Autosomal Recessive Non-Syndromic Deafness: Is AAV Gene Therapy a Real Chance?

DFNB adeno-associated virus (AAV) gene therapies hearing restoration recessive mutations sensorineural hearing loss

Journal

Audiology research
ISSN: 2039-4330
Titre abrégé: Audiol Res
Pays: Switzerland
ID NLM: 101644681

Informations de publication

Date de publication:
22 Feb 2024
Historique:
received: 17 11 2023
revised: 01 02 2024
accepted: 15 02 2024
medline: 25 3 2024
pubmed: 25 3 2024
entrez: 25 3 2024
Statut: epublish

Résumé

The etiology of sensorineural hearing loss is heavily influenced by genetic mutations, with approximately 80% of cases attributed to genetic causes and only 20% to environmental factors. Over 100 non-syndromic deafness genes have been identified in humans thus far. In non-syndromic sensorineural hearing impairment, around 75-85% of cases follow an autosomal recessive inheritance pattern. In recent years, groundbreaking advancements in molecular gene therapy for inner-ear disorders have shown promising results. Experimental studies have demonstrated improvements in hearing following a single local injection of adeno-associated virus-derived vectors carrying an additional normal gene or using ribozymes to modify the genome. These pioneering approaches have opened new possibilities for potential therapeutic interventions. Following the PRISMA criteria, we summarized the AAV gene therapy experiments showing hearing improvement in the preclinical phases of development in different animal models of DFNB deafness and the AAV gene therapy programs currently in clinical phases targeting autosomal recessive non syndromic hearing loss. A total of 17 preclinical studies and 3 clinical studies were found and listed. Despite the hurdles, there have been significant breakthroughs in the path of HL gene therapy, holding great potential for providing patients with novel and effective treatment.

Identifiants

pubmed: 38525683
pii: audiolres14020022
doi: 10.3390/audiolres14020022
doi:

Types de publication

Journal Article Review

Langues

eng

Pagination

239-253

Auteurs

Davide Brotto (D)

Department of Neuroscience DNS, Otolaryngology Section, Padova University, 35128 Padova, Italy.
Otolaryngology Unit, Azienda Ospedale Università Padova, 35128 Padova, Italy.

Marco Greggio (M)

Department of Neuroscience DNS, Otolaryngology Section, Padova University, 35128 Padova, Italy.
Otolaryngology Unit, Azienda Ospedale Università Padova, 35128 Padova, Italy.

Cosimo De Filippis (C)

Department of Neuroscience DNS, Otolaryngology Section, Padova University, 35128 Padova, Italy.

Patrizia Trevisi (P)

Department of Neuroscience DNS, Otolaryngology Section, Padova University, 35128 Padova, Italy.
Otolaryngology Unit, Azienda Ospedale Università Padova, 35128 Padova, Italy.

Classifications MeSH