Predisposing factors to pattern change in cervical dystonia.

Adult-onset idiopathic dystonia Botulinum toxin (BoNT) Cervical dystonia (CD) Movement disorders

Journal

Journal of neural transmission (Vienna, Austria : 1996)
ISSN: 1435-1463
Titre abrégé: J Neural Transm (Vienna)
Pays: Austria
ID NLM: 9702341

Informations de publication

Date de publication:
14 Oct 2024
Historique:
received: 21 06 2024
accepted: 07 10 2024
medline: 15 10 2024
pubmed: 15 10 2024
entrez: 14 10 2024
Statut: aheadofprint

Résumé

Cervical dystonia (CD) patterns may change with Botulinum toxin (BoNT) treatment. To evaluate the time within those changes usually occur, the most predisposed phenotypes and predisposing factors. We divided idiopathic CD patients into two groups- change YES and NO, collecting general clinical and demographic variables. We also evaluated duration of BoNT treatment, Tsui total scores and subscores - assessed at T0 - before BoNT start - and at T1- time to chenge in the YES group or last visit in the NO group. The risk of pattern change was assessed by Kaplan Meyer curves and Cox regression analysis. Finally, Multivariate linear regressions were employed to assess if Tsui severity correlated with the change. Among 100 patients (60 women), 37 experienced a phenotype switch, mostly in the first five years of BoNT treatment, YES and NO groups were comparable. Multivariate Cox Regression revealed the presence of laterocollis or rotatocollis at T0 as predictors of switch (respectively P = 0.01, HR = 3.5; P = 0.03, HR = 1.5). Multivariate linear regressions revealed that high Tsui subscores for the tilt and low Tsui total scores were risk factors for the change of pattern (respectively P = 0.002, OR = 6; P = 0.03, OR = 0.8). Latero and Rotatocollis are the CD phenotypes most predisposed to change. CD characterized by neck tilt are more likely to change phenotype following treatment. Dystonias with a low degree of severity are more predisposed to switch. Both, the different degree of muscle activation and BoNT mechanism of action, may impact on that phenomenon.

Sections du résumé

BACKGROUND BACKGROUND
Cervical dystonia (CD) patterns may change with Botulinum toxin (BoNT) treatment.
OBJECTIVE OBJECTIVE
To evaluate the time within those changes usually occur, the most predisposed phenotypes and predisposing factors.
METHODS METHODS
We divided idiopathic CD patients into two groups- change YES and NO, collecting general clinical and demographic variables. We also evaluated duration of BoNT treatment, Tsui total scores and subscores - assessed at T0 - before BoNT start - and at T1- time to chenge in the YES group or last visit in the NO group. The risk of pattern change was assessed by Kaplan Meyer curves and Cox regression analysis. Finally, Multivariate linear regressions were employed to assess if Tsui severity correlated with the change.
RESULTS RESULTS
Among 100 patients (60 women), 37 experienced a phenotype switch, mostly in the first five years of BoNT treatment, YES and NO groups were comparable. Multivariate Cox Regression revealed the presence of laterocollis or rotatocollis at T0 as predictors of switch (respectively P = 0.01, HR = 3.5; P = 0.03, HR = 1.5). Multivariate linear regressions revealed that high Tsui subscores for the tilt and low Tsui total scores were risk factors for the change of pattern (respectively P = 0.002, OR = 6; P = 0.03, OR = 0.8).
CONCLUSIONS CONCLUSIONS
Latero and Rotatocollis are the CD phenotypes most predisposed to change. CD characterized by neck tilt are more likely to change phenotype following treatment. Dystonias with a low degree of severity are more predisposed to switch. Both, the different degree of muscle activation and BoNT mechanism of action, may impact on that phenomenon.

Identifiants

pubmed: 39402173
doi: 10.1007/s00702-024-02848-1
pii: 10.1007/s00702-024-02848-1
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2024. The Author(s), under exclusive licence to Springer-Verlag GmbH Austria, part of Springer Nature.

Références

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Auteurs

Assunta Trinchillo (A)

Neuroscience and Cell Biology Institute, Neuromodulation and Motor Control Section, St. George's University of London, London, UK. assuntatrinchillo94@gmail.com.

Nunzia Cuomo (N)

Department of Neurosciences, Reproductive Sciences and Odontostomatology, "Federico II", University, Naples, Italy.

Francesco Habetswallner (F)

Clinical Neurophysiology Unit, Cardarelli Hospital, Naples, Italy.

Marcello Esposito (M)

Clinical Neurophysiology Unit, Cardarelli Hospital, Naples, Italy.

Classifications MeSH