Managing the Unusual Causes of Fetal Anemia.


Journal

Fetal diagnosis and therapy
ISSN: 1421-9964
Titre abrégé: Fetal Diagn Ther
Pays: Switzerland
ID NLM: 9107463

Informations de publication

Date de publication:
2020
Historique:
received: 25 10 2018
accepted: 18 06 2019
pubmed: 11 9 2019
medline: 18 11 2020
entrez: 11 9 2019
Statut: ppublish

Résumé

Rare causes of fetal anemia requiring intrauterine transfusion (IUT) are challenging for fetal medicine specialists. The aim of this study was to describe the perinatal patterns and prognosis in a consecutive series of fetuses transfused for fetal anemia of rare or unknown etiology, and to propose a protocol of investigation for fetal anemia of undetermined cause and for the management of subsequent pregnancies. We conducted a retrospective descriptive study on fetuses transfused for severe anemia of rare or unknown etiology managed in our national referral center (Centre National de Référence d'Hémobiologie Périnatale) and born between 2010 and 2017. During the study period, 584 IUT were performed in 253 fetuses. Among those IUT, 23 (3.9%) were performed for a rare or unknown cause of anemia in 13 fetuses (5.1% of transfused fetuses). The median gestational age at diagnosis was 26 weeks of gestation (WG; range 21-33). Hemoglobin levels ranged from 1.6 to 9.1 g/dL (0.18-0.83 multiples of median) before the first IUT. The fetuses received between 1 and 6 IUT (39% received at least 2 IUT). The definitive etiologies for central anemia were: congenital syphilis, neonatal poikilocytosis, type II congenital dyserythropoietic anemia (CDA), and neonatal hemochromatosis. There was 1 case with suspected type I CDA and 1 with suspected Diamond-Blackfan anemia. There was 1 case of peripheral anemia, secondary to cerebral hemorrhages of different ages, related to a variant of the COL4A1 gene. In 6 fetuses corresponding to 4 mothers, no precise diagnosis was found despite a complete workup. In our series, there were 8 live births, 4 terminations of pregnancy, and 1 intrauterine fetal death. Fetal anemia of rare or unknown diagnosis represents 5% of all transfused fetuses in our cohort. Fetal and neonatal anemias can be recurrent in further pregnancies, with variable expressivity.

Sections du résumé

BACKGROUND BACKGROUND
Rare causes of fetal anemia requiring intrauterine transfusion (IUT) are challenging for fetal medicine specialists.
OBJECTIVES OBJECTIVE
The aim of this study was to describe the perinatal patterns and prognosis in a consecutive series of fetuses transfused for fetal anemia of rare or unknown etiology, and to propose a protocol of investigation for fetal anemia of undetermined cause and for the management of subsequent pregnancies.
METHOD METHODS
We conducted a retrospective descriptive study on fetuses transfused for severe anemia of rare or unknown etiology managed in our national referral center (Centre National de Référence d'Hémobiologie Périnatale) and born between 2010 and 2017.
RESULTS RESULTS
During the study period, 584 IUT were performed in 253 fetuses. Among those IUT, 23 (3.9%) were performed for a rare or unknown cause of anemia in 13 fetuses (5.1% of transfused fetuses). The median gestational age at diagnosis was 26 weeks of gestation (WG; range 21-33). Hemoglobin levels ranged from 1.6 to 9.1 g/dL (0.18-0.83 multiples of median) before the first IUT. The fetuses received between 1 and 6 IUT (39% received at least 2 IUT). The definitive etiologies for central anemia were: congenital syphilis, neonatal poikilocytosis, type II congenital dyserythropoietic anemia (CDA), and neonatal hemochromatosis. There was 1 case with suspected type I CDA and 1 with suspected Diamond-Blackfan anemia. There was 1 case of peripheral anemia, secondary to cerebral hemorrhages of different ages, related to a variant of the COL4A1 gene. In 6 fetuses corresponding to 4 mothers, no precise diagnosis was found despite a complete workup. In our series, there were 8 live births, 4 terminations of pregnancy, and 1 intrauterine fetal death.
CONCLUSIONS CONCLUSIONS
Fetal anemia of rare or unknown diagnosis represents 5% of all transfused fetuses in our cohort. Fetal and neonatal anemias can be recurrent in further pregnancies, with variable expressivity.

Identifiants

pubmed: 31505487
pii: 000501554
doi: 10.1159/000501554
doi:

Substances chimiques

Biomarkers 0
Fetal Hemoglobin 9034-63-3

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

156-164

Informations de copyright

© 2019 S. Karger AG, Basel.

Auteurs

Emeline Maisonneuve (E)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France, emelinem@yahoo.com.
Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France, emelinem@yahoo.com.

Imane Ben M'Barek (I)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France.

Thierry Leblanc (T)

Department of Clinic Hematology, Hôpital Robert-Debré, Paris, France.

Lydie Da Costa (L)

Department of Biologic Hematology, Hôpital Robert-Debré, Paris, France.

Stéphanie Friszer (S)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France.
Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France.

Françoise Pernot (F)

Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France.

Pauline Thomas (P)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France.
Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France.

Vanina Castaigne (V)

Department of Obstetrics and Gynecology, Hôpital Intercommunal de Créteil, Créteil, France.

Cécile Toly N'Dour (C)

Department of Immunohematology, Centre National de Référence en Hémobiologie Périnatale (CNRHP) Biologique, Hôpital Saint-Antoine, Paris, France.

Agnès Mailloux (A)

Department of Immunohematology, Centre National de Référence en Hémobiologie Périnatale (CNRHP) Biologique, Hôpital Saint-Antoine, Paris, France.

Anne Cortey (A)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France.
Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France.

Jean-Marie Jouannic (JM)

Department of Fetal Medicine, Hôpital Trousseau, Paris, France.
Centre National de Référence en Hémobiologie Périnatale (CNRHP) Clinique, Hôpital Trousseau, Paris, France.

Articles similaires

[Redispensing of expensive oral anticancer medicines: a practical application].

Lisanne N van Merendonk, Kübra Akgöl, Bastiaan Nuijen
1.00
Humans Antineoplastic Agents Administration, Oral Drug Costs Counterfeit Drugs

Smoking Cessation and Incident Cardiovascular Disease.

Jun Hwan Cho, Seung Yong Shin, Hoseob Kim et al.
1.00
Humans Male Smoking Cessation Cardiovascular Diseases Female
Humans United States Aged Cross-Sectional Studies Medicare Part C
1.00
Humans Yoga Low Back Pain Female Male

Classifications MeSH