Atypical Presentation of Hypothenar Hammer Syndrome.


Journal

The Journal of craniofacial surgery
ISSN: 1536-3732
Titre abrégé: J Craniofac Surg
Pays: United States
ID NLM: 9010410

Informations de publication

Date de publication:
26 Aug 2024
Historique:
received: 22 06 2024
accepted: 13 07 2024
medline: 23 8 2024
pubmed: 23 8 2024
entrez: 23 8 2024
Statut: aheadofprint

Résumé

Hypothenar hammer syndrome (HHS) is a rare vascular disease caused by repetitive trauma to the hypothenar eminence, leading to thrombi and sometimes aneurysm development in the ulnar artery. This case report presents an atypical presentation of HHS with pathology extending distally into the digital arteries, complicated by an unclear history and unique genetic contributions. The patient, a 58-year-old male with a distant history of jackhammer work, presented with progressive pain in his fourth and fifth digits. CT angiography revealed patchy vascular lesions in the palmar arch. He developed another thrombi despite being treated initially with heparin. Genetic analysis revealed that he was heterozygous for Factor V Leiden with decreased protein C levels. Following surgical intervention, he recovered well. The author report a case of HHS in which medical management was superior to surgical treatment due to combined occupational and genetic predisposition for vascular pathology with findings extending beyond the ulnar artery.

Identifiants

pubmed: 39178401
doi: 10.1097/SCS.0000000000010548
pii: 00001665-990000000-01829
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2024 by Mutaz B. Habal, MD.

Déclaration de conflit d'intérêts

The authors report no conflicts of interest

Références

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Auteurs

Lydia Yang (L)

University of Iowa Carver College of Medicine.

Shady Al-Hayek (S)

Division of Plastic and Reconstructive Surgery, University of Iowa Hospitals and Clinics, Iowa City, IA.

Classifications MeSH