Congenital Infiltrating Lipomatosis of Face-Induced Temporomandibular Joint Ankylosis.


Journal

The Journal of craniofacial surgery
ISSN: 1536-3732
Titre abrégé: J Craniofac Surg
Pays: United States
ID NLM: 9010410

Informations de publication

Date de publication:
03 Jun 2024
Historique:
received: 20 02 2024
accepted: 04 05 2024
medline: 3 6 2024
pubmed: 3 6 2024
entrez: 3 6 2024
Statut: aheadofprint

Résumé

Temporomandibular joint ankylosis (TMJA) secondary to congenital infiltrating lipomatosis of the face (CILF) is an exceptionally uncommon condition which is characterized by the involvement of unilateral facial soft tissues and bones. In some cases, the extensive exophytic bony growth in the temporomandibular joint region often extends toward the skull base and lies near adjacent vital structures. Only very few cases of TMJA associated with CILF have been reported in the literature. The authors report a case of a 36-year-old female with right TMJA secondary to CILF. The bony overgrowth in the right temporomandibular joint region was arising from a deformed right mandibular condyle, extending towards the ipsilateral temporal bone, greater wing of the sphenoid, skull base, and approaching the lateral limit of foramen ovale, and foramen spinosum. To prevent any damage to the skull base and adjacent vital structures and to achieve adequate mouth opening, the authors have performed a unique technique of subankylotic osteotomy for the release of TMJA, instead of conventional gap arthroplasty.

Identifiants

pubmed: 38830084
doi: 10.1097/SCS.0000000000010355
pii: 00001665-990000000-01672
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2024 by Mutaz B. Habal, MD.

Déclaration de conflit d'intérêts

The authors report no conflicts of interest.

Références

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Auteurs

Vidya Rattan (V)

Department of Oral and Maxillofacial Surgery, Oral Health Sciences Centre Post Graduate Institute of Medical Education and Research, Chandigarh, India.

Classifications MeSH