Temporal implementation of a regional referral pathway in transthyretin cardiac amyloidosis: Emilia-Romagna experience.


Journal

Journal of cardiovascular medicine (Hagerstown, Md.)
ISSN: 1558-2035
Titre abrégé: J Cardiovasc Med (Hagerstown)
Pays: United States
ID NLM: 101259752

Informations de publication

Date de publication:
23 Jul 2024
Historique:
medline: 31 7 2024
pubmed: 31 7 2024
entrez: 31 7 2024
Statut: aheadofprint

Résumé

Transthyretin cardiac amyloidosis (ATTR-CA) is a rare and progressive cardiomyopathy caused by amyloid fibril deposition in myocardial tissue. Diagnostic challenges have historically hampered timely detection. Recent advances in noninvasive diagnostic techniques have facilitated ATTR-CA diagnosis. We aimed to examine the development of a regional network for the diagnosis and management of ATTR-CA and describe a cohort of patients with ATTR-CA, investigate diagnostic pathways and assess clinical outcomes according to diagnosis periods. We performed a survey study analyzing answers from 11 cardiology centers and we conducted a retrospective study including patients with ATTR-CA attending a referral center between 1 January 2012 and 31 December 2022, and categorized by the period of diagnosis (2012-2016 and 2017-2022). Over the years, a growing number of patients reached a diagnosis and were treated in the surveyed nonreferral centers of the region. The retrospective study showed a more significant diagnostic delay in the earlier period rather than the later one [13.4 (5-30.2) vs. 10.6 (5.0-17.9) months, P = 0.04]. Patients diagnosed after 2017 showed a greater survival rate than those diagnosed earlier (P = 0.02). In the multivariate analysis, the year of diagnosis from 2017 remained independently associated with mortality [hazard ratio (HR) 0.46, 95% confidence interval (CI) 0.28-0.79; P = 0.005]. This study emphasized the shift toward noninvasive diagnostic criteria. It revealed a positive impact on patient survival and disease management with the use of disease-modifying therapies and diagnostic developments in more recent years. The findings underscore the importance of disease awareness and networking to reduce diagnostic delays and enhance patient journeys for ATTR-CA.

Identifiants

pubmed: 39083075
doi: 10.2459/JCM.0000000000001633
pii: 01244665-990000000-00232
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2024 Italian Federation of Cardiology - I.F.C. All rights reserved.

