Deep brain stimulation and pallidotomy in primary Meige syndrome: a prospective cohort study.

Deep brain stimulation Dystonia Pallidotomy Psychiatric disorders Sleep

Journal

Neurological sciences : official journal of the Italian Neurological Society and of the Italian Society of Clinical Neurophysiology
ISSN: 1590-3478
Titre abrégé: Neurol Sci
Pays: Italy
ID NLM: 100959175

Informations de publication

Date de publication:
13 Sep 2024
Historique:
received: 22 06 2024
accepted: 26 08 2024
medline: 13 9 2024
pubmed: 13 9 2024
entrez: 12 9 2024
Statut: aheadofprint

Résumé

Primary Meige syndrome (PMS) is a rare form of dystonia, and comparative analysis of globus pallidus internal deep brain stimulation (GPi-DBS), subthalamic nucleus deep brain stimulation (STN-DBS), and pallidotomy has been lacking. This study aims to compare the efficacy, safety, and psychiatric features of GPi-DBS, STN-DBS, and pallidotomy in patients with PMS. This prospective cohort study was divided into three groups: GPi-DBS, STN-DBS, and pallidotomy. Clinical assessments, including motor and non-motor domains, were evaluated at baseline and at 1 year and 3 years after neurostimulation/surgery. Ninety-eight patients were recruited: 46 patients received GPi-DBS, 34 received STN-DBS, and 18 underwent pallidotomy. In the GPi-DBS group, the movement score of the Burke-Fahn-Marsden Dystonia Rating Scale (BFMDRS) improved from a mean (SE) of 13.8 (1.0) before surgery to 5.0 (0.7) (95% CI, -10.5 to -7.1; P < 0.001) at 3 years. Similarly, in the STN-DBS group, the mean (SE) score improved from 13.2 (0.8) to 3.5 (0.5) (95% CI, -10.3 to -8.1; P < 0.001) at 3 years, and in the pallidotomy group, it improved from 14.9 (1.3) to 6.0 (1.1) (95% CI, -11.3 to -6.5; P < 0.001) at 3 years. They were comparable therapeutic approaches for PMS that can improve motor function and quality of life without non-motor side effects. DBS and pallidotomy are safe and effective treatments for PMS, and an in-depth exploration of non-motor symptoms may be a new entry point for gaining a comprehensive understanding of the pathophysiology.

Sections du résumé

BACKGROUND BACKGROUND
Primary Meige syndrome (PMS) is a rare form of dystonia, and comparative analysis of globus pallidus internal deep brain stimulation (GPi-DBS), subthalamic nucleus deep brain stimulation (STN-DBS), and pallidotomy has been lacking. This study aims to compare the efficacy, safety, and psychiatric features of GPi-DBS, STN-DBS, and pallidotomy in patients with PMS.
METHODS METHODS
This prospective cohort study was divided into three groups: GPi-DBS, STN-DBS, and pallidotomy. Clinical assessments, including motor and non-motor domains, were evaluated at baseline and at 1 year and 3 years after neurostimulation/surgery.
RESULTS RESULTS
Ninety-eight patients were recruited: 46 patients received GPi-DBS, 34 received STN-DBS, and 18 underwent pallidotomy. In the GPi-DBS group, the movement score of the Burke-Fahn-Marsden Dystonia Rating Scale (BFMDRS) improved from a mean (SE) of 13.8 (1.0) before surgery to 5.0 (0.7) (95% CI, -10.5 to -7.1; P < 0.001) at 3 years. Similarly, in the STN-DBS group, the mean (SE) score improved from 13.2 (0.8) to 3.5 (0.5) (95% CI, -10.3 to -8.1; P < 0.001) at 3 years, and in the pallidotomy group, it improved from 14.9 (1.3) to 6.0 (1.1) (95% CI, -11.3 to -6.5; P < 0.001) at 3 years. They were comparable therapeutic approaches for PMS that can improve motor function and quality of life without non-motor side effects.
CONCLUSIONS CONCLUSIONS
DBS and pallidotomy are safe and effective treatments for PMS, and an in-depth exploration of non-motor symptoms may be a new entry point for gaining a comprehensive understanding of the pathophysiology.

