Selective degradation of mutant FMS-like tyrosine kinase-3 requires BIM-dependent depletion of heat shock proteins.


Journal

Leukemia
ISSN: 1476-5551
Titre abrégé: Leukemia
Pays: England
ID NLM: 8704895

Informations de publication

Date de publication:
17 Sep 2024
Historique:
received: 03 04 2024
accepted: 02 09 2024
revised: 28 08 2024
medline: 20 9 2024
pubmed: 20 9 2024
entrez: 19 9 2024
Statut: aheadofprint

Résumé

Internal tandem duplications in the FMS-like tyrosine kinase-3 (FLT3-ITD) are common mutations in acute myeloid leukemia (AML). Proteolysis-targeting chimeras (PROTACs) that induce proteasomal degradation of mutated FLT3 emerge as innovative pharmacological approach. Molecular mechanisms that control targeted proteolysis beyond the ubiquitin-proteasome-system are undefined and PROTACs are the only known type of FLT3 degraders. We report that the von-Hippel-Lindau ubiquitin-ligase based FLT3 PROTAC MA49 (melotinib-49) and the FLT3 hydrophobic tagging molecule MA50 (halotinib-50) reduce endoplasmic reticulum-associated, oncogenic FLT3-ITD but spare FLT3. Nanomolar doses of MA49 and MA50 induce apoptosis of human leukemic cell lines and primary AML blasts with FLT3-ITD (p < 0.05-0.0001), but not of primary hematopoietic stem cells and differentiated immune cells, FLT3 wild-type cells, retinal cells, and c-KIT-dependent cells. In vivo activity of MA49 against FLT3-ITD-positive leukemia cells is verified in a Danio rerio model. The degrader-induced loss of FLT3-ITD involves the pro-apoptotic BH3-only protein BIM and a previously unidentified degrader-induced depletion of protein-folding chaperones. The expression levels of HSP90 and HSP110 correlate with reduced AML patient survival (p < 0.1) and HSP90, HSP110, and BIM are linked to the expression of FLT3 in primary AML cells (p < 0.01). HSP90 suppresses degrader-induced FLT3-ITD elimination and thereby establishes a mechanistically defined feed-back circuit.

Identifiants

pubmed: 39300221
doi: 10.1038/s41375-024-02405-5
pii: 10.1038/s41375-024-02405-5
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : KR2291
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : SI 868/26-1, DFG-project number 49527183

Informations de copyright

© 2024. The Author(s).

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Auteurs

Melisa Halilovic (M)

Department of Toxicology, University Medical Center, 55131, Mainz, Germany.

Mohamed Abdelsalam (M)

Department of Pharmaceutical Chemistry, Faculty of Pharmacy, Alexandria University, Alexandria, Egypt.
Department of Medicinal Chemistry, Institute of Pharmacy, Martin-Luther-University of Halle-Wittenberg, Halle, Saale, Germany.

Joanna Zabkiewicz (J)

Academic Department of Haematology, University of Cardiff, Heath Park, Cardiff, UK.

Michelle Lazenby (M)

Academic Department of Haematology, University of Cardiff, Heath Park, Cardiff, UK.

Caroline Alvares (C)

Academic Department of Haematology, University of Cardiff, Heath Park, Cardiff, UK.

Matthias Schmidt (M)

Department of Medicinal Chemistry, Institute of Pharmacy, Martin-Luther-University of Halle-Wittenberg, Halle, Saale, Germany.

Walburgis Brenner (W)

Clinic for Obstetrics and Women's Health, University Medical Center, 55131, Mainz, Germany.

Sara Najafi (S)

Hopp Children's Cancer Center Heidelberg (KiTZ), Heidelberg, Germany.
Clinical Cooperation Unit Pediatric Oncology (B310), German Cancer Research Center (DKFZ) and German Cancer Consortium (DKTK), Heidelberg, Germany.
National Center for Tumor Diseases Heidelberg, Heidelberg, Germany.

Ina Oehme (I)

Hopp Children's Cancer Center Heidelberg (KiTZ), Heidelberg, Germany.
Clinical Cooperation Unit Pediatric Oncology (B310), German Cancer Research Center (DKFZ) and German Cancer Consortium (DKTK), Heidelberg, Germany.
National Center for Tumor Diseases Heidelberg, Heidelberg, Germany.

Christoph Hieber (C)

Department of Dermatology, University Medical Center Mainz, Mainz, Germany.

Yanira Zeyn (Y)

Department of Dermatology, University Medical Center Mainz, Mainz, Germany.

Matthias Bros (M)

Department of Dermatology, University Medical Center Mainz, Mainz, Germany.

Wolfgang Sippl (W)

Department of Medicinal Chemistry, Institute of Pharmacy, Martin-Luther-University of Halle-Wittenberg, Halle, Saale, Germany. wolfgang.sippl@pharmazie.uni-halle.de.

Oliver H Krämer (OH)

Department of Toxicology, University Medical Center, 55131, Mainz, Germany. okraemer@uni-mainz.de.

Classifications MeSH