Generation of an iPSC line from skin fibroblasts of a patient with Joubert syndrome carrying the homozygous loss of function variant c.787dupC in the AHI1 gene.


Journal

Stem cell research
ISSN: 1876-7753
Titre abrégé: Stem Cell Res
Pays: England
ID NLM: 101316957

Informations de publication

Date de publication:
02 2023
Historique:
received: 08 07 2022
revised: 04 12 2022
accepted: 07 12 2022
pubmed: 16 12 2022
medline: 17 1 2023
entrez: 15 12 2022
Statut: ppublish

Résumé

We produced an iPSC line from a patient with Joubert syndrome carrying the homozygous c.787dupC variant in the AHI1 gene. The iPSC line was obtained by reprogramming skin fibroblasts, mycoplasma-free, using Sendai-virus-based technique. Characterization of iPSCs showed the same Short Tandem Repeats profile than fibroblasts, normal karyotype, expression of staminal markers (OCT4, SOX2, SSEA4 and NANOG) and ability to differentiate into three germ layers in vitro.

Identifiants

pubmed: 36521382
pii: S1873-5061(22)00351-8
doi: 10.1016/j.scr.2022.103002
pii:
doi:

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

103002

Informations de copyright

Copyright © 2022. Published by Elsevier B.V.

Déclaration de conflit d'intérêts

Declaration of Competing Interest The authors declare that they have no known competing financial interests or personal relationships that could have appeared to influence the work reported in this paper.

Auteurs

V Serpieri (V)

Neurogenetics Research Centre, IRCCS Mondino Foundation, Pavia, Italy.

A Orsi (A)

Department of Molecular Medicine, University of Pavia, Pavia, Italy.

C Mazzotta (C)

Department of Molecular Medicine, University of Pavia, Pavia, Italy.

S Cavan (S)

Department of Molecular Medicine, University of Pavia, Pavia, Italy.

E Rossi (E)

Neurogenetics Research Centre, IRCCS Mondino Foundation, Pavia, Italy; Department of Molecular Medicine, University of Pavia, Pavia, Italy.

B Scelsa (B)

Unit of Pediatric Neurology, Vittore Buzzi Hospital, ASST Fatebenefratelli Sacco, Milan, Italy.

E M Valente (EM)

Neurogenetics Research Centre, IRCCS Mondino Foundation, Pavia, Italy; Department of Molecular Medicine, University of Pavia, Pavia, Italy. Electronic address: enzamaria.valente@unipv.it.

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Classifications MeSH