Références

Gillmore JD, Damy T, Fontana M, et al. A new staging system for cardiac transthyretin amyloidosis. Eur Heart J 2018; 39:2799–2806.
Ioannou A, Patel RK, Razvi Y, et al. Impact of earlier diagnosis in cardiac ATTR amyloidosis over the course of 20 years. Circulation 2022; 146:1657–1670.
Garcia-Pavia P, Rapezzi C, Adler Y, et al. Diagnosis and treatment of cardiac amyloidosis: a position statement of the ESC Working Group on Myocardial and Pericardial Diseases. Eur Heart J 2021; 42:1554–1568.
Lopez-Sainz A, Hernandez-Hernandez A, Gonzalez-Lopez E, et al. Clinical profile and outcome of cardiac amyloidosis in a Spanish referral center. Rev Esp Cardiol (Engl Ed) 2021; 74:149–158.
Pagura L, Porcari A, Cameli M, et al. ECG/echo indexes in the diagnostic approach to amyloid cardiomyopathy: a head-to-head comparison from the AC-TIVE study. Eur J Intern Med 2023; 122:68–77.
Argiro’ A, Zampieri M, Mazzoni C, et al. Red flags for the diagnosis of cardiac amyloidosis: simple suggestions to raise suspicion and achieve earlier diagnosis. J Cardiovasc Med (Hagerstown) 2022; 23:493–504.
De Marneffe N, Dulgheru R, Ancion A, et al. Cardiac amyloidosis: a review of the literature. Acta Cardiol 2022; 77:683–692.
Merlo M, Pagura L, Porcari A, et al. Unmasking the prevalence of amyloid cardiomyopathy in the real world: results from Phase 2 of the AC-TIVE study, an Italian nationwide survey. Eur J Heart Fail 2022; 24:1377–1386.
Tini G, Milani P, Zampieri M, et al. Diagnostic pathways to wild-type transthyretin amyloid cardiomyopathy: a multicentre network study. Eur J Heart Fail 2023; 25:845–853.
Gillmore JD, Maurer MS, Falk RH, et al. Nonbiopsy diagnosis of cardiac transthyretin amyloidosis. Circulation 2016; 133:2404–2412.
Kitaoka H, Izumi C, Izumiya Y, et al. JCS 2020 guideline on diagnosis and treatment of cardiac amyloidosis. Circ J 2020; 84:1610–1671.
Dorbala S, Ando Y, Bokhari S, et al. ASNC/AHA/ASE/EANM/HFSA/ISA/SCMR/SNMMI expert consensus recommendations for multimodality imaging in cardiac amyloidosis: Part 1 of 2—evidence base and standardized methods of imaging. J Nucl Cardiol 2019; 26:2065–2123.
Maurer MS, Schwartz JH, Gundapaneni B, et al. Tafamidis treatment for patients with transthyretin amyloid cardiomyopathy. N Engl J Med 2018; 379:1007–1016.
Benson MD, Waddington-Cruz M, Berk JL, et al. Inotersen treatment for patients with hereditary transthyretin amyloidosis. N Engl J Med 2018; 379:22–31.
Fontana M, Martinez-Naharro A, Chacko L, et al. Reduction in CMR derived extracellular volume with patisiran indicates cardiac amyloid regression. JACC Cardiovasc Imaging 2021; 14:189–199.
Apostolou EA, Fontrier AM, Efthimiadis GK, et al. The patient pathway in ATTR-CM in Greece and how to improve it: a multidisciplinary perspective. Hellenic J Cardiol 2023; 73:73–80.
Maurer MS, Elliott P, Comenzo R, et al. Addressing common questions encountered in the diagnosis and management of cardiac amyloidosis. Circulation 2017; 135:1357–1377.
Autore C, Bariani R, Bauce B, et al. From the phenotype to precision medicine: an update on the cardiomyopathies diagnostic workflow. J Cardiovasc Med (Hagerstown) 2023; 24:e178–e186.
Rapezzi C, Aimo A, Barison A, et al. Restrictive cardiomyopathy: definition and diagnosis. Eur Heart J 2022; 43:4679–4693.
Arbelo E, Protonotarios A, Gimeno JR, et al. ESC Scientific Document Group. 2023 ESC Guidelines for the management of cardiomyopathies. Eur Heart J 2023; 44:3503–3626.
Todiere G, Barison A, Baritussio A, et al. Working Group on Cardiac Magnetic Resonance of the Italian Society of Cardiology. Acute clinical presentation of nonischemic cardiomyopathies: early detection by cardiovascular magnetic resonance. J Cardiovasc Med (Hagerstown) 2023; 24:e36–e46.
Rauf MU, Hawkins PN, Cappelli F, et al. Tc-99m labelled bone scintigraphy in suspected cardiac amyloidosis. Eur Heart J 2023; 44:2187–2198.
Aimo A, Tomasoni D, Porcari A, et al. Left ventricular wall thickness and severity of cardiac disease in women and men with transthyretin amyloidosis. Eur J Heart Fail 2023; 25:510–514.
Elliott P, Gundapaneni B, Sultan MB, Ines M, Garcia-Pavia P. Improved long-term survival with tafamidis treatment in patients with transthyretin amyloid cardiomyopathy and severe heart failure symptoms. Eur J Heart Fail 2023; 25:2060–2064.
McDonagh TA, Metra M, Adamo M, et al. 2023 Focused Update of the 2021 ESC Guidelines for the diagnosis and treatment of acute and chronic heart failure. Eur Heart J 2023; 44:3627–3639.
Brugada J, Katritsis DG, Arbelo E, et al. 2019 ESC Guidelines for the management of patients with supraventricular tachycardia: the Task Force for the management of patients with supraventricular tachycardia of the European Society of Cardiology (ESC). Eur Heart J 2020; 41:655–720.
Coelho T, Dispenzieri A, Grogan M, et al. Patients with transthyretin amyloidosis enrolled in THAOS between 2018 and 2021 continue to experience substantial diagnostic delay. Amyloid 2023; 30:445–448.
Ilelaboye AI, Vardar U, Baskaran N, Shaka A, DeAngelo S, Shaka H. Effect of coronavirus disease 2019 pandemic on heart failure hospitalization rates and disparities: a National Inpatient Sample study. J Cardiovasc Med (Hagerstown) 2023; 24:689–690.
Moscucci F, Gallina S, Bucciarelli V, et al. Impact of COVID-19 on the cardiovascular health of women: a review by the Italian Society of Cardiology Working Group on ‘gender cardiovascular diseases’. J Cardiovasc Med (Hagerstown) 2023; 24:e15–e23.
Boriani G, Guerra F, De Ponti R, et al. for AIAC Ricerca Network Investigators. Five waves of COVID-19 pandemic in Italy: results of a national survey evaluating the impact on activities related to arrhythmias, pacing, and electrophysiology promoted by AIAC (Italian Association of Arrhythmology and Cardiac Pacing). Intern Emerg Med 2023; 18:137–149.
Bonfioli G, Tomasoni D, Metra M, Adamo M. Coronavirus disease 2019 and cardiovascular disease: what we have learnt during the last 2 years. J Cardiovasc Med (Hagerstown) 2022; 23:710–714.
Palazzuoli A, Carl J, Lavie, et al. Co-management of COVID-19 and heart failure during the COVID-19 pandemic: lessons learned. Rev Cardiovasc Med 2022; 23:218.
Ostrowska M, Kasprzak M, Stolarek W, et al. Longer hospitalizations and higher in-hospital mortality for acute heart failure during the COVID-19 pandemic in larger vs. smaller cardiology departments: subanalysis of the COV-HF-SIRIO 6 multicenter study. Rev Cardiovasc Med 2022; 23:292.