Identifiants

pubmed: 39266808
doi: 10.1007/s10072-024-07752-w
pii: 10.1007/s10072-024-07752-w
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Peking University People's Hospital
ID : 2017-T-01
Organisme : Beijing Municipal Health Commission
ID : (SHOUFA-202224085

Informations de copyright

© 2024. Fondazione Società Italiana di Neurologia.

Références

Pandey S, Sharma S (2017) Meige’s syndrome: history, epidemiology, clinical features, pathogenesis and treatment. J Neurol Sci 372:162–170. https://doi.org/10.1016/j.jns.2016.11.053
doi: 10.1016/j.jns.2016.11.053 pubmed: 28017205
Albanese A, Bhatia K, Bressman SB, Delong MR, Fahn S, Fung VS, Hallett M, Jankovic J, Jinnah HA, Klein C, Lang AE, Mink JW, Teller JK (2013) Phenomenology and classification of dystonia: a consensus update. Mov Disord 28:863–873. https://doi.org/10.1002/mds.25475
doi: 10.1002/mds.25475 pubmed: 23649720 pmcid: 3729880
Colosimo C, Suppa A, Fabbrini G, Bologna M, Berardelli A (2010) Craniocervical dystonia: clinical and pathophysiological features. Eur J Neurol 17(Suppl 1):15–21. https://doi.org/10.1111/j.1468-1331.2010.03045.x
doi: 10.1111/j.1468-1331.2010.03045.x pubmed: 20590803
Defazio G, Livrea P (2002) Epidemiology of primary blepharospasm. Mov Disord 17:7–12. https://doi.org/10.1002/mds.1275
doi: 10.1002/mds.1275 pubmed: 11835433
Muller J, Kemmler G, Wissel J, Schneider A, Voller B, Grossmann J, Diez J, Homann N, Wenning GK, Schnider P, Poewe W, Austrian Botulinum T, Dystonia Study G (2002) The impact of blepharospasm and cervical dystonia on health-related quality of life and depression. J Neurol 249:842-846. https://doi.org/10.1007/s00415-002-0733-1
Wagle Shukla A, Brown R, Heese K, Jones J, Rodriguez RL, Malaty IM, Okun MS, Kluger BM (2016) High rates of fatigue and sleep disturbances in dystonia. Int J Neurosci 126:928–935. https://doi.org/10.3109/00207454.2015.1085035
doi: 10.3109/00207454.2015.1085035 pubmed: 26289935
Ma H, Qu J, Ye L, Shu Y, Qu Q (2021) Blepharospasm, oromandibular dystonia, and Meige syndrome: clinical and genetic update. Front Neurol 12:630221. https://doi.org/10.3389/fneur.2021.630221
doi: 10.3389/fneur.2021.630221 pubmed: 33854473 pmcid: 8039296
Jankovic J (2006) Treatment of dystonia. Lancet Neurol 5:864–872. https://doi.org/10.1016/s1474-4422(06)70574-9
doi: 10.1016/s1474-4422(06)70574-9 pubmed: 16987733
Balint B, Mencacci NE, Valente EM, Pisani A, Rothwell J, Jankovic J, Vidailhet M, Bhatia KP (2018) Dystonia Nat Rev Dis Primers 4:25. https://doi.org/10.1038/s41572-018-0023-6
doi: 10.1038/s41572-018-0023-6 pubmed: 30237473
Centen LM, Oterdoom DLM, Tijssen MAJ, Lesman-Leegte I, van Egmond ME, van Dijk JMC (2021) Bilateral pallidotomy for dystonia: a systematic review. Mov Disord 36:547–557. https://doi.org/10.1002/mds.28384
doi: 10.1002/mds.28384 pubmed: 33215750
Sanghera MK, Grossman RG, Kalhorn CG, Hamilton WJ, Ondo WG, Jankovic J (2003) Basal ganglia neuronal discharge in primary and secondary dystonia in patients undergoing pallidotomy. Neurosurgery 52:1358–1370; discussion 1370–1353. https://doi.org/10.1227/01.neu.0000064805.91249.f5 .
Sako W, Morigaki R, Mizobuchi Y, Tsuzuki T, Ima H, Ushio Y, Nagahiro S, Kaji R, Goto S (2011) Bilateral pallidal deep brain stimulation in primary Meige syndrome. Parkinsonism Relat Disord 17:123–125. https://doi.org/10.1016/j.parkreldis.2010.11.013
doi: 10.1016/j.parkreldis.2010.11.013 pubmed: 21147544
