Sensitivity analyses in longitudinal clinical trials via distributional imputation.
Longitudinal clinical trial
distributional imputation
missing data
multiple imputation
sensitivity analysis
Journal
Statistical methods in medical research
ISSN: 1477-0334
Titre abrégé: Stat Methods Med Res
Pays: England
ID NLM: 9212457
Informations de publication
Date de publication:
01 2023
01 2023
Historique:
pubmed:
8
11
2022
medline:
5
1
2023
entrez:
7
11
2022
Statut:
ppublish
Résumé
Missing data is inevitable in longitudinal clinical trials. Conventionally, the missing at random assumption is assumed to handle missingness, which however is unverifiable empirically. Thus, sensitivity analyses are critically important to assess the robustness of the study conclusions against untestable assumptions. Toward this end, regulatory agencies and the pharmaceutical industry use sensitivity models such as return-to-baseline, control-based, and washout imputation, following the ICH E9(R1) guidance. Multiple imputation is popular in sensitivity analyses; however, it may be inefficient and result in an unsatisfying interval estimation by Rubin's combining rule. We propose distributional imputation in sensitivity analysis, which imputes each missing value by samples from its target imputation model given the observed data. Drawn on the idea of Monte Carlo integration, the distributional imputation estimator solves the mean estimating equations of the imputed dataset. It is fully efficient with theoretical guarantees. Moreover, we propose weighted bootstrap to obtain a consistent variance estimator, taking into account the variabilities due to model parameter estimation and target parameter estimation. The superiority of the distributional imputation framework is validated in the simulation study and an antidepressant longitudinal clinical trial.
Identifiants
pubmed: 36341772
doi: 10.1177/09622802221135251
pmc: PMC10950063
mid: NIHMS1975616
doi:
Substances chimiques
Antidepressive Agents
0
Benzenesulfonates
0
Types de publication
Journal Article
Research Support, U.S. Gov't, Non-P.H.S.
Research Support, N.I.H., Extramural
Langues
eng
Sous-ensembles de citation
IM
Pagination
181-194Subventions
Organisme : NIA NIH HHS
ID : R01 AG066883
Pays : United States
Organisme : NIEHS NIH HHS
ID : R01 ES031651
Pays : United States
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