Auteurs

Simone Longhi (S)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
European Reference Network for Rare, Low Prevalence and Complex Diseases of the Heart-ERN GUARD-Heart.

Elena Biagini (E)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
European Reference Network for Rare, Low Prevalence and Complex Diseases of the Heart-ERN GUARD-Heart.

Pietro Guaraldi (P)

IRCCS Istituto delle Scienze Neurologiche di Bologna, Bologna.

Samuela Carigi (S)

Cardiology Unit, Infermi Hospital, AUSL della Romagna.

Marco Currò Dossi (MC)

Department of Neurology, Infermi Hospital, AUSL della Romagna, Rimini.

Michela Bartolotti (M)

Cardiology Unit, Bufalini Hospital, AUSL della Romagna, Cesena.

Elisa Gardini (E)

Cardiology Unit, 'Morgagni - Pierantoni' Hospital, AUSL della Romagna, Forlì.

Elisa Merli (E)

Cardiology Unit, 'Degli Infermi' Hospital, Ausl della Romagna, Faenza.

Francesca Marzo (F)

Cardiology Unit, Infermi Hospital, AUSL della Romagna.

Emanuela Postiglione (E)

Neurology Unit, 'Santa Maria delle Croci' Hospital, Ausl della Romagna, Ravenna.

Matteo Serenelli (M)

Cardiology Unit, Azienda Ospedaliero Universitaria di Ferrara, Ferrara.

Valeria Tugnoli (V)

Department of Neuroscience and Rehabilitation, Azienda Ospedaliero-Universitaria S, Anna, Ferrara.

Riccardo De Gennaro (R)

Department of Neuroscience and Rehabilitation, Azienda Ospedaliero-Universitaria S, Anna, Ferrara.

Angelo Giuseppe Caponetti (AG)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
Department of Experimental, Diagnostic and Specialty Medicine, University of Bologna.

Christian Gagliardi (C)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
European Reference Network for Rare, Low Prevalence and Complex Diseases of the Heart-ERN GUARD-Heart.

Giulia Saturi (G)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
Department of Experimental, Diagnostic and Specialty Medicine, University of Bologna.

Alberto Ponziani (A)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
Department of Experimental, Diagnostic and Specialty Medicine, University of Bologna.

Enrica Perugini (E)

Cardiology Unit, Maggiore Hospital, Bologna.

Rita Rinaldi (R)

IRCCS Istituto delle Scienze Neurologiche di Bologna, Bologna.

Andrea Barbieri (A)

Cardiology Division, Department of Biomedical, Metabolic and Neural Sciences, University of Modena and Reggio Emilia, Policlinico di Modena.

Silvia Bonatti (S)

Cardiology Division, Department of Biomedical, Metabolic and Neural Sciences, University of Modena and Reggio Emilia, Policlinico di Modena.

Alessandra Ariatti (A)

Department of Biomedical, Metabolic Neural Sciences, University of Modena, Modena.

Chiara Leuzzi (C)

Cardiology Unit, IRCCS Arcispedale S. Maria Nuova.

Luca Codeluppi (L)

Neurology Unit, Neuromotor & Rehabilitation Department, Azienda USL-IRCCS di Reggio Emilia, Reggio Emilia.

Walter Serra (W)

Cardiology Division.

Isabella Allegri (I)

Neurology Department, University Hospital of Parma.

Gianluca Lanati (G)

Cardiology Unit, Castel San Giovanni Hospital, Castel S. Giovanni.

Chiara Terracciano (C)

Neurology Unit, 'Guglielmo da Saliceto' Hospital, Piacenza.

Pietro Cortelli (P)

IRCCS Istituto delle Scienze Neurologiche di Bologna, Bologna.
Department of Biomedical and Neuromotor Sciences (DIBINEM).

Nazzareno Galiè (N)

Cardiology Unit, Cardiac Thoracic and Vascular Department, IRCCS Azienda Ospedaliero- Universitaria di Bologna.
Department of Medical and Surgical Sciences (DIMEC), Alma Mater Studiorum, University of Bologna, Bologna, Italy.

Giuseppe Boriani (G)

Cardiology Division, Department of Biomedical, Metabolic and Neural Sciences, University of Modena and Reggio Emilia, Policlinico di Modena.

Classifications MeSH