Vidailhet M, Vercueil L, Houeto J-L, Krystkowiak P, Lagrange C, Yelnik J, Bardinet E, Benabid A-L, Navarro S, Dormont D, Grand S, Blond S, Ardouin C, Pillon B, Dujardin K, Hahn-Barma V, Agid Y, Destée A, Pollak P (2007) Bilateral, pallidal, deep-brain stimulation in primary generalised dystonia: a prospective 3 year follow-up study. Lancet Neurol 6:223–229. https://doi.org/10.1016/s1474-4422(07)70035-2
doi: 10.1016/s1474-4422(07)70035-2 pubmed: 17303528
Volkmann J, Wolters A, Kupsch A, Müller J, Kühn AA, Schneider G-H, Poewe W, Hering S, Eisner W, Müller J-U, Deuschl G, Pinsker MO, Skogseid I-M, Roeste GK, Krause M, Tronnier V, Schnitzler A, Voges J, Nikkhah G, Vesper J, Classen J, Naumann M, Benecke R (2012) Pallidal deep brain stimulation in patients with primary generalised or segmental dystonia: 5-year follow-up of a randomised trial. The Lancet Neurology 11:1029–1038. https://doi.org/10.1016/s1474-4422(12)70257-0
doi: 10.1016/s1474-4422(12)70257-0 pubmed: 23123071
Hao Q, Wang D, OuYang J, Ding H, Wu G, Liu Z, Liu R (2020) Pallidal deep brain stimulation in primary Meige syndrome: clinical outcomes and psychiatric features. J Neurol Neurosurg Psychiatry 91:1343–1348. https://doi.org/10.1136/jnnp-2020-323701
doi: 10.1136/jnnp-2020-323701 pubmed: 33028603
Conte A, Berardelli I, Ferrazzano G, Pasquini M, Berardelli A, Fabbrini G (2016) Non-motor symptoms in patients with adult-onset focal dystonia: sensory and psychiatric disturbances. Parkinsonism Relat Disord 22(Suppl 1):S111-114. https://doi.org/10.1016/j.parkreldis.2015.09.001
doi: 10.1016/j.parkreldis.2015.09.001 pubmed: 26360238
Burke RE, Fahn S, Marsden CD, Bressman SB, Moskowitz C, Friedman J (1985) Validity and reliability of a rating scale for the primary torsion dystonias. Neurology 35:73–77. https://doi.org/10.1212/WNL.35.1.73
doi: 10.1212/WNL.35.1.73 pubmed: 3966004
Ware JE, Sherbourne CD (1992) The MOS 36-item short-form health survey (SF-36): I. Conceptual framework and item selection. Med Care 30:473–483. https://doi.org/10.1097/00005650-199206000-00002
doi: 10.1097/00005650-199206000-00002 pubmed: 1593914
Nasreddine ZS, Phillips NA, Bedirian V, Charbonneau S, Whitehead V, Collin I, Cummings JL, Chertkow H (2005) The Montreal cognitive assessment, MoCA: a brief screening tool for mild cognitive impairment. J Am Geriatr Soc 53:695–699. https://doi.org/10.1111/j.1532-5415.2005.53221.x
doi: 10.1111/j.1532-5415.2005.53221.x pubmed: 15817019
Beck AT, Steer RA, Garbin MG (1988) Psychometric properties of the Beck depression inventory twenty five years of evaluation. Clini Psychol Rev 8:77–100. https://doi.org/10.1016/0272-7358(88)90050-5
doi: 10.1016/0272-7358(88)90050-5
DJ Buysse Reynolds lll CF, Monk TH, Berman SR, Kupfer DJ, 1989 The Pittsburgh sleep quality index: a new instrument for psychiatric practice and research Psychiatry Res 28 193 213. https://doi.org/10.1016/0165-1781(89)90047-4
Zhan S, Sun F, Pan Y, Liu W, Huang P, Cao C, Zhang J, Li D, Sun B (2018) Bilateral deep brain stimulation of the subthalamic nucleus in primary Meige syndrome. J Neurosurg 128:897–902. https://doi.org/10.3171/2016.12.JNS16383
doi: 10.3171/2016.12.JNS16383 pubmed: 28548593
Lyons MK, Birch BD, Hillman RA, Boucher OK, Evidente VG (2010) Long-term follow-up of deep brain stimulation for Meige syndrome. Neurosurg Focus 29:E5. https://doi.org/10.3171/2010.4.FOCUS1067
doi: 10.3171/2010.4.FOCUS1067 pubmed: 20672922
Loher TJ, Capelle HH, Kaelin-Lang A, Weber S, Weigel R, Burgunder JM, Krauss JK (2008) Deep brain stimulation for dystonia: outcome at long-term follow-up. J Neurol 255:881–884. https://doi.org/10.1007/s00415-008-0798-6
doi: 10.1007/s00415-008-0798-6 pubmed: 18338193
