Unusual orbital, scleral and choroidal findings in Erdheim-Chester disease: a case report.
Erdheim-Chester disease
choroid
histiocytosis
orbit
scleral infiltration
Journal
Orbit (Amsterdam, Netherlands)
ISSN: 1744-5108
Titre abrégé: Orbit
Pays: England
ID NLM: 8301221
Informations de publication
Date de publication:
08 Jul 2024
08 Jul 2024
Historique:
medline:
8
7
2024
pubmed:
8
7
2024
entrez:
8
7
2024
Statut:
aheadofprint
Résumé
This case report highlights a unique presentation of Erdheim-Chester Disease (ECD) with bilateral scleral lesions, choroidal infiltration, and extensive sinus involvement. It is the first case report where the diagnosis was confirmed through a scleral biopsy after an initial presentation of a unilateral nodular scleritis. There was a gradual disease progression and ocular examination later revealed bilateral subconjunctival hyperemic lesions and mild exophthalmos, ophthalmoplegia, and extensive choroidal infiltration. Infiltration of the frontal and maxillary sinus was present and extended into the nasal cavity and both orbits. The diagnostic work-up is described in detail. Current treatment options are analyzed. It is emphasized that the ophthalmologist can play a crucial role in the diagnosis of ECD, given the substantial prevalence of orbital and ocular symptoms. The overall prognosis for ECD remains unfavorable, particularly in cases with orbital involvement. This case underscores the complexity and importance of a multidisciplinary approach in managing ECD.
Identifiants
pubmed: 38976616
doi: 10.1080/01676830.2024.2373791
doi:
Types de publication
Journal Article
Langues
eng
Sous-ensembles de citation
IM