A novel gene editing lexicon strategy for the haemophilia community: Research plan for development and preliminary results.

CRISPR blood coagulation disorders gene editing haemophilia lexicon

Journal

Haemophilia : the official journal of the World Federation of Hemophilia
ISSN: 1365-2516
Titre abrégé: Haemophilia
Pays: England
ID NLM: 9442916

Informations de publication

Date de publication:
22 Oct 2024
Historique:
revised: 01 10 2024
received: 17 06 2024
accepted: 02 10 2024
medline: 22 10 2024
pubmed: 22 10 2024
entrez: 22 10 2024
Statut: aheadofprint

Résumé

Despite the progress in gene editing platforms like CRISPR/Cas9 with the potential to transform the standard of care for haemophilia, the language used to explain and discuss gene editing is not aligned across the haemophilia community. Here, we present the objective and rationale for developing a clear, consistent, and globally aligned gene editing lexicon to address these communication gaps. Effectively communicating complex gene editing concepts requires a clear and consistent vocabulary. Through collaboration with a diversity of haemophilia stakeholders, our main goal is to develop an accurate, informative lexicon which avoids overpromising or highly technical terminology. Using an innovative process, representatives from several patient and scientific haemophilia organizations and select biotechnology companies will develop and refine language concepts to be tested with approximately seventy participants across the United States of America, United Kingdom, and Germany. Participants will include lived experience experts (LEEs) and haematologists. The process will be overseen by the Lexicon Steering Committee of global experts from leading scientific and patient organizations in the haemophilia and gene editing fields. Initial feedback provided a robust foundation and rationale for building clear, consistent language around gene editing. This lexicon development framework will allow for increased understanding across the haemophilia community, including the development of valid informed consent and shared decision-making materials. Results provide important building blocks for stimuli development and highlight the need for a novel gene editing lexicon. In the next phase, language stimuli will be tested with LEEs and haematologists to better understand audience preferences and help shape the final lexicon.

Identifiants

pubmed: 39437171
doi: 10.1111/hae.15108
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Regeneron Pharmaceuticals, Inc.
Organisme : Intellia Therapeutics, Inc

Informations de copyright

© 2024 The Author(s). Haemophilia published by John Wiley & Sons Ltd.

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Auteurs

Cedric Hermans (C)

Cliniques universitaires saint-Luc, Université catholique de Louvain (UCLOuvain), Brussels, Belgium.

Leonard A Valentino (LA)

National Bleeding Disorders Foundation, New York City, New York, USA.
Hemophilia and Thrombophilia Center, Rush University, Chicago, Illinois, USA.

Courtney D Thornburg (CD)

Department of Pediatrics, University of California San Diego, La Jolla, California, USA.
Hemophilia and Thrombosis Treatment Cente, Rady Children's Hospital San Diego, San Diego, California, USA.

Carmen Unzu (C)

DNA&RNA Medicine Division, CIMA-Universidad de Navarra, IdisNA, Pamplona, Spain.

Mark A Kay (MA)

Pediatrics - Human Gene Therapy, Stanford University, Stanford, California, USA.

Flora Peyvandi (F)

Department of Pathophysiology and Transplantation, University of Milan, Milan, Italy.

Penni Smith (P)

Utah Center for Bleeding and Clotting Disorders, Salt Lake City, Utah, USA.

Wolfgang Miesbach (W)

Department of Haemostaseology, University Hospital Frankfurt, Frankfurt, Germany.

William McKeown (W)

Care of Elderly Medicine, Antrim Area Hospital, Antrim, Northern Ireland.

Glenn F Pierce (GF)

World Federation of Hemophilia, Montreal, Quebec, Canada.

Steven W Pipe (SW)

Pediatric Hematology-Oncology, University of Michigan, Ann Arbor, Michigan, USA.

Katarina Starcevic (K)

Language Strategy, Maslansky and Partners, New York City, New York, USA.

Monisha Pillai (M)

Language Strategy, Maslansky and Partners, New York City, New York, USA.

Micheala Jones (M)

Regeneron Pharmaceuticals, Inc., Tarrytown, New York, USA.

Megan Chiao (M)

Regeneron Pharmaceuticals, Inc., Tarrytown, New York, USA.

Ilia Antonino (I)

Intellia Therapeutics, Inc., Cambridge, Massachusetts, USA.

Craig Kessler (C)

Medicine and Pathology, Georgetown University, Washington, District of Columbia, USA.

Classifications MeSH