Wagle Shukla A, Ostrem JL, Vaillancourt DE, Chen R, Foote KD, Okun MS (2018) Physiological effects of subthalamic nucleus deep brain stimulation surgery in cervical dystonia. J Neurol Neurosurg Psychiatry 89:1296–1300. https://doi.org/10.1136/jnnp-2017-317098
doi: 10.1136/jnnp-2017-317098 pubmed: 29326293
Perl S, Luttig A, Kohling R, Richter A (2022) Deep brain stimulation in animal models of dystonia. Neurobiol Dis 175:105912. https://doi.org/10.1016/j.nbd.2022.105912
doi: 10.1016/j.nbd.2022.105912 pubmed: 36307031
Hamani C, Temel Y (2012) Deep brain stimulation for psychiatric disease: contributions and validity of animal models. Sci Transl Med 4:142rv148. https://doi.org/10.1126/scitranslmed.3003722 .
Martino D, Muglia M, Abbruzzese G, Berardelli A, Girlanda P, Liguori M, Livrea P, Quattrone A, Roselli F, Sprovieri T, Valente EM, Defazio G (2009) Brain-derived neurotrophic factor and risk for primary adult-onset cranial-cervical dystonia. Eur J Neurol 16:949–952. https://doi.org/10.1111/j.1468-1331.2009.02633.x
doi: 10.1111/j.1468-1331.2009.02633.x pubmed: 19473353
Tian H, Zhang B, Yu Y, Zhen X, Zhang L, Yuan Y, Wang L (2021) Electrophysiological signatures predict clinical outcomes after deep brain stimulation of the globus pallidus internus in Meige syndrome. Brain Stimul 14:685–692. https://doi.org/10.1016/j.brs.2021.04.005
doi: 10.1016/j.brs.2021.04.005 pubmed: 33848676
Lenz FA, Suarez JI, Metman LV, Reich SG, Karp BI, Hallett M, Rowland LH, Dougherty PM (1998) Pallidal activity during dystonia: somatosensory reorganisation and changes with severity. J Neurol Neurosurg Psychiatry 65:767–770. https://doi.org/10.1136/jnnp.65.5.767
doi: 10.1136/jnnp.65.5.767 pubmed: 9810954 pmcid: 2170350
Jinnah HA, Neychev V, Hess EJ (2017) The anatomical basis for dystonia: the motor network model. Tremor Other Hyperkinet Mov 7:506–520. https://doi.org/10.7916/D8V69X3S
doi: 10.7916/D8V69X3S
Tisch S (2022) Deep brain stimulation in dystonia: factors contributing to variability in outcome in short and long term follow-up. Curr Opin Neurol 35:510–517. https://doi.org/10.1097/WCO.0000000000001072
doi: 10.1097/WCO.0000000000001072 pubmed: 35787538
Chakravarty MM, Hamani C, Martinez-Canabal A, Ellegood J, Laliberte C, Nobrega JN, Sankar T, Lozano AM, Frankland PW, Lerch JP (2016) Deep brain stimulation of the ventromedial prefrontal cortex causes reorganization of neuronal processes and vasculature. Neuroimage 125:422–427. https://doi.org/10.1016/j.neuroimage.2015.10.049
doi: 10.1016/j.neuroimage.2015.10.049 pubmed: 26525655
Bakker J (2022) The role of steroid hormones in the sexual differentiation of the human brain. J Neuroendocrinol 34:e13050. https://doi.org/10.1111/jne.13050
doi: 10.1111/jne.13050 pubmed: 34708466
Sacher J, Neumann J, Okon-Singer H, Gotowiec S, Villringer A (2013) Sexual dimorphism in the human brain: evidence from neuroimaging. Magn Reson Imaging 31:366–375. https://doi.org/10.1016/j.mri.2012.06.007
doi: 10.1016/j.mri.2012.06.007 pubmed: 22921939
Aires A, Gomes T, Linhares P, Cunha F, Rosas MJ, Vaz R (2018) The impact of deep brain stimulation on health related quality of life and disease-specific disability in Meige Syndrome (MS). Clin Neurol Neurosurg 171:53–57. https://doi.org/10.1016/j.clineuro.2018.05.012
doi: 10.1016/j.clineuro.2018.05.012 pubmed: 29807200
Yoshor D, Hamilton WJ, Ondo W, Jankovic J, Grossman RG (2001) Comparison of thalamotomy and pallidotomy for the treatment of dystonia. Neurosurgery 58:818–826. https://doi.org/10.1097/00006123-200104000-00025
