Circulating microRNAs and isomiRs as biomarkers for the initial insult and epileptogenesis in four experimental epilepsy models: The EPITARGET study.

amygdala stimulation perforant pathway stimulation pilocarpine posttraumatic epilepsy status epilepticus traumatic brain injury

Journal

Epilepsia
ISSN: 1528-1167
Titre abrégé: Epilepsia
Pays: United States
ID NLM: 2983306R

Informations de publication

Date de publication:
01 Oct 2024
Historique:
revised: 17 09 2024
received: 15 05 2024
accepted: 17 09 2024
medline: 1 10 2024
pubmed: 1 10 2024
entrez: 1 10 2024
Statut: aheadofprint

Résumé

Structural epilepsies can manifest months or years after the occurrence of an initial epileptogenic insult, making them amenable for secondary prevention. However, development of preventive treatments has been challenged by a lack of biomarkers for identifying the subset of individuals with the highest risk of epilepsy after the epileptogenic insult. Four different rat models of epileptogenesis were investigated to identify differentially expressed circulating microRNA (miRNA) and isomiR profiles as biomarkers for epileptogenesis. Plasma samples were collected on day 2 and day 9 during the latency period from animals that did or did not develop epilepsy during long-term video-electroencephalographic monitoring. miRNAs and isomiRs were identified and measured in an unsupervised manner, using a genome-wide small RNA sequencing platform. Receiver operating characteristic analysis was performed to determine the performance of putative biomarkers. Two days after an epileptogenic insult, alterations in the levels of several plasma miRNAs and isomiRs predicted epileptogenesis in a model-specific manner. One miRNA, miR-3085, showed good sensitivity (but low specificity) as a prognostic biomarker for epileptogenesis in all four models (area under the curve = .729, sensitivity = 83%, specificity = 64%, p < .05). Identified plasma miRNAs and isomiRs are mostly etiology-specific rather than common prognostic biomarkers of epileptogenesis. These data imply that in preclinical and clinical studies, it may be necessary to identify specific biomarkers for different epilepsy etiologies. Importantly, circulating miRNAs like miR-3085 with high negative predictive value for epileptogenesis in different etiologies could be useful candidates for initial screening purposes of epileptogenesis risk.

Identifiants

pubmed: 39352406
doi: 10.1111/epi.18134
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Seventh Framework Programme
ID : FP7- HEALTH project 602102 [EPITARGET]

Informations de copyright

© 2024 The Author(s). Epilepsia published by Wiley Periodicals LLC on behalf of International League Against Epilepsy.

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Auteurs

Erwin A van Vliet (EA)

Department of (Neuro)pathology, Amsterdam Neuroscience, Amsterdam UMC, University of Amsterdam, Amsterdam, The Netherlands.
Swammerdam Institute for Life Sciences, Center for Neuroscience, University of Amsterdam, Amsterdam, The Netherlands.

Mirte Scheper (M)

Department of (Neuro)pathology, Amsterdam Neuroscience, Amsterdam UMC, University of Amsterdam, Amsterdam, The Netherlands.

James D Mills (JD)

Department of (Neuro)pathology, Amsterdam Neuroscience, Amsterdam UMC, University of Amsterdam, Amsterdam, The Netherlands.
Department of Clinical and Experimental Epilepsy, UCL Queen Square Institute of Neurology, London, UK.
Chalfont Centre for Epilepsy, Buckinghamshire, UK.

Noora Puhakka (N)

A. I. Virtanen Institute for Molecular Sciences, University of Eastern Finland, Kuopio, Finland.

Kinga Szydlowska (K)

Laboratory of Epileptogenesis, Nencki Institute of Experimental Biology, Warsaw, Poland.

Manuela Ferracin (M)

Department of Medical and Surgical Sciences, University of Bologna, Bologna, Italy.
IRCCS Azienda Ospedaliero-Universitaria di Bologna, Bologna, Italy.

Francesca Lovisari (F)

Department of Neuroscience and Rehabilitation, University of Ferrara, Ferrara, Italy.
Division of Neuroscience, IRCCS San Raffaele Scientific Institute, Milan, Italy.

Marie Soukupova (M)

Department of Neuroscience and Rehabilitation, University of Ferrara, Ferrara, Italy.

Silvia Zucchini (S)

Department of Neuroscience and Rehabilitation, University of Ferrara, Ferrara, Italy.

Prashant K Srivastava (PK)

National Heart and Lung Institute, Imperial College London, London, UK.

Michael R Johnson (MR)

Division of Brain Sciences, Imperial College London, London, UK.

Katarzyna Lukasiuk (K)

Laboratory of Epileptogenesis, Nencki Institute of Experimental Biology, Warsaw, Poland.

Jan A Gorter (JA)

Swammerdam Institute for Life Sciences, Center for Neuroscience, University of Amsterdam, Amsterdam, The Netherlands.

Eleonora Aronica (E)

Department of (Neuro)pathology, Amsterdam Neuroscience, Amsterdam UMC, University of Amsterdam, Amsterdam, The Netherlands.

Asla Pitkänen (A)

A. I. Virtanen Institute for Molecular Sciences, University of Eastern Finland, Kuopio, Finland.

Michele Simonato (M)

Department of Neuroscience and Rehabilitation, University of Ferrara, Ferrara, Italy.
Division of Neuroscience, IRCCS San Raffaele Scientific Institute, Milan, Italy.

Classifications MeSH