FGF9 SYNS3 cleft palate craniosynostoses fusion of interphalangeal joints human genetics multiple synostoses syndrome type 3 whole exome sequencing

Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
15 03 2023
Historique:
received: 03 02 2023
revised: 08 03 2023
accepted: 13 03 2023
medline: 30 3 2023
entrez: 29 3 2023
pubmed: 30 3 2023
Statut: epublish

Résumé

Multiple synostoses syndrome (OMIM: #186500, #610017, #612961, #617898) is a genetically heterogeneous group of autosomal dominant diseases characterized by abnormal bone unions. The joint fusions frequently involve the hands, feet, elbows or vertebrae. Pathogenic variants in

Identifiants

pubmed: 36980996
pii: genes14030724
doi: 10.3390/genes14030724
pmc: PMC10048304
pii:
doi:

Substances chimiques

FGF9 protein, human 0
Fibroblast Growth Factor 9 0

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Références

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Auteurs

Ariane Schmetz (A)

Institute of Human Genetics, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Jörg Schaper (J)

Center for Rare Diseases, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Simon Thelen (S)

Department of Orthopedic and Trauma Surgery, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Majeed Rana (M)

Department of Oral, Maxillo- and Plastic Facial Surgery, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Thomas Klenzner (T)

Department of Otorhinolaryngology, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Katharina Schaumann (K)

Department of Otorhinolaryngology, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Jasmin Beygo (J)

Institute of Human Genetics, University Hospital Essen, University Duisburg-Essen, 45147 Essen, Germany.

Harald Surowy (H)

Institute of Human Genetics, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Hermann-Josef Lüdecke (HJ)

Institute of Human Genetics, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

Dagmar Wieczorek (D)

Institute of Human Genetics, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.
Center for Rare Diseases, Medical Faculty and University Hospital Düsseldorf, Heinrich Heine University Düsseldorf, 40225 Düsseldorf, Germany.

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Classifications MeSH