferrara, Via Aldo Moro 8, 44124, Cona, FE, Italy. dott.albertocaranti@gmail.com.
Gruppo Otorinolaringologico Della Romagna, Primus Medical Center of Forlì, Via Punta di Ferro 2/C, 47122, Forlì, FC, Italy. dott.albertocaranti@gmail.com.

Roberto Spasiano (R)

ENT Department, Ospedale Regionale Di Lugano, Ente Ospedaliero Cantonale EOC, Via Tesserete 46, 6900, Lugano, Tissin, Switzerland. roberto.spasiano@eoc.ch.
USI - University of Italian Switzerland, Via Giuseppe Buffi 13, 6900, Lugano, Switzerland. roberto.spasiano@eoc.ch.

Renato Piantanida (R)

ENT Department, Ospedale Regionale Di Lugano, Ente Ospedaliero Cantonale EOC, Via Tesserete 46, 6900, Lugano, Tissin, Switzerland.

Salvatore Catalano (S)

ENT Department, Ospedale Regionale Di Lugano, Ente Ospedaliero Cantonale EOC, Via Tesserete 46, 6900, Lugano, Tissin, Switzerland.

Ruggero Campisi (R)

ENT & Audiology Department, University Hospital of Ferrara, Via Aldo Moro 8, 44124, Cona, FE, Italy.
Gruppo Otorinolaringologico Della Romagna, Primus Medical Center of Forlì, Via Punta di Ferro 2/C, 47122, Forlì, FC, Italy.

Manuela Bergmann (M)

Institute of Pathology, Ente Ospedaliero Cantonale (EOC), Locarno, Switzerland.

Matteo Trimarchi (M)

ENT Department, Ospedale Regionale Di Lugano, Ente Ospedaliero Cantonale EOC, Via Tesserete 46, 6900, Lugano, Tissin, Switzerland.
USI - University of Italian Switzerland, Via Giuseppe Buffi 13, 6900, Lugano, Switzerland.

Classifications MeSH