Investigation of a novel PROS1 splicing variant in a patient with protein S deficiency.


Journal

Human genome variation
ISSN: 2054-345X
Titre abrégé: Hum Genome Var
Pays: England
ID NLM: 101652445

Informations de publication

Date de publication:
26 Jul 2024
Historique:
received: 11 11 2023
accepted: 29 06 2024
revised: 14 05 2024
medline: 27 7 2024
pubmed: 27 7 2024
entrez: 26 7 2024
Statut: epublish

Résumé

Here, we report a novel PROS1 splicing mutation in a patient with type I protein S deficiency. Qualitative and quantitative analysis of pathogenic splicing variants at the mRNA level was performed by long-range PCR-based targeted DNA and RNA sequencing. A base substitution in the exon 4 splicing donor site activates a potential splicing donor site in intron 4, resulting in an in-frame insertion of 48 bases (16 amino acids).

Identifiants

pubmed: 39060248
doi: 10.1038/s41439-024-00286-9
pii: 10.1038/s41439-024-00286-9
doi:

Types de publication

Journal Article

Langues

eng

Pagination

28

Subventions

Organisme : Kanazawa Medical University
ID : 11181
Organisme : Kanazawa Medical University
ID : 26699

Informations de copyright

© 2024. The Author(s).

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Auteurs

Yo Niida (Y)

Center for Clinical Genomics, Kanazawa Medical University Hospital, Ishikawa, Uchinada, Japan. niida@kanazawa-med.ac.jp.
Division of Genomic Medicine, Department of Advanced Medicine, Medical Research Institute, Kanazawa Medical University, Ishikawa, Uchinada, Japan. niida@kanazawa-med.ac.jp.

Wataru Fujita (W)

Department of Cardiology, Kanazawa Medical University, Ishikawa, Uchinada, Japan.

Sumihito Togi (S)

Center for Clinical Genomics, Kanazawa Medical University Hospital, Ishikawa, Uchinada, Japan.
Division of Genomic Medicine, Department of Advanced Medicine, Medical Research Institute, Kanazawa Medical University, Ishikawa, Uchinada, Japan.

Hiroki Ura (H)

Center for Clinical Genomics, Kanazawa Medical University Hospital, Ishikawa, Uchinada, Japan.
Division of Genomic Medicine, Department of Advanced Medicine, Medical Research Institute, Kanazawa Medical University, Ishikawa, Uchinada, Japan.

Classifications MeSH