doi: 10.1097/00006123-200104000-00025
Paus S, Gross J, Moll-Muller M, Hentschel F, Spottke A, Wabbels B, Klockgether T, Abele M (2011) Impaired sleep quality and restless legs syndrome in idiopathic focal dystonia: a controlled study. J Neurol 258:1835–1840. https://doi.org/10.1007/s00415-011-6029-6
doi: 10.1007/s00415-011-6029-6 pubmed: 21499724
Yang J, Zhang L, Hou Y, Wei Q, Ou R, Lin J, Song W, Cao B, Shang H (2021) Excessive daytime sleepiness in idiopathic blepharospasm. Parkinsonism Relat Disord 89:134–138. https://doi.org/10.1016/j.parkreldis.2021.07.005
doi: 10.1016/j.parkreldis.2021.07.005 pubmed: 34298213
Caverzasio S, Amato N, Manconi M, Prosperetti C, Kaelin-Lang A, Hutchison WD, Galati S (2018) Brain plasticity and sleep: Implication for movement disorders. Neurosci Biobehav Rev 86:21–35. https://doi.org/10.1016/j.neubiorev.2017.12.009
doi: 10.1016/j.neubiorev.2017.12.009 pubmed: 29278685
Hertenstein E, Tang NK, Bernstein CJ, Nissen C, Underwood MR, Sandhu HK (2016) Sleep in patients with primary dystonia: a systematic review on the state of research and perspectives. Sleep Med Rev 26:95–107. https://doi.org/10.1016/j.smrv.2015.04.004
doi: 10.1016/j.smrv.2015.04.004 pubmed: 26164369
Medina Escobar A, Pringsheim T, Goodarzi Z, Martino D (2021) The prevalence of depression in adult onset idiopathic dystonia: systematic review and metaanalysis. Neurosci Biobehav Rev 125:221–230. https://doi.org/10.1016/j.neubiorev.2021.02.036
doi: 10.1016/j.neubiorev.2021.02.036 pubmed: 33662441
Miller KM, Okun MS, Fernandez HF, Jacobson CEt, Rodriguez RL, Bowers D, (2007) Depression symptoms in movement disorders: comparing Parkinson’s disease, dystonia, and essential tremor. Mov Disord 22:666–672. https://doi.org/10.1002/mds.21376
doi: 10.1002/mds.21376 pubmed: 17266084
Hinz A, Finck C, Gomez Y, Daig I, Glaesmer H, Singer S (2014) Anxiety and depression in the general population in Colombia: reference values of the Hospital Anxiety and Depression Scale (HADS). Soc Psychiatry Psychiatr Epidemiol 49:41–49. https://doi.org/10.1007/s00127-013-0714-y
doi: 10.1007/s00127-013-0714-y pubmed: 23748887
Huang M, de Koning TJ, Tijssen MAJ, Verbeek DS (2021) Cross-disease analysis of depression, ataxia and dystonia highlights a role for synaptic plasticity and the cerebellum in the pathophysiology of these comorbid diseases. Biochim Biophys Acta Mol Basis Dis 1867:165976. https://doi.org/10.1016/j.bbadis.2020.165976
doi: 10.1016/j.bbadis.2020.165976 pubmed: 33011198
Birchall EL, Walker HC, Cutter G, Guthrie S, Joop A, Memon RA, Watts RL, Standaert DG, Amara AW (2017) The effect of unilateral subthalamic nucleus deep brain stimulation on depression in Parkinson’s disease. Brain Stimul 10:651–656. https://doi.org/10.1016/j.brs.2016.12.014
doi: 10.1016/j.brs.2016.12.014 pubmed: 28065487
Elias GJB, Boutet A, Parmar R, Wong EHY, Germann J, Loh A, Paff M, Pancholi A, Gwun D, Chow CT, Gouveia FV, Harmsen IE, Beyn ME, Santarnecchi E, Fasano A, Blumberger DM, Kennedy SH, Lozano AM, Bhat V (2021) Neuromodulatory treatments for psychiatric disease: A comprehensive survey of the clinical trial landscape. Brain Stimul 14:1393–1403. https://doi.org/10.1016/j.brs.2021.08.021
doi: 10.1016/j.brs.2021.08.021 pubmed: 34461326
Mahlknecht P, Limousin P, Foltynie T (2015) Deep brain stimulation for movement disorders: update on recent discoveries and outlook on future developments. J Neurol 262:2583–2595. https://doi.org/10.1007/s00415-015-7790-8
doi: 10.1007/s00415-015-7790-8 pubmed: 26037016

