Robust Genetic Analysis of the X-Linked Anophthalmic (


Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
05 10 2022
Historique:
received: 05 08 2022
revised: 25 09 2022
accepted: 29 09 2022
entrez: 27 10 2022
pubmed: 28 10 2022
medline: 29 10 2022
Statut: epublish

Résumé

Anophthalmia (missing eye) describes a failure of early embryonic ocular development. Mutations in a relatively small set of genes account for 75% of bilateral anophthalmia cases, yet 25% of families currently are left without a molecular diagnosis. Here, we report our experimental work that aimed to uncover the developmental and genetic basis of the anophthalmia characterising the X-linked

Identifiants

pubmed: 36292683
pii: genes13101797
doi: 10.3390/genes13101797
pmc: PMC9601528
pii:
doi:

Substances chimiques

Transcription Factors 0
Chromatin 0
DNA 9007-49-2
Zic3 protein, mouse 0
Homeodomain Proteins 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Medical Research Council
ID : MC_UU_00009/2
Pays : United Kingdom
Organisme : Medical Research Council
ID : MR/S033165/1
Pays : United Kingdom
Organisme : Biotechnology and Biological Sciences Research Council
ID : BBS/E/D/10002071
Pays : United Kingdom

Déclaration de conflit d'intérêts

The authors declare no conflicts of interest.

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Auteurs

Brianda A Hernandez-Moran (BA)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Andrew S Papanastasiou (AS)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

David Parry (D)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Alison Meynert (A)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Philippe Gautier (P)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Graeme Grimes (G)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Ian R Adams (IR)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Violeta Trejo-Reveles (V)

The Division of Functional Genetics and Development, The Roslin Institute, Midlothian EH25 9RG, UK.

Hemant Bengani (H)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Margaret Keighren (M)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Ian J Jackson (IJ)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

David J Adams (DJ)

Wellcome Sanger Institute, Hinxton, Cambridgeshire CB10 1SA, UK.

David R FitzPatrick (DR)

MRC Human Genetics Unit, Institute of Genetics and Cancer, University of Edinburgh, Crewe Rd South, Edinburgh EH4 2XU, UK.

Joe Rainger (J)

The Division of Functional Genetics and Development, The Roslin Institute, Midlothian EH25 9RG, UK.

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Classifications MeSH