Efficacy and safety of larotrectinib in TRK fusion-positive primary central nervous system tumors.


Journal

Neuro-oncology
ISSN: 1523-5866
Titre abrégé: Neuro Oncol
Pays: England
ID NLM: 100887420

Informations de publication

Date de publication:
01 06 2022
Historique:
pubmed: 2 12 2021
medline: 7 6 2022
entrez: 1 12 2021
Statut: ppublish

Résumé

Larotrectinib is a first-in-class, highly selective tropomyosin receptor kinase (TRK) inhibitor approved to treat adult and pediatric patients with TRK fusion-positive cancer. The aim of this study was to evaluate the efficacy and safety of larotrectinib in patients with TRK fusion-positive primary central nervous system (CNS) tumors. Patients with TRK fusion-positive primary CNS tumors from two clinical trials (NCT02637687, NCT02576431) were identified. The primary endpoint was investigator-assessed objective response rate (ORR). As of July 2020, 33 patients with TRK fusion-positive CNS tumors were identified (median age: 8.9 years; range: 1.3-79.0). The most common histologies were high-grade glioma (HGG; n = 19) and low-grade glioma (LGG; n = 8). ORR was 30% (95% confidence interval [CI]: 16-49) for all patients. The 24-week disease control rate was 73% (95% CI: 54-87). Twenty-three of 28 patients (82%) with measurable disease had tumor shrinkage. The 12-month rates for duration of response, progression-free survival, and overall survival were 75% (95% CI: 45-100), 56% (95% CI: 38-74), and 85% (95% CI: 71-99), respectively. Median time to response was 1.9 months (range 1.0-3.8 months). Duration of treatment ranged from 1.2-31.3+ months. Treatment-related adverse events were reported for 20 patients, with grade 3-4 in 3 patients. No new safety signals were identified. In patients with TRK fusion-positive CNS tumors, larotrectinib demonstrated rapid and durable responses, high disease control rate, and a favorable safety profile.

Sections du résumé

BACKGROUND
Larotrectinib is a first-in-class, highly selective tropomyosin receptor kinase (TRK) inhibitor approved to treat adult and pediatric patients with TRK fusion-positive cancer. The aim of this study was to evaluate the efficacy and safety of larotrectinib in patients with TRK fusion-positive primary central nervous system (CNS) tumors.
METHODS
Patients with TRK fusion-positive primary CNS tumors from two clinical trials (NCT02637687, NCT02576431) were identified. The primary endpoint was investigator-assessed objective response rate (ORR).
RESULTS
As of July 2020, 33 patients with TRK fusion-positive CNS tumors were identified (median age: 8.9 years; range: 1.3-79.0). The most common histologies were high-grade glioma (HGG; n = 19) and low-grade glioma (LGG; n = 8). ORR was 30% (95% confidence interval [CI]: 16-49) for all patients. The 24-week disease control rate was 73% (95% CI: 54-87). Twenty-three of 28 patients (82%) with measurable disease had tumor shrinkage. The 12-month rates for duration of response, progression-free survival, and overall survival were 75% (95% CI: 45-100), 56% (95% CI: 38-74), and 85% (95% CI: 71-99), respectively. Median time to response was 1.9 months (range 1.0-3.8 months). Duration of treatment ranged from 1.2-31.3+ months. Treatment-related adverse events were reported for 20 patients, with grade 3-4 in 3 patients. No new safety signals were identified.
CONCLUSIONS
In patients with TRK fusion-positive CNS tumors, larotrectinib demonstrated rapid and durable responses, high disease control rate, and a favorable safety profile.

Identifiants

pubmed: 34850167
pii: 6444692
doi: 10.1093/neuonc/noab274
pmc: PMC9159442
doi:

Substances chimiques

Antineoplastic Agents 0
Oncogene Proteins, Fusion 0
Protein Kinase Inhibitors 0
Pyrazoles 0
Pyrimidines 0
larotrectinib PF9462I9HX

Banques de données

ClinicalTrials.gov
['NCT02637687', 'NCT02576431']

Types de publication

Clinical Trial Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

997-1007

Subventions

Organisme : NCI NIH HHS
ID : P30 CA008748
Pays : United States
Organisme : Department of Health
Pays : United Kingdom

Commentaires et corrections

Type : CommentIn

Informations de copyright

© The Author(s) 2021. Published by Oxford University Press on behalf of the Society for Neuro-Oncology.

