Sustained effectiveness of elexacaftor-tezacaftor-ivacaftor in lung transplant candidates with cystic fibrosis.


Journal

Journal of cystic fibrosis : official journal of the European Cystic Fibrosis Society
ISSN: 1873-5010
Titre abrégé: J Cyst Fibros
Pays: Netherlands
ID NLM: 101128966

Informations de publication

Date de publication:
05 2022
Historique:
received: 08 11 2021
revised: 29 12 2021
accepted: 20 01 2022
pubmed: 7 2 2022
medline: 3 6 2022
entrez: 6 2 2022
Statut: ppublish

Résumé

Elexacaftor-tezacaftor-ivacaftor induces rapid clinical improvement in patients with cystic fibrosis (CF) and advanced pulmonary disease, often leading to suspend the indication for lung transplantation. Yet no long-term data is available in lung transplant candidates. Lung transplant candidates (defined as being waitlisted for lung transplantation or considered for listing within 3 months) who have initiated elexacaftor-tezacaftor-ivacaftor were identified in the French cohort of patients with CF and advanced pulmonary disease. Patients were prospectively followed to evaluate treatment safety and effectiveness from initiation to July 20th, 2021. Among the 331 patients with advanced CF pulmonary disease who initiated elexacaftor-tezacaftor-ivacaftor, 65 were lung transplant candidates (17 listed for transplantation, 48 considered for listing within 3 months). Median [IQR] follow-up time was 363 [329; 377] days. At the end of the follow-up period, two patients were transplanted five and 11 days following treatment initiation, two were listed for transplantation, and 61 no longer met transplantation criteria. Improvement in percent predicted forced expiratory volume in 1 s (ppFEV In lung transplant candidates eligible for elexacaftor-tezacaftor-ivacaftor, the rapid improvement following initiation of treatment persisted over one year with a reduction in treatment burden and lung transplantation could be safely deferred in most patients.

Sections du résumé

BACKGROUND
Elexacaftor-tezacaftor-ivacaftor induces rapid clinical improvement in patients with cystic fibrosis (CF) and advanced pulmonary disease, often leading to suspend the indication for lung transplantation. Yet no long-term data is available in lung transplant candidates.
METHODS
Lung transplant candidates (defined as being waitlisted for lung transplantation or considered for listing within 3 months) who have initiated elexacaftor-tezacaftor-ivacaftor were identified in the French cohort of patients with CF and advanced pulmonary disease. Patients were prospectively followed to evaluate treatment safety and effectiveness from initiation to July 20th, 2021.
RESULTS
Among the 331 patients with advanced CF pulmonary disease who initiated elexacaftor-tezacaftor-ivacaftor, 65 were lung transplant candidates (17 listed for transplantation, 48 considered for listing within 3 months). Median [IQR] follow-up time was 363 [329; 377] days. At the end of the follow-up period, two patients were transplanted five and 11 days following treatment initiation, two were listed for transplantation, and 61 no longer met transplantation criteria. Improvement in percent predicted forced expiratory volume in 1 s (ppFEV
CONCLUSION
In lung transplant candidates eligible for elexacaftor-tezacaftor-ivacaftor, the rapid improvement following initiation of treatment persisted over one year with a reduction in treatment burden and lung transplantation could be safely deferred in most patients.

Identifiants

pubmed: 35123901
pii: S1569-1993(22)00032-7
doi: 10.1016/j.jcf.2022.01.012
pii:
doi:

Substances chimiques

Aminophenols 0
Benzodioxoles 0
Chloride Channel Agonists 0
Indoles 0
Pyrazoles 0
Pyridines 0
Pyrrolidines 0
Quinolones 0
tezacaftor 0
Cystic Fibrosis Transmembrane Conductance Regulator 126880-72-6
ivacaftor 1Y740ILL1Z
elexacaftor RRN67GMB0V

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

489-496

Informations de copyright

Copyright © 2022 European Cystic Fibrosis Society. Published by Elsevier B.V. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of Competing Interest All authors declare no conflicts of interest related to the work submitted for publication.

