Generation of a new mouse model for Usher syndrome crossing Kunming mice with CBA/J mice.

Adgrv1 Auditory brainstem response Electroretinogram Inbred strain Mutation Usher Syndrome

Journal

Gene
ISSN: 1879-0038
Titre abrégé: Gene
Pays: Netherlands
ID NLM: 7706761

Informations de publication

Date de publication:
14 May 2024
Historique:
received: 15 11 2023
revised: 06 04 2024
accepted: 13 05 2024
medline: 17 5 2024
pubmed: 17 5 2024
entrez: 16 5 2024
Statut: aheadofprint

Résumé

Previously, we discovered a strain of Kunming mice, referred to as the KM ERG readings, ABR testing, fundus morphology, histological examination of the retina and inner ear, reverse transcription-quantitative polymerase chain reaction (RT-qPCR) analysis, western blotting, DNA sequence analysis and behavioural experiments were performed to assess the phenotypes and genotypes of the progeny lines. No obvious waveforms in the ERG were detected in F1 hybrid mice while normal ABR results were recorded. The F2 hybrids, which were called J1 We successfully introduced the hearing-loss phenotype of inbred mice with USH into CBA/J mice, which provides a good animal model for future studies on the important physiological roles of the Adgrv1 gene in inner-ear structure and for therapeutic studies targeting Adgrv1-mutated USH.

Sections du résumé

BACKGROUND BACKGROUND
Previously, we discovered a strain of Kunming mice, referred to as the KM
METHODS METHODS
ERG readings, ABR testing, fundus morphology, histological examination of the retina and inner ear, reverse transcription-quantitative polymerase chain reaction (RT-qPCR) analysis, western blotting, DNA sequence analysis and behavioural experiments were performed to assess the phenotypes and genotypes of the progeny lines.
RESULTS RESULTS
No obvious waveforms in the ERG were detected in F1 hybrid mice while normal ABR results were recorded. The F2 hybrids, which were called J1
CONCLUSIONS CONCLUSIONS
We successfully introduced the hearing-loss phenotype of inbred mice with USH into CBA/J mice, which provides a good animal model for future studies on the important physiological roles of the Adgrv1 gene in inner-ear structure and for therapeutic studies targeting Adgrv1-mutated USH.

Identifiants

pubmed: 38754567
pii: S0378-1119(24)00443-8
doi: 10.1016/j.gene.2024.148562
pii:
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

148562

Informations de copyright

Copyright © 2024 Elsevier B.V. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of competing interest The authors declare that they have no known competing financial interests or personal relationships that could have appeared to influence the work reported in this paper.

Auteurs

Shaoheng Li (S)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China; Department of Ophthalmology, Eye Institute of Chinese PLA, Xijing Hospital, Fourth Military Medical University, Xi'an 710032, China.

Yihong Jiang (Y)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China.

Lei Zhang (L)

Shaanxi Eye Hospital, Xi'an People's Hospital (Xi'an Fourth Hospital), Xi'an 710004, Shaanxi Province, China.

Weiming Yan (W)

The 900th Hospital of Joint Logistic Support Force, PLA, Fuzhou, China. Electronic address: ywming@fjmu.edu.cn.

Dongyu Wei (D)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China.

Min Zhang (M)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China. Electronic address: zhangmin2015@fmmu.edu.cn.

Bin Zhu (B)

Outpatient Department, General Hospital of Xizang Military Region, Lhasa 850007, China. Electronic address: antony-2004@163.com.

Tao Chen (T)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China; Department of Aviation Medicine, Xijing Hospital, Air Force Medical University, Xi'an, China. Electronic address: ct1988@fmmu.edu.cn.

Xiaocheng Wang (X)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China; Department of Aviation Medicine, Xijing Hospital, Air Force Medical University, Xi'an, China. Electronic address: wxcnose@126.com.

Zuoming Zhang (Z)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China. Electronic address: zhangzm@fmmu.edu.cn.

Yuting Su (Y)

Center of Clinical Aerospace Medicine, School of Aerospace Medicine, Air Force Medical University, Xi'an, China; Department of Aviation Medicine, Xijing Hospital, Air Force Medical University, Xi'an, China. Electronic address: sssusyt@163.com.

Classifications MeSH