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Auteurs

François Doz (F)

SIREDO Oncology Center (Care, Innovation and Research for Children and AYA with Cancer), Institut Curie and Université de Paris, Paris, France.

Cornelis M van Tilburg (CM)

Hopp Children's Cancer Center Heidelberg (KiTZ), Heidelberg University Hospital and German Cancer Research Center (DKFZ), Heidelberg, Germany.

Birgit Geoerger (B)

Gustave Roussy Cancer Center, Department of Pediatric and Adolescent Oncology, Université Paris-Saclay, INSERM U1015, Villejuif, France.

Martin Højgaard (M)

Department of Oncology, Righospitalet , Copenhagen, Denmark.

Ingrid Øra (I)

Department of Pediatric Oncology, Skåne University Hospital, Lund & Karolinska University Hospital, Stockholm, Sweden.

Valentina Boni (V)

START Madrid CIOCC, HM Hospital Universitario Sanchinarro, Madrid, Spain.

Michael Capra (M)

Paediatric Oncology, Children's Health Ireland, Crumlin, Dublin, Ireland.

Julia Chisholm (J)

Children and Young People's Unit, Royal Marsden Hospital, Surrey, UK.

Hyun Cheol Chung (HC)

Yonsei Cancer Center, Yonsei University College of Medicine, Seoul, South Korea.

Steven G DuBois (SG)

Department of Pediatrics, Dana-Farber/Boston Children's Cancer and Blood Disorders Center, Boston, Massachusetts, USA.

Soledad Gallego-Melcon (S)

Vall d'Hebron Children's Hospital, Barcelona, Spain.

Nicolas U Gerber (NU)

Department of Oncology, University Children's Hospital, Zurich, Switzerland.

Hiroaki Goto (H)

Division of Hematology/Oncology, Kanagawa Children's Medical Center, Yokohama, Japan.

Juneko E Grilley-Olson (JE)

Lineberger Cancer Center, University of North Carolina Hospitals, Chapel Hill, North Carolina, USA.

Jordan R Hansford (JR)

Royal Children's Hospital Melbourne, Murdoch Children's Research Institute, University of Melbourne, Melbourne, Australia.

David S Hong (DS)

Department of Investigational Cancer Therapeutics, The University of Texas MD Anderson Cancer Center, Houston, Texas, USA.

Antoine Italiano (A)

Department of Medical Oncology, Institute Bergonie, Bordeaux, France.

Hyoung Jin Kang (HJ)

Department of Pediatrics, Cancer Research Institute, Seoul National University College of Medicine, Seoul, South Korea.

Karsten Nysom (K)

Department of Pediatrics and Adolescent Medicine, University Hospital Rigshospitalet, Copenhagen, Denmark.

Anne Thorwarth (A)

Department of Pediatric Oncology/Hematology, Charité-Universitätsmedizin Berlin, Berlin, Germany.

Joanna Stefanowicz (J)

Department of Paediatrics, Hematology and Oncology, Faculty of Medicine, Medical University of Gdansk, Gdansk, Poland.

Makoto Tahara (M)

Department of Head and Neck Medical Oncology, National Cancer Center Hospital East, Kashiwa, Japan.

David S Ziegler (DS)

Kids Cancer Centre, Sydney Children's Hospital, Randwick, Australia.
School of Women's and Children's Health, University of New South Wales Sydney, Sydney, Australia.

Igor T Gavrilovic (IT)

Department of Neurology, Memorial Sloan Kettering Cancer Center, New York, New York, USA.

Ricarda Norenberg (R)

Chrestos Concept GmbH & Co. KG, Essen, Germany.

Laura Dima (L)

Bayer Consumer Care AG, Basel, Switzerland.

Esther De La Cuesta (E)

Bayer HealthCare Pharmaceuticals, Whippany, New Jersey, USA.

Theodore W Laetsch (TW)

Department of Pediatrics and Harold C. Simmons Comprehensive Cancer Center, University of Texas Southwestern Medical Center/Children's Health, Dallas, Texas, USA.

Alexander Drilon (A)

Department of Medicine, Memorial Sloan Kettering Cancer Center, New York, New York, USA (A.D.); Department of Medicine, Weill Cornell Medical College, New York, New York, USA.

Sebastien Perreault (S)

Department of Neurosciences, CHU Sainte Justine, Montreal, Quebec, Canada.

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Classifications MeSH