Assessment of urinary 6-oxo-pipecolic acid as a biomarker for ALDH7A1 deficiency.

6‐oxo‐pipecolic acid ALDH7A1 deficiency aminoadipic semialdehyde piperideine‐6‐carboxylate pyridoxine‐dependent epilepsy

Journal

Journal of inherited metabolic disease
ISSN: 1573-2665
Titre abrégé: J Inherit Metab Dis
Pays: United States
ID NLM: 7910918

Informations de publication

Date de publication:
22 Jul 2024
Historique:
revised: 20 06 2024
received: 20 03 2024
accepted: 08 07 2024
medline: 23 7 2024
pubmed: 23 7 2024
entrez: 22 7 2024
Statut: aheadofprint

Résumé

ALDH7A1 deficiency is an epileptic encephalopathy whose seizures respond to treatment with supraphysiological doses of pyridoxine. It arises as a result of damaging variants in ALDH7A1, a gene in the lysine catabolism pathway. α-Aminoadipic semialdehyde (α-AASA) and Δ

Identifiants

pubmed: 39038845
doi: 10.1002/jimd.12783
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Ministry of Health of the Czech Republic
ID : AZV NU23-07-00383
Organisme : Ministry of Health of the Czech Republic
ID : RVO-VFN64165
Organisme : Charles University
Organisme : Eunice Kennedy Shriver National Institute of Child Health & Human Development
ID : R21HD104952

Informations de copyright

© 2024 The Author(s). Journal of Inherited Metabolic Disease published by John Wiley & Sons Ltd on behalf of SSIEM.

Références

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Auteurs

Youssef Khalil (Y)

Genetics and Genomic Medicine, University College London Great Ormond Street Institute of Child Health, London, UK.

Emma Footitt (E)

Department of Metabolic Paediatrics, Great Ormond Street Hospital, London, UK.

Reddy Vootukuri (R)

Genetics and Genomic Medicine, University College London Great Ormond Street Institute of Child Health, London, UK.

Michael F Wempe (MF)

School of Pharmacy, Department of Pharmaceutical Sciences, University of Colorado, Aurora, Colorado, USA.

Curtis R Coughlin (CR)

Department of Pediatrics, Section of Clinical Genetics and Metabolism, University of Colorado School of Medicine, Aurora, Colorado, USA.

Spyros Batzios (S)

Department of Metabolic Paediatrics, Great Ormond Street Hospital, London, UK.

Matthew P Wilson (MP)

Genetics and Genomic Medicine, University College London Great Ormond Street Institute of Child Health, London, UK.
Laboratory for Molecular Diagnosis, Center for Human Genetics, KU Leuven, Leuven, Belgium.

Viktor Kožich (V)

Department of Pediatrics and Inherited Metabolic Disorders, Charles University-First Faculty of Medicine and General University Hospital in Prague, Prague, Czech Republic.

Peter T Clayton (PT)

Genetics and Genomic Medicine, University College London Great Ormond Street Institute of Child Health, London, UK.

Philippa B Mills (PB)

Genetics and Genomic Medicine, University College London Great Ormond Street Institute of Child Health, London, UK.

Classifications MeSH