Clinical Variability in P102L Gerstmann-Sträussler-Scheinker Syndrome.


Journal

Annals of neurology
ISSN: 1531-8249
Titre abrégé: Ann Neurol
Pays: United States
ID NLM: 7707449

Informations de publication

Date de publication:
11 2019
Historique:
received: 05 03 2019
revised: 05 08 2019
accepted: 07 08 2019
pubmed: 10 8 2019
medline: 9 4 2020
entrez: 10 8 2019
Statut: ppublish

Résumé

Gerstmann-Sträussler-Scheinker syndrome (GSS) with the P102L mutation is a rare genetic prion disease caused by a pathogenic mutation at codon 102 in the prion protein gene. Cluster analysis encompassing data from 7 Czech patients and 87 published cases suggests the existence of 4 clinical phenotypes (typical GSS, GSS with areflexia and paresthesia, pure dementia GSS, and Creutzfeldt-Jakob disease-like GSS); GSS may be more common than previously estimated. In making a clinical diagnosis or progression estimates of GSS, magnetic resonance imaging and real-time quaking-induced conversion may be helpful, but the results should be evaluated with respect to the overall clinical context. ANN NEUROL 2019;86:643-652.

Identifiants

pubmed: 31397917
doi: 10.1002/ana.25579
doi:

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

643-652

Subventions

Organisme : Charles University
ID : Progress Q27/LF1
Pays : International
Organisme : Charles University
ID : Q28/LF1
Pays : International
Organisme : Charles University
ID : Q35/LF3
Pays : International
Organisme : Charles University
ID : GAUK 113115
Pays : International
Organisme : Ministry of Health
ID : AZV NV180400179
Pays : International
Organisme : Ministry of Health, Czech Republic
ID : VFN64165
Pays : International
Organisme : Ministry of Health, Czech Republic
ID : DZ1716
Pays : International
Organisme : Ministry of Health, Czech Republic
ID : TN 64190
Pays : International
Organisme : Ministry of Health, Czech Republic
ID : DZ1916
Pays : International
Organisme : Ministry of Health, Czech Republic
ID : FNM64203
Pays : International

Informations de copyright

© 2019 American Neurological Association.

Références

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Auteurs

Adam Tesar (A)

The Department of Neurology and Center of Clinical Neuroscience, First Faculty of Medicine, Charles University, and General University Hospital, Prague.

Radoslav Matej (R)

Department of Pathology and Molecular Medicine, Third Faculty of Medicine, Charles University, and Thomayer Hospital, Prague.
Department of Pathology, First Faculty of Medicine, Charles University, and General University Hospital, Prague.
Department of Pathology, Third Faculty of Medicine, Charles University, and Kralovske Vinohrady University Hospital, Prague.

Jaromir Kukal (J)

Faculty of Nuclear Sciences and Physical Engineering, Czech Technical University, Prague.

Silvie Johanidesova (S)

Department of Neurology, Third Faculty of Medicine, Charles University, and Thomayer Hospital, Prague.

Irena Rektorova (I)

Applied Neuroscience Research Group, Central European Institute of Technology, Masaryk University, Brno.
Department of Neurology, Faculty of Medicine, Masaryk University, and Saint Anne's University Hospital, Brno.

Martin Vyhnalek (M)

Department of Neurology, Second Faculty of Medicine, Charles University, and Motol University Hospital, Prague.
International Clinical Research Center, St Anne's University Hospital Brno, Brno.

Jiri Keller (J)

The Department of Neurology and Center of Clinical Neuroscience, First Faculty of Medicine, Charles University, and General University Hospital, Prague.
Department of Radiology, Na Homolce Hospital, Prague.

Ilona Eliasova (I)

Applied Neuroscience Research Group, Central European Institute of Technology, Masaryk University, Brno.
Department of Neurology, Faculty of Medicine, Masaryk University, and Saint Anne's University Hospital, Brno.

Eva Parobkova (E)

Department of Pathology and Molecular Medicine, Third Faculty of Medicine, Charles University, and Thomayer Hospital, Prague.
Department of Pathology, Third Faculty of Medicine, Charles University, and Kralovske Vinohrady University Hospital, Prague.

Magdalena Smetakova (M)

Department of Pathology and Molecular Medicine, Third Faculty of Medicine, Charles University, and Thomayer Hospital, Prague.
Department of Pathology, Third Faculty of Medicine, Charles University, and Kralovske Vinohrady University Hospital, Prague.

Zuzana Musova (Z)

Department of Biology and Medical Genetics, Second Faculty of Medicine, Charles University, and Motol University Hospital, Prague, Czech Republic.

Robert Rusina (R)

The Department of Neurology and Center of Clinical Neuroscience, First Faculty of Medicine, Charles University, and General University Hospital, Prague.
Department of Neurology, Third Faculty of Medicine, Charles University, and Thomayer Hospital, Prague.

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