Alternative splicing in a presenilin 2 variant associated with Alzheimer disease.


Journal

Annals of clinical and translational neurology
ISSN: 2328-9503
Titre abrégé: Ann Clin Transl Neurol
Pays: United States
ID NLM: 101623278

Informations de publication

Date de publication:
Apr 2019
Historique:
received: 16 10 2018
revised: 25 01 2019
accepted: 12 02 2019
entrez: 26 4 2019
pubmed: 26 4 2019
medline: 26 4 2019
Statut: epublish

Résumé

Autosomal-dominant familial Alzheimer disease (AD) is caused by by variants in presenilin 1 ( We combined genomic, neuropathological, clinical, and molecular techniques to characterize the PSEN2 K115Efs*11 variant in two families. Neuropathological and clinical evaluation confirmed the AD diagnosis in two individuals carrying the PSEN2 K115Efs*11 variant. A truncated transcript from the variant allele is detectable in patient fibroblasts while levels of wild-type These data suggest that PSEN2 K115Efs*11 is a likely pathogenic variant associated with AD. We uncovered novel

Identifiants

pubmed: 31020001
doi: 10.1002/acn3.755
pii: ACN3755
pmc: PMC6469258
doi:

Substances chimiques

Amyloid beta-Peptides 0
Amyloid beta-Protein Precursor 0
Peptide Fragments 0
Presenilin-1 0
Presenilin-2 0
amyloid beta-protein (1-40) 0
Amyloid Precursor Protein Secretases EC 3.4.-

Types de publication

Case Reports Journal Article

Langues

eng

Pagination

762-777

Subventions

Organisme : NIA NIH HHS
ID : P50 AG005136
Pays : United States
Organisme : NIA NIH HHS
ID : T32 AG052354
Pays : United States

Déclaration de conflit d'intérêts

The authors have no conflicts of interest to disclose.

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Auteurs

Jacquelyn E Braggin (JE)

Department of Neurology University of Washington Seattle Washington.

Stephanie A Bucks (SA)

Department of Neurology University of Washington Seattle Washington.

Meredith M Course (MM)

Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.

Carole L Smith (CL)

Department of Neurology University of Washington Seattle Washington.

Bryce Sopher (B)

Department of Neurology University of Washington Seattle Washington.

Leah Osnis (L)

Department of Neurology University of Washington Seattle Washington.

Kiel D Shuey (KD)

Department of Neurology University of Washington Seattle Washington.

Kimiko Domoto-Reilly (K)

Department of Neurology University of Washington Seattle Washington.

Christina Caso (C)

Department of Neurology University of Washington Seattle Washington.

Chizuru Kinoshita (C)

Department of Neurological Surgery University of Washington Seattle Washington.

Kathryn P Scherpelz (KP)

Department of Pathology University of Washington Seattle Washington.

Chloe Cross (C)

School of Medicine University of Utah Salt Lake City Utah.

Thomas Grabowski (T)

Department of Neurology University of Washington Seattle Washington.
Department of Radiology University of Washington Seattle Washington.

Seyyed H M Nik (SHM)

Genetics and Evolution University of Adelaide Adelaide South Australia.

Morgan Newman (M)

Genetics and Evolution University of Adelaide Adelaide South Australia.

Gwenn A Garden (GA)

Department of Neurology University of Washington Seattle Washington.
Department of Pathology University of Washington Seattle Washington.

James B Leverenz (JB)

Cleveland Lou Ruvo Center for Brain Health Cleveland OH.

Debby Tsuang (D)

Department of Neurology University of Washington Seattle Washington.
Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.
Department of Psychiatry & Behavioral Sciences University of Washington Seattle Washington.
Geriatric Research, Education, and Clinical Center VA Puget Sound Health Care System Seattle Washington.

Caitlin Latimer (C)

Department of Pathology University of Washington Seattle Washington.

Luis F Gonzalez-Cuyar (LF)

Department of Pathology University of Washington Seattle Washington.

Christopher Dirk Keene (CD)

Department of Pathology University of Washington Seattle Washington.

Richard S Morrison (RS)

Department of Neurological Surgery University of Washington Seattle Washington.

Kristoffer Rhoads (K)

Department of Neurology University of Washington Seattle Washington.

Ellen M Wijsman (EM)

Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.
Univeristy of Washington Department of Biostatistics Seattle Washington.

Michael O Dorschner (MO)

Department of Pathology University of Washington Seattle Washington.
Department of Psychiatry & Behavioral Sciences University of Washington Seattle Washington.
UW Medicine Center for Precision Diagnostics University of Washington Seattle Washington.

Michael Lardelli (M)

Genetics and Evolution University of Adelaide Adelaide South Australia.

Jessica E Young (JE)

Department of Pathology University of Washington Seattle Washington.

Paul N Valdmanis (PN)

Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.

Thomas D Bird (TD)

Department of Neurology University of Washington Seattle Washington.
Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.
Geriatric Research, Education, and Clinical Center VA Puget Sound Health Care System Seattle Washington.

Suman Jayadev (S)

Department of Neurology University of Washington Seattle Washington.
Division of Medical Genetics Department of Medicine University of Washington Seattle Washington.

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Classifications MeSH