Scotopic Microperimetric Assessment of Rod Function in Stargardt Disease (SMART) Study: Design and Baseline Characteristics (Report No. 1).


Journal

Ophthalmic research
ISSN: 1423-0259
Titre abrégé: Ophthalmic Res
Pays: Switzerland
ID NLM: 0267442

Informations de publication

Date de publication:
2019
Historique:
received: 16 03 2018
accepted: 22 03 2018
pubmed: 26 6 2018
medline: 12 2 2019
entrez: 26 6 2018
Statut: ppublish

Résumé

To describe the study design and characteristics at first visit of participants in the longitudinal Scotopic Microperimetric Assessment of Rod Function in Stargardt Disease (SMART) study. Scotopic microperimetry (sMP) was performed in one designated study eye in a subset of participants with molecularly proven ABCA4-associated Stargardt disease (STGD1) enrolled in a multicenter natural history study (ProgStar). Study visits were every 6 months over a period ranging from 6 to 24 months, and also included fundus autofluorescence (FAF). SMART enrolled 118 participants (118 eyes). At the first visit of SMART, the mean sensitivity in mesopic microperimetry was 11.48 (±5.05; range 0.00-19.88) dB and in sMP 11.25 (±5.26; 0-19.25) dB. For FAF, all eyes had a lesion of decreased autofluorescence (mean lesion size 3.62 [±3.48; 0.10-21.46] mm2), and a total of 76 eyes (65.5%) had a lesion of definitely decreased autofluorescence with a mean lesion size of 3.46 (±3.60; 0.21-21.46) mm2. Rod function is impaired in STGD1 and can be assessed by sMP. Testing rod function may serve as a potential outcome measure for future clinical treatment trials. This is evaluated in the SMART study.

Identifiants

pubmed: 29940588
pii: 000488711
doi: 10.1159/000488711
pmc: PMC7175756
mid: NIHMS1573836
doi:

Types de publication

Journal Article Multicenter Study

Langues

eng

Sous-ensembles de citation

IM

Pagination

36-43

Subventions

Organisme : NEI NIH HHS
ID : R01 EY009076
Pays : United States

Informations de copyright

© 2018 S. Karger AG, Basel.

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Auteurs

Rupert W Strauss (RW)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.
Moorfields Eye Hospital NHS Foundation Trust, and UCL Institute of Ophthalmology, University College London, London, United Kingdom.
Department of Ophthalmology, Kepler University Clinic and Kepler University Linz, Linz, Austria.
Department of Ophthalmology, Medical University Graz, Graz, Austria.

Xiangrong Kong (X)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.
Department of Biostatistics and Epidemiology, University of Massachusetts-Amherst, Amherst, Massachusetts, USA.

Millena G Bittencourt (MG)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Alexander Ho (A)

Doheny Eye Institute, David Geffen School of Medicine at University of California, Los Angeles, Los Angeles, California, USA.

Anamika Jha (A)

Doheny Eye Institute, David Geffen School of Medicine at University of California, Los Angeles, Los Angeles, California, USA.

Etienne M Schönbach (EM)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Mohamed I Ahmed (MI)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Beatriz Muñoz (B)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Ann-Margret Ervin (AM)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Michel Michaelides (M)

Moorfields Eye Hospital NHS Foundation Trust, and UCL Institute of Ophthalmology, University College London, London, United Kingdom.

David G Birch (DG)

Retina Foundation of the Southwest, Dallas, Texas, USA.

José-Alain Sahel (JA)

Sorbonne Universités, University Pierre et Marie Curie (UPMC) Université de Paris 06, Institut National de la Santé et de la Recherche Médicale (INSERM), Centre National de la Recherche Scientifique (CNRS), Institut de la Vision, Centre Hospitalier National d'Ophtalmologie (CHNO) des Quinze-Vingts, Paris, France.

Janet S Sunness (JS)

Hoover Low Vision Rehabilitation Services, Greater Baltimore Medical Center and University of Maryland School of Medicine, Baltimore, Maryland, USA.

Eberhart Zrenner (E)

Center for Ophthalmology, Eberhard-Karls University Hospital, Tübingen, Germany.

Saghar Bagheri (S)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.
Department of Ophthalmology, Massachusetts Eye and Ear, Harvard Medical School, Boston, Massachusetts, USA.

Michael Ip (M)

Doheny Eye Institute, David Geffen School of Medicine at University of California, Los Angeles, Los Angeles, California, USA.

SriniVas Sadda (S)

Doheny Eye Institute, David Geffen School of Medicine at University of California, Los Angeles, Los Angeles, California, USA.

Sheila West (S)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USA.

Hendrik P N Scholl (HPN)

Wilmer Eye Institute, Johns Hopkins University, Baltimore, Maryland, USAHendrik.Scholl@usb.ch.
Department of Ophthalmology, University of Basel, Basel, SwitzerlandHendrik.Scholl@usb.ch.
Institute of Molecular and Clinical Ophthalmology Basel, Basel, SwitzerlandHendrik.Scholl@usb.ch.

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