Persistent Desmoglein-1 downregulation and Periostin accumulation in histologic remission of Eosinophilic Esophagitis.

Eosinophilic Esophagitis Epithelial barrier dysfunction Fibrosis Proteome Transcriptome

Journal

The Journal of allergy and clinical immunology
ISSN: 1097-6825
Titre abrégé: J Allergy Clin Immunol
Pays: United States
ID NLM: 1275002

Informations de publication

Date de publication:
27 Sep 2024
Historique:
received: 16 05 2024
revised: 19 08 2024
accepted: 04 09 2024
medline: 30 9 2024
pubmed: 30 9 2024
entrez: 29 9 2024
Statut: aheadofprint

Résumé

Patients with Eosinophilic esophagitis (EoE) require long-lasting resolution of inflammation to prevent fibrostenosis and dysphagia. However, the dissociation between symptoms and histologic improvement suggests persistent molecular drivers despite histologic remission. To characterize persisting molecular alterations in pediatric patients with EoE using tissue transcriptomics and proteomics. Esophageal biopsies (n=247) collected prospectively during 189 endoscopies from pediatric patients with EoE (N=36, up to 11 follow-up endoscopies) and pediatric controls (N=44, single endoscopies) were subjected to bulk transcriptomics (n=96) and proteomics (n=151). Intercellular junctions (Desmoglein-1/-3, Desmoplakin, E-cadherin) and epithelial-to-mesenchymal transition (EMT, Vimentin:E-cadherin ratio) were assessed by immunofluorescence staining. Active EoE (≥15 eosinophils/hpf), inactive EoE (<15 eosinophils/hpf) and deep remission EoE (0 eosinophils/hpf) were diagnosed in 107/185, 78/185 and 41/185 biopsies, respectively. Among the dysregulated genes (up-/downregulated 310/112) and proteins (up-/downregulated 68/16) between active EoE and controls, 17 genes and 6 proteins remained dysregulated in inactive EoE. Using persistently upregulated genes (n=9) and proteins (n=3) only, such as ALOX15, CXCL1, CXCL6, CTSG, CDH26, PRRX1, CLC, EPX, and POSTN was sufficient to separate inactive EoE, as well as deep remission biopsies from control tissue. While 32 differentially expressed genes persisted in deep remission of EoE compared to controls, the proteome normalized except for persistently upregulated Periostin (POSTN). Epithelial-mesenchymal transition normalized in inactive EoE, whereas desmosome recovery remained impaired due to Desmoglein-1 downregulation. The analysis of molecular changes shows persistent EoE-associated esophageal dysregulation despite histologic remission. These data expand our understanding of inflammatory processes and possible mechanisms that underlie tissue remodeling in EoE.

Sections du résumé

BACKGROUND BACKGROUND
Patients with Eosinophilic esophagitis (EoE) require long-lasting resolution of inflammation to prevent fibrostenosis and dysphagia. However, the dissociation between symptoms and histologic improvement suggests persistent molecular drivers despite histologic remission.
OBJECTIVE OBJECTIVE
To characterize persisting molecular alterations in pediatric patients with EoE using tissue transcriptomics and proteomics.
METHODS METHODS
Esophageal biopsies (n=247) collected prospectively during 189 endoscopies from pediatric patients with EoE (N=36, up to 11 follow-up endoscopies) and pediatric controls (N=44, single endoscopies) were subjected to bulk transcriptomics (n=96) and proteomics (n=151). Intercellular junctions (Desmoglein-1/-3, Desmoplakin, E-cadherin) and epithelial-to-mesenchymal transition (EMT, Vimentin:E-cadherin ratio) were assessed by immunofluorescence staining.
RESULTS RESULTS
Active EoE (≥15 eosinophils/hpf), inactive EoE (<15 eosinophils/hpf) and deep remission EoE (0 eosinophils/hpf) were diagnosed in 107/185, 78/185 and 41/185 biopsies, respectively. Among the dysregulated genes (up-/downregulated 310/112) and proteins (up-/downregulated 68/16) between active EoE and controls, 17 genes and 6 proteins remained dysregulated in inactive EoE. Using persistently upregulated genes (n=9) and proteins (n=3) only, such as ALOX15, CXCL1, CXCL6, CTSG, CDH26, PRRX1, CLC, EPX, and POSTN was sufficient to separate inactive EoE, as well as deep remission biopsies from control tissue. While 32 differentially expressed genes persisted in deep remission of EoE compared to controls, the proteome normalized except for persistently upregulated Periostin (POSTN). Epithelial-mesenchymal transition normalized in inactive EoE, whereas desmosome recovery remained impaired due to Desmoglein-1 downregulation.
CONCLUSION CONCLUSIONS
The analysis of molecular changes shows persistent EoE-associated esophageal dysregulation despite histologic remission. These data expand our understanding of inflammatory processes and possible mechanisms that underlie tissue remodeling in EoE.

Identifiants

pubmed: 39343172
pii: S0091-6749(24)00990-4
doi: 10.1016/j.jaci.2024.09.016
pii:
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2024. Published by Elsevier Inc.

Auteurs

Hannes Hoelz (H)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Tim Faro (T)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Marie-Luise Frank (ML)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Ignasi Forné (I)

Protein Analysis Unit, Biomedical Center Munich, LMU Munich, Germany.

Daniela Kugelmann (D)

Chair of Vegetative Anatomy, Institute of Anatomy, Faculty of Medicine, LMU Munich, Germany.

Anja Jurk (A)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Simon Buehler (S)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Kolja Siebert (K)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany.

Monica Matchado (M)

Chair of Experimental Bioinformatics, TUM School of Life Sciences, Technical University of Munich, 85354 Freising, Germany.

Tobias Straub (T)

Biomedical Center Munich, Bioinformatics Core Facility, LMU Munich, Germany.

Annett Hering (A)

Institute of Pathology, School of Medicine and Health, Technische Universität München, Munich, Germany; Comparative Experimental Pathology, School of Medicine and Health, Technische Universität München, Munich, Germany.

Guido Piontek (G)

Institute of Pathology, Faculty of Medicine, LMU Munich, Germany.

Susanna Mueller (S)

Institute of Pathology, Faculty of Medicine, LMU Munich, Germany.

Sibylle Koletzko (S)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany; Department of Pediatrics, Gastroenterology and Nutrition, School of Medicine Collegium Medicum University of Warmia and Mazury, Olsztyn, Poland.

Markus List (M)

Data Science in Systems Biology, TUM School of Life Sciences, Technical University of Munich, 85354 Freising, Germany; Munich Data Science Institute (MDSI), Technical University of Munich, 85748 Garching, Germany.

Katja Steiger (K)

Institute of Pathology, School of Medicine and Health, Technische Universität München, Munich, Germany; Comparative Experimental Pathology, School of Medicine and Health, Technische Universität München, Munich, Germany.

Martina Rudelius (M)

Institute of Pathology, Faculty of Medicine, LMU Munich, Germany.

Jens Waschke (J)

Chair of Vegetative Anatomy, Institute of Anatomy, Faculty of Medicine, LMU Munich, Germany.

Tobias Schwerd (T)

Department of Pediatrics, Dr. von Hauner Children's Hospital, University Hospital, LMU Munich, Germany. Electronic address: tschwerd@med.lmu.de.

Classifications MeSH