Unusually severe neonatal presentation of mediastinal bronchogenic cyst.

bronchogenic cysts mediastinal mass neonate pulmonary emphysema respiratory distress

Journal

Pediatric pulmonology
ISSN: 1099-0496
Titre abrégé: Pediatr Pulmonol
Pays: United States
ID NLM: 8510590

Informations de publication

Date de publication:
14 May 2024
Historique:
revised: 11 04 2024
received: 02 11 2023
accepted: 28 04 2024
medline: 14 5 2024
pubmed: 14 5 2024
entrez: 14 5 2024
Statut: aheadofprint

Résumé

Bronchogenic cysts are rare congenital malformations that occur in adults and children, with differences in distribution and presentation. We present the case of a newborn who initiated respiratory distress from the first minutes of life, presenting with hypoventilation and rightward displacement of the cardiac impulse, requiring oxygen therapy and intubation. The first radiograph shows a left pulmonary emphysema. The computerized axial tomography revealed a large mediastinal mass causing an obstructive syndrome of the left bronchus. The mass was successfully excised, resulting in a favorable clinical evolution. Although the presentation of our case is exceptional, it is worth noting that while most bronchogenic cysts are asymptomatic, they can occur in childhood, even from birth, as in our case.

Identifiants

pubmed: 38742252
doi: 10.1002/ppul.27048
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : None

Informations de copyright

© 2024 Wiley Periodicals LLC.

Références

Arun S, Kumar M, Ross BJ. Mediastinal bronchogenic cyst mimicking congenital lobar emphysema. BMJ Case Rep. 2016;2016:bcr2016216704. https://pubmed.ncbi.nlm.nih.gov/27609589/
Chatterjee D, Hawkins JL, Somme S, Galan HL, Prager JD, Crombleholme TM. Ex utero intrapartum treatment to resection of a bronchogenic cyst causing airway compression. Fetal Diagn Ther. 2014;35(2):137‐140. https://pubmed.ncbi.nlm.nih.gov/24281263/
Jiang JH, Yen SL, Lee SY, Chuang JH. Differences in the distribution and presentation of bronchogenic cysts between adults and children. J Pediatr Surg. 2015;50(3):399‐401. https://pubmed.ncbi.nlm.nih.gov/25746696/
Busino RS, Quraishi HA, Cohen IT. Stridor secondary to a bronchogenic cyst in a neonate. Ear Nose Throat J. 2011;90(11):8‐10.
Khemiri M, Ouederni M, Mansour F Ben, Barsaoui S. Bronchogenic cyst: an uncommon cause of congenital lobar emphysema. Respir Med. 2008;102(11):1663‐1666.

Auteurs

Francisco Sanchez-Ferrer (F)

Facultad de Medicina Universidad Miguel Hernández de Elche, Sant Joan d'Alacant, España.
Hospital Universitario de San Juan de Alicante, FISABIO, Alicante, España.

Ana Pilar Nso-Roca (AP)

Facultad de Medicina Universidad Miguel Hernández de Elche, Sant Joan d'Alacant, España.
Hospital Universitario de San Juan de Alicante, FISABIO, Alicante, España.

Classifications MeSH