Inborn error of immunity as the cause of recurrent pericarditis.


Journal

BMJ case reports
ISSN: 1757-790X
Titre abrégé: BMJ Case Rep
Pays: England
ID NLM: 101526291

Informations de publication

Date de publication:
19 May 2021
Historique:
entrez: 20 5 2021
pubmed: 21 5 2021
medline: 22 5 2021
Statut: epublish

Résumé

Familial Mediterranean fever (FMF) is an autoinflammatory disease caused by a pyrin dysfunction, leading to uncontrolled interleukin-1 production that triggers the attacks. Here we report a case of a 36-year-old female patient repeatedly admitted to the cardiology ward with recurrent episodes of pericarditis, with intervals of 1 and 2 months between the episodes. During the attacks, chest pain and fever were the only symptoms. Following the administration of steroids and non-steroidal anti-inflammatory drugs, the patient became afebrile. She also had lymphoma and thyroid carcinoma in anamnesis essential for differential diagnosis. Laboratory tests for infection and autoimmune disease were all negative, and the positron emission tomography-CT scan did not reveal lymphoma relapse. Genetic testing revealed a mutation in the

Identifiants

pubmed: 34011672
pii: 14/5/e241449
doi: 10.1136/bcr-2020-241449
pmc: PMC8137168
pii:
doi:

Substances chimiques

MEFV protein, human 0
Pyrin 0

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© BMJ Publishing Group Limited 2021. No commercial re-use. See rights and permissions. Published by BMJ.

Déclaration de conflit d'intérêts

Competing interests: None declared.

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Auteurs

Zane Lucane (Z)

Faculty of Residency, Riga Stradins University, Riga, Latvia.

Dace Freidenberga (D)

Paul Stradins Clinical University Hospital, Riga, Latvia.

Natalja Kurjane (N)

Paul Stradins Clinical University Hospital, Riga, Latvia natalja.kurjane@rsu.lv.
Department of Biology and Microbiology, Riga Stradins University, Riga, Latvia.

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