SMARCA4 biology in alveolar rhabdomyosarcoma.


Journal

Oncogene
ISSN: 1476-5594
Titre abrégé: Oncogene
Pays: England
ID NLM: 8711562

Informations de publication

Date de publication:
03 2022
Historique:
received: 02 04 2021
accepted: 20 01 2022
revised: 21 12 2021
pubmed: 31 1 2022
medline: 20 4 2022
entrez: 30 1 2022
Statut: ppublish

Résumé

Rhabdomyosarcoma (RMS) is the most common soft tissue sarcoma in children and phenocopies a muscle precursor that fails to undergo terminal differentiation. The alveolar subtype (ARMS) has the poorest prognosis and represents the greatest unmet medical need for RMS. Emerging evidence supports the role of epigenetic dysregulation in RMS. Here we show that SMARCA4/BRG1, an ATP-dependent chromatin remodeling enzyme of the SWI/SNF complex, is prominently expressed in primary tumors from ARMS patients and cell cultures. Our validation studies for a CRISPR screen of 400 epigenetic targets identified SMARCA4 as a unique factor for long-term (but not short-term) tumor cell survival in ARMS. A SMARCA4/SMARCA2 protein degrader (ACBI-1) demonstrated similar long-term tumor cell dependence in vitro and in vivo. These results credential SMARCA4 as a tumor cell dependency factor and a therapeutic target in ARMS.

Identifiants

pubmed: 35094009
doi: 10.1038/s41388-022-02205-0
pii: 10.1038/s41388-022-02205-0
pmc: PMC9985831
mid: NIHMS1787372
doi:

Substances chimiques

Nuclear Proteins 0
Transcription Factors 0
SMARCA4 protein, human EC 3.6.1.-
DNA Helicases EC 3.6.4.-

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

1647-1656

Subventions

Organisme : NCI NIH HHS
ID : P01 CA013106
Pays : United States
Organisme : NCI NIH HHS
ID : P30 CA045508
Pays : United States
Organisme : NCI NIH HHS
ID : R01 CA258720
Pays : United States
Organisme : NCI NIH HHS
ID : R21 CA245859
Pays : United States

Informations de copyright

© 2022. The Author(s), under exclusive licence to Springer Nature Limited.

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Auteurs

Narendra Bharathy (N)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.
Gene Therapy Program, Perelman School of Medicine, University of Pennsylvania, Philadelphia, PA, 19104, USA.

Megan M Cleary (MM)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Jin-Ah Kim (JA)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Kiyo Nagamori (K)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Kenneth A Crawford (KA)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Eric Wang (E)

Cold Spring Harbor Laboratory, Cold Spring Harbor, NY, 11724, USA.

Debarya Saha (D)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.
CSIR-CCMB, Uppal Road, Hyderabad, 500007, India.

Teagan P Settelmeyer (TP)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Reshma Purohit (R)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Damianos Skopelitis (D)

Cold Spring Harbor Laboratory, Cold Spring Harbor, NY, 11724, USA.

Kenneth Chang (K)

Cold Spring Harbor Laboratory, Cold Spring Harbor, NY, 11724, USA.

Jessica A Doran (JA)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

C Ward Kirschbaum (CW)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Suriya Bharathy (S)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Davis W Crews (DW)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Matthew E Randolph (ME)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Anthony N Karnezis (AN)

University of California C Davis Medical Center, Sacramento, CA, 95817, USA.
British Columbia Cancer Research Center, Vancouver, BC, V5Z 1L3, Canada.

Lisa Hudson-Price (L)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA.

Jyotsna Dhawan (J)

CSIR-CCMB, Uppal Road, Hyderabad, 500007, India.

Joel E Michalek (JE)

Department of Epidemiology and Biostatistics, University of Texas Health Science Center, San Antonio, TX, 78229, USA.

Alessio Ciulli (A)

Division of Biological Chemistry and Drug Discovery, School of Life Sciences, University of Dundee, Dundee, UK. a.ciulli@dundee.ac.uk.

Christopher R Vakoc (CR)

Cold Spring Harbor Laboratory, Cold Spring Harbor, NY, 11724, USA.

Charles Keller (C)

Children's Cancer Therapy Development Institute, Beaverton, OR, 97005, USA. charles@cc-tdi.org.

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Classifications MeSH