Auteurs

Clémence Martin (C)

Université de Paris, Institut Cochin, Inserm U1016, Paris, France; Respiratory Medicine and Cystic Fibrosis National Reference Center, Cochin Hospital, Assistance Publique Hôpitaux de Paris (AP-HP), Paris, France; ERN-Lung CF network, Frankfurt, Germany.

Martine Reynaud-Gaubert (M)

Department of Respiratory Medicine and Lung Transplantation, Adult Cystic Fibrosis Center Aix Marseille Université, APHM, Hôpital Nord, Marseille, France.

Rebecca Hamidfar (R)

Service Hospitalo-Universitaire de Pneumologie et Physiologie, Pôle Thorax et Vaisseaux, Centre Hospitalier Universitaire de Grenoble-Alpes, La Tronche, France.

Isabelle Durieu (I)

Centre de référence Adulte de la Mucoviscidose, Service de médecine interne, Hospices Civils de Lyon, Pierre Bénite, France; Université de Lyon, Équipe d'Accueil Health Services and Performance Research (HESPER) 7425, Lyon, France.

Marlène Murris-Espin (M)

Cystic Fibrosis Center Service de Pneumologie Pôle des Voies Respiratoires, Hôpital Larrey CHU de Toulouse, Toulouse, France.

Isabelle Danner-Boucher (I)

Service de Pneumologie, L'Institut Du Thorax, CHU Nantes, Nantes, France.

Raphaël Chiron (R)

Cystic Fibrosis Center, Hôpital Arnaud de Villeneuve, Centre Hospitalier Universitaire de Montpellier, Montpellier, France.

Sylvie Leroy (S)

Pulmonology Department, Université Côte d'Azur, Centre Hospitalier Universitaire de Nice, Fédération Hospitalo-Universitaire OncoAge, CNRS, Inserm, Institute for Research on Cancer and Aging Nice Team 3, Nice, France.

Benoit Douvry (B)

Service de Pneumologie, Centre Hospitalier Intercommunal, FHU SENEC, Créteil, France.

Dominique Grenet (D)

CRCM - Centre de Transplantation Pulmonaire, Service de pneumologie, Hôpital Foch, Suresnes, France.

Laurent Mely (L)

Hôpital Renée Sabran, Cystic Fibrosis Center, Giens, France.

Sophie Ramel (S)

Centre de Ressources et de Compétences de la Mucoviscidose, Fondation Ildys, Roscoff, France.

Sylvie Montcouquiol (S)

CHU Clermont-Ferrand, Centre de Référence et de Compétence Mucoviscidose, Clermont-Ferrand, France.

Lydie Lemonnier (L)

Association Vaincre la Mucoviscidose, Paris, France.

Espérie Burnet (E)

Respiratory Medicine and Cystic Fibrosis National Reference Center, Cochin Hospital, Assistance Publique Hôpitaux de Paris (AP-HP), Paris, France; ERN-Lung CF network, Frankfurt, Germany.

Jean-Louis Paillasseur (JL)

Effi-stat, Paris, France.

Jennifer Da Silva (J)

Respiratory Medicine and Cystic Fibrosis National Reference Center, Cochin Hospital, Assistance Publique Hôpitaux de Paris (AP-HP), Paris, France; ERN-Lung CF network, Frankfurt, Germany; URC-CIC Paris Descartes Necker Cochin, AP-HP, Hôpital Cochin, Paris, France.

Pierre-Régis Burgel (PR)

Université de Paris, Institut Cochin, Inserm U1016, Paris, France; Respiratory Medicine and Cystic Fibrosis National Reference Center, Cochin Hospital, Assistance Publique Hôpitaux de Paris (AP-HP), Paris, France; ERN-Lung CF network, Frankfurt, Germany. Electronic address: pierre-regis.burgel@aphp.fr.

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