Calpain inhibitor and ibudilast rescue β cell functions in a cellular model of Wolfram syndrome.


Journal

Proceedings of the National Academy of Sciences of the United States of America
ISSN: 1091-6490
Titre abrégé: Proc Natl Acad Sci U S A
Pays: United States
ID NLM: 7505876

Informations de publication

Date de publication:
21 07 2020
Historique:
pubmed: 8 7 2020
medline: 15 9 2020
entrez: 8 7 2020
Statut: ppublish

Résumé

Wolfram syndrome is a rare multisystem disease characterized by childhood-onset diabetes mellitus and progressive neurodegeneration. Most cases are attributed to pathogenic variants in a single gene, Wolfram syndrome 1 (

Identifiants

pubmed: 32632005
pii: 2007136117
doi: 10.1073/pnas.2007136117
pmc: PMC7382278
doi:

Substances chimiques

Antineoplastic Agents 0
Calmodulin-Binding Proteins 0
Cysteine Proteinase Inhibitors 0
Glycoproteins 0
Membrane Proteins 0
Pyridines 0
WFS1 protein, rat 0
calpain inhibitors 0
Receptor, Insulin EC 2.7.10.1
ibudilast M0TTH61XC5
Calcium SY7Q814VUP

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

17389-17398

Subventions

Organisme : NCATS NIH HHS
ID : UH3 TR002065
Pays : United States
Organisme : NCATS NIH HHS
ID : UL1 TR001863
Pays : United States
Organisme : NIDDK NIH HHS
ID : F30 DK111070
Pays : United States
Organisme : NIDDK NIH HHS
ID : P01 DK057751
Pays : United States
Organisme : NIDDK NIH HHS
ID : P60 DK020579
Pays : United States
Organisme : NIDDK NIH HHS
ID : P30 DK020579
Pays : United States
Organisme : NIDDK NIH HHS
ID : R01 DK112921
Pays : United States
Organisme : NCATS NIH HHS
ID : UH2 TR002065
Pays : United States

Déclaration de conflit d'intérêts

Competing interest statement: B.E.E. is a cofounder of Osmol Therapeutics, a company that is targeting NCS1 for therapeutic purposes.

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Auteurs

Lien D Nguyen (LD)

Department of Pharmacology, Yale University, New Haven, CT 06520.
Interdepartmental Neuroscience Program, Yale University, New Haven, CT 06520.

Tom T Fischer (TT)

Department of Pharmacology, Yale University, New Haven, CT 06520.
Institute of Pharmacology, University of Heidelberg, 69117 Heidelberg, Germany.

Damien Abreu (D)

Department of Medicine, Division of Endocrinology, Metabolism, and Lipid Research, Washington University School of Medicine, St. Louis, MO 63110.
Medical Scientist Training Program, Washington University School of Medicine, St. Louis, MO 63110.

Alfredo Arroyo (A)

Department of Pharmacology, Yale University, New Haven, CT 06520.

Fumihiko Urano (F)

Department of Medicine, Division of Endocrinology, Metabolism, and Lipid Research, Washington University School of Medicine, St. Louis, MO 63110.
Department of Pathology and Immunology, Washington University School of Medicine, St. Louis, MO 63110.

Barbara E Ehrlich (BE)

Department of Pharmacology, Yale University, New Haven, CT 06520; barbara.ehrlich@yale.edu.
Interdepartmental Neuroscience Program, Yale University, New Haven, CT 06520.

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