Evaluation of an Updated Gene Panel as a Diagnostic Tool for Both Male and Female Infertility.

Female infertility Gene panel Male infertility Reproductive genetics

Journal

Reproductive sciences (Thousand Oaks, Calif.)
ISSN: 1933-7205
Titre abrégé: Reprod Sci
Pays: United States
ID NLM: 101291249

Informations de publication

Date de publication:
25 Apr 2024
Historique:
received: 08 01 2024
accepted: 02 04 2024
medline: 26 4 2024
pubmed: 26 4 2024
entrez: 25 4 2024
Statut: aheadofprint

Résumé

In recent years, an increasing number of genes associated with male and female infertility have been identified. The genetics of infertility is no longer limited to the analysis of karyotypes or specific genes, and it is now possible to analyse several dozen infertility genes simultaneously. Here, we present the diagnostic activity over the past two years including 140 patients (63 women and 77 men). Targeted sequencing revealed causative variants in 17 patients, representing an overall diagnostic rate of 12.1%, with prevalence rates in females and males of 11% and 13%, respectively. The gene-disease relationship (GDR) was re-evaluated for genes due to the addition of new patients and/or variants in the actual study. Five genes changed categories: two female genes (MEIOB and TBPL2) moved from limited to moderate; two male genes (SOHLH1 and GALNTL5) moved from no evidence to strong and from limited to moderate; and SEPTIN12, which was unable to classify male infertility, was reclassified as limited. Many infertility genes have yet to be identified. With the increasing integration of genetics in reproductive medicine, the scope of intervention extends to include other family members, in addition to individual patients or couples. Genetic counselling consultations and appropriate staffing will need to be established in fertility centres. Trial registration number: Not applicable.

Identifiants

pubmed: 38664359
doi: 10.1007/s43032-024-01553-4
pii: 10.1007/s43032-024-01553-4
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2024. The Author(s), under exclusive licence to Society for Reproductive Investigation.

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Auteurs

Özlem Okutman (Ö)

Service de Gynécologie-Obstetrique, Clinique de Fertilité, Université Libre de Bruxelles (ULB), Hôpital Universitaire de Bruxelles (H.U.B), Hôpital Erasme, Route de Lennik, 808, 1070, Brussels, Belgium. ozlem.okutman@hubruxelles.be.

Ali Sami Gürbüz (AS)

Novafertil IVF Center, 27060, Konya, Turkey.

Ahmet Salvarci (A)

Novafertil IVF Center, 27060, Konya, Turkey.

Umut Büyük (U)

Department of Molecular Biology and Genetics, Institute of Graduate Studies in Sciences, Istanbul University, Istanbul, Turkey.

Halil Ruso (H)

Gürgan Clinic Women's Health and IVF Centre, Ankara, Turkey.
Faculty of Medicine, Department of Histology and Embryology, Gazi University, Ankara, Turkey.

Timur Gürgan (T)

Gürgan Clinic Women's Health and IVF Centre, Ankara, Turkey.
Department of Obstetrics and Gynecology, Bahçeşehir University School of Medicine, Istanbul, Turkey.

Julien Tarabeux (J)

Laboratoires de Diagnostic Génétique, IGMA, Hôpitaux Universitaires de Strasbourg, Strasbourg, France.

Anne-Sophie Leuvrey (AS)

Laboratoires de Diagnostic Génétique, IGMA, Hôpitaux Universitaires de Strasbourg, Strasbourg, France.

Elsa Nourisson (E)

Laboratoires de Diagnostic Génétique, IGMA, Hôpitaux Universitaires de Strasbourg, Strasbourg, France.

Cécile Lang (C)

Laboratoire de Diagnostic Génétique, Unité de Génétique de L'infertilité (UF3472), Hôpitaux Universitaires de Strasbourg, Strasbourg, France.

Jean Muller (J)

Laboratoires de Diagnostic Génétique, IGMA, Hôpitaux Universitaires de Strasbourg, Strasbourg, France.
Laboratoire de Génétique Médicale LGM, Institut de Génétique Médicale d'Alsace (IGMA), Université de Strasbourg, INSERM UMR 1112, Strasbourg, France.
Unité Fonctionnelle de Bioinformatique Médicale Appliquée Au Diagnostic (UF7363), Hôpitaux Universitaires de Strasbourg, Strasbourg, France.

Stephane Viville (S)

Laboratoire de Diagnostic Génétique, Unité de Génétique de L'infertilité (UF3472), Hôpitaux Universitaires de Strasbourg, Strasbourg, France.
Laboratoire de Génétique Médicale LGM, Institut de Génétique Médicale d'Alsace (IGMA), Université de Strasbourg, INSERM UMR 1112, Strasbourg, France.

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