Auteurs

Qing-Pei Hao (QP)

Department of Neurosurgery, Peking University People's Hospital, Xizhimen South Street, Xicheng DistrictBeijing, 100044, China.

Wen-Tao Zheng (WT)

Department of Neurosurgery, The First Affiliated Hospital of Xiamen University, Xiamen, China.

Zi-Hao Zhang (ZH)

Department of Neurosurgery, Peking University People's Hospital, Xizhimen South Street, Xicheng DistrictBeijing, 100044, China.

Hu Ding (H)

Department of Neurosurgery, Peking University People's Hospital, Xizhimen South Street, Xicheng DistrictBeijing, 100044, China.

Guang-Biao Qin (GB)

Department of Neurology, Peking University People's Hospital, Beijing, China.

Ye-Zu Liu (YZ)

Department of Psychology, Peking University People's Hospital, Beijing, China.

Yao Tan (Y)

Clinical Research Institute, Peking University, Beijing, China.

Zhi Liu (Z)

Department of Neurosurgery, Peking University People's Hospital, Xizhimen South Street, Xicheng DistrictBeijing, 100044, China. jylc143509@163.com.
Functional Neurosurgery Research Center, Peking University Health Science Center, Haidian District, Xueyuan Road, BeijingBeijing, 100191, No. 38, China. jylc143509@163.com.

Ru-En Liu (RE)

Department of Neurosurgery, Peking University People's Hospital, Xizhimen South Street, Xicheng DistrictBeijing, 100044, China. liuruen@pku.edu.cn.
Functional Neurosurgery Research Center, Peking University Health Science Center, Haidian District, Xueyuan Road, BeijingBeijing, 100191, No. 38, China. liuruen@pku.edu.cn.

